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Developmental Onset of Polysaccharide Storage Myopathy in 4 Quarter Horse Foals

2002· article· en· W2036106856 on OpenAlexaboutno aff
Flávio Desessards De La Côrte, Stephanie J. Valberg, Jennifer M. MacLeay, James R. Mickelson

Bibliographic record

VenueJournal of Veterinary Internal Medicine · 2002
Typearticle
Languageen
FieldMedicine
TopicGlycogen Storage Diseases and Myoclonus
Canadian institutionsnot available
Fundersnot available
KeywordsMedicineHorseMyopathyQuarter (Canadian coin)PediatricsInternal medicine

Abstract

fetched live from OpenAlex

Polysaccharide storage myopathy (PSSM) is characterized by the accumulation of glycogen and an abnormal polysaccharide in the skeletal muscle fibers of Quarter Horse–related breeds. Glycogen storage disorders have been identified in human beings and other animal species that are due to single gene mutations causing deficiencies in the enzyme activities of the glycogenolytic or glycolytic pathways.1 Biochemical studies have demonstrated that horses with PSSM have functional glycogenolytic and glycolytic pathways.2 More recently, muscle glycogen and abnormal polysaccharide accumulation in PSSM horses have been suggested to be due to a novel defect in glucose transport in skeletal muscle. Results of IV and oral glucose tolerance tests in adult PSSM horses indicated that affected individuals have enhanced glucose clearance from the bloodstream, which occurs at lower insulin concentrations than in controls.3 Clinical signs of PSSM include muscle stiffness, pain, and reluctance to exercise and are usually 1st noticed in adult horses at the commencement of training or when exercise resumes after a lay-up period.4 Serum creatine kinase (CK) activity may be high at rest in PSSM horses and can increase up to 80,000 IU/L after a 15-minute submaximal exercise test.5 Although pedigree analysis suggests that PSSM is probably transmitted as an autosomal recessive trait, there is little information about the expression of the disease from birth to the beginning of training at 2–3 years of age.6 Recently, 2 foals with pneumonia developed severe rhabdomyolysis and were diagnosed with PSSM, suggesting that, under certain circumstances, this disorder may be expressed in young animals.7 The purpose of this longitudinal study was to follow the offspring from PSSM mares bred to a closely related stallion to determine the age of onset of skeletal muscle glycogen and abnormal polysaccharide accumulation, enhanced glucose clearance, and exertional rhabdomyolysis that are indicative of PSSM. The

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesInsufficient payload (model declined to judge)
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Case report · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.512
Threshold uncertainty score0.999

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0010.000
Bibliometrics0.0010.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0020.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.041
GPT teacher head0.302
Teacher spread0.261 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

Study designCase report
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations64
Published2002
Admission routes1
Has abstractyes

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