{"id":"W4362704228","doi":"10.1007/s40273-023-01262-x","title":"Developing a Framework of Cost Elements of Socioeconomic Burden of Rare Disease: A Scoping Review","year":2023,"lang":"en","type":"review","venue":"PharmacoEconomics","topic":"Genomics and Rare Diseases","field":"Biochemistry, Genetics and Molecular Biology","cited_by":13,"is_retracted":false,"has_abstract":false,"ca_institutions":"Hospital for Sick Children; Alberta Health Services; SickKids Foundation; University of Toronto; Ontario Genomics; Children's Hospital of Eastern Ontario; Genome Canada; Alberta Bone and Joint Health Institute; McGill University; University of Ottawa; Institute for Clinical Evaluative Sciences; University of Calgary; Alberta Children's Hospital","funders":"Canadian Institutes of Health Research","keywords":"EconLit; PsycINFO; Health economics; Socioeconomic status; Medicine; Health care; Systematic review; MEDLINE; Health administration; Rare disease; Comparability; Public health; Family medicine; Disease; Nursing; Environmental health; Population; Political science; Economic growth; Economics; Pathology","routes":{"ca_aff":true,"ca_fund":true,"ca_venue":false,"about_ca":false,"invisible_to_affiliation_only":false},"retraction":null,"screen":null,"direct_labels":[],"prediction":{"model_version":"metacan-v3-hybrid-931329e0061c","candidate_categories":[],"consensus_categories":[],"category_scores_codex":[0.01295765,0.001946564,0.00446205,0.01016595,0.0006803208,0.005454725,0.002554058,0.003178274,0.004599886],"category_scores_gemma":[0.03525176,0.0008786601,0.003274492,0.009952056,0.001792593,0.005689259,0.002998802,0.003650927,0.0005170385],"about_ca_system_candidate":false,"about_ca_system_consensus":false,"about_ca_system_score_codex":0.006223215,"about_ca_system_score_gemma":0.01373461,"about_ca_topic_candidate":false,"about_ca_topic_consensus":false,"about_ca_topic_score_codex":0.0116135,"about_ca_topic_score_gemma":0.01770552,"domain_scores_codex":[0.995544,0.001891414,0.0009466559,0.0004014204,0.001019504,0.0001969905],"domain_scores_gemma":[0.972568,0.02334246,0.001609113,0.0002563795,0.002030127,0.0001939949],"domain_codex":null,"domain_gemma":null,"domain_candidate":null,"domain_consensus":null,"study_design_codex":"design_other","study_design_gemma":"systematic_review","study_design_scores_codex":[0.0001472943,0.00007488731,0.001654488,0.1558708,0.002985146,0.0002811568,0.0005203661,0.002843236,0.0001918408,0.07684185,0.02083205,0.7377568],"study_design_scores_gemma":[0.00009327549,0.0001129721,0.003615526,0.5959689,0.007354272,0.0008716943,0.001035517,0.001390687,0.0002056464,0.05801718,0.3312159,0.0001183267],"study_design_candidate":"systematic_review","study_design_consensus":null,"genre_codex":"review","genre_gemma":"review","genre_scores_codex":[0.0001447387,0.9958019,0.0008044093,0.002191147,0.0002608156,0.00003108659,0.00009598209,0.000005842039,0.0006641157],"genre_scores_gemma":[0.002884804,0.9941849,0.0015221,0.0008827679,0.0002439757,0.00008331461,0.00007274984,0.000004165759,0.0001212412],"genre_candidate":"review","genre_consensus":"review","teacher_disagreement_score":0.01295765,"threshold_uncertainty_score":0.0685274,"prediction_status":"machine_predicted_unvalidated"},"machine_scores":{"provisional":true,"baseline":true,"maturity_gate_passed":false,"score_opus":0.06618045749901443,"score_gpt":0.4211234294511541,"score_spread":0.3549429719521396,"validation_status":"score_only:v0-immature-baseline","note":"Baseline scores from an immature model (maturity gate not passed). Scores rank; they never assert a category."}}