MétaCan
Menu
Back to cohort

Adrenal Disorders and Pubertal Development in Children: Hormonal Pathways, Timing Disruptions and Clinical Outcome

2025· article· W4416722267 on OpenAlex

Why this work is in the frame

A frame that forgets how it found something cannot be audited. These are the routes that admitted this work.

aboutThe title or abstract carries a Canadian signal from the geographic lexicon.
no affNo Canadian affiliation: this work is invisible to an affiliation-only frame.
No Canadian affiliation. An affiliation-only frame, the usual design, would never have seen this work. It is one of the works that make the case for inverting the frame.

Bibliographic record

VenueGSC Advanced Research and Reviews · 2025
Typearticle
Language
FieldBiochemistry, Genetics and Molecular Biology
TopicSexual Differentiation and Disorders
Canadian institutionsnot available
Fundersnot available
KeywordsAdrenal disorderAdrenal crisisAdrenal insufficiencyCongenital adrenal hyperplasiaPrecocious pubertyHypogonadotropic hypogonadismGlucocorticoid

Abstract

fetched live from OpenAlex

Background: Pubertal development is tightly regulated by the hypothalamic–pituitary–gonadal axis and modulated by adrenal glucocorticoids and androgens. Disruption of adrenal function—through hyposecretion or hypersecretion—can alter the timing, tempo, and outcome of puberty, but data are scattered across heterogeneous pediatric conditions. This review integrates current evidence on how adrenal disorders shape pubertal development and growth outcomes, and to what extent these abnormalities are reversible with treatment. Methods: A structured narrative review was conducted using PubMed/MEDLINE, Scopus, and Google Scholar (January 2000–June 2025). Search terms combined adrenal disorders (e.g., adrenal insufficiency, congenital adrenal hyperplasia, Cushing syndrome, premature adrenarche, adrenal hypoplasia congenita, Triple A syndrome, McCune–Albright syndrome) with pubertal terms (delayed puberty, precocious puberty, pubertal progression, adrenarche, pubarche). Human studies in patients <20 years reporting adrenal diagnosis plus at least one pubertal or growth outcome were included. Case reports (<5 patients), adult-only series, purely biochemical reports, and non–full-text abstracts were excluded. Study quality was assessed using a modified Newcastle–Ottawa Scale and synthesized qualitatively in four domains: adrenal hyposecretion, hypersecretion, syndromic disorders, and reversibility. Results: Adrenal hyposecretion (primary and central adrenal insufficiency, adrenal hypoplasia, familial glucocorticoid deficiency, autoimmune polyglandular syndromes) was consistently associated with delayed adrenarche, delayed or sparse pubarche, slow pubertal progression, and reduced growth velocity. Syndromic forms (e.g., DAX-1–related adrenal hypoplasia, Triple A, IMAGe, APS-1) frequently combined adrenal failure with hypogonadotropic hypogonadism or primary gonadal failure, leading to profound pubertal delay or absent puberty. In contrast, adrenal hypersecretion states showed a spectrum from mild to severe precocious development. Classic 21-hydroxylase–deficient congenital adrenal hyperplasia, nonclassic CAH, premature adrenarche, and androgen-secreting adrenal tumors were linked to premature pubarche, virilization, advanced bone age, and, in many cases, central precocious puberty with compromised adult height. Cushing syndrome (ACTH-dependent and independent) uniquely caused growth failure and pubertal delay due to cortisol-mediated suppression of GnRH, gonadotropins, and growth hormone action. Across disorders, early and optimized treatment improved pubertal trajectories: strict androgen control in CAH limited progression and preserved height; surgical cure of Cushing syndrome allowed recovery of pubertal progression; metabolic management in premature adrenarche mitigated progression to early menarche and PCOS. However, in genetic syndromic adrenal insufficiency, pubertal abnormalities were rarely reversible without exogenous sex-steroid or gonadotropin replacement. Overall study quality was moderate to high, supporting the robustness of these patterns. Conclusions: Adrenal hypofunction predominantly delays puberty, whereas adrenal androgen excess accelerates or distorts pubertal onset, and cortisol excess suppresses pubertal maturation and growth. Many pubertal disturbances are partially reversible when adrenal disorders are recognized and treated early, but syndromic forms often require lifelong hormone replacement. Routine pubertal surveillance in children with adrenal disease and integrated hormonal, metabolic, and genetic evaluation are essential to optimize growth and reproductive outcomes.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.001
metaresearch head score (Gemma)0.001
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMeta-epidemiology (narrow)
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.649
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0010.001
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0010.000
Bibliometrics0.0000.000
Science and technology studies0.0000.001
Scholarly communication0.0000.000
Open science0.0000.001
Research integrity0.0000.001
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.096
GPT teacher head0.444
Teacher spread0.348 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it