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Record W2223510497 · doi:10.1093/pch/18.5.251

Fragile X syndrome: Are paediatric health care providers missing the diagnosis?

2013· article· en· W2223510497 on OpenAlexaff
Gudrun Aubertin

Bibliographic record

VenuePaediatrics & Child Health · 2013
Typearticle
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicGenetics and Neurodevelopmental Disorders
Canadian institutionsVictoria General Hospital
Fundersnot available
KeywordsFragile X syndromeMedicineHealth carePediatricsIntensive care medicineFamily medicinePsychiatry

Abstract

fetched live from OpenAlex

A 12-month-old boy is referred to you for developmental delay. He was slow to roll over and began sitting unassisted at 10 months of age. In retrospect, the parents believe he was floppy and less sociable compared with his older sister. Otherwise, his health is generally good, with normal growth. The pregnancy and delivery were uncomplicated. On the maternal side, an aunt experienced infertility secondary to early menopause in her twenties, and the grandfather, currently in his sixties, has experienced some balance problems and a tremor. On physical examination, the height, weight and head circumference are all in the 50th to 85th percentiles. There are no dysmorphic features. The examination is noteworthy for generalized low muscle tone and reduced social interaction. The child is diagnosed with global developmental delay. Investigations show a full mutation in the FMR1 gene, consistent with fragile X syndrome (FXS). A referral for genetic counselling is recommended.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.006
metaresearch head score (Gemma)0.064
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Not applicable · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: none
Teacher disagreement score0.018
Threshold uncertainty score0.041

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0060.064
Meta-epidemiology (narrow)0.0000.001
Meta-epidemiology (broad)0.0020.000
Bibliometrics0.0010.001
Science and technology studies0.0020.002
Scholarly communication0.0030.008
Open science0.0020.002
Research integrity0.0060.009
Insufficient payload (model declined to judge)0.0120.002

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.008
GPT teacher head0.238
Teacher spread0.230 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designNot applicable
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

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Citations0
Published2013
Admission routes1
Has abstractno

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