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Record W2583663599 · doi:10.1038/ejhg.2016.203

Evaluation of copy-number variants as modifiers of breast and ovarian cancer risk for BRCA1 pathogenic variant carriers

2017· article· en· W2583663599 on OpenAlexafffund
Logan C. Walker, Louise Marquart, George A. R. Wiggins, Tracy A. O’Mara, Michael T. Parsons, Daniel Barrowdale, Lesley McGuffog, Joe Dennis, Javier Benı́tez, Thomas P. Slavin, Paolo Radice, Debra Frost, Andrew K. Godwin, Alfons Meindl, Rita K. Schmutzler, Claudine Isaacs, Beth N. Peshkin, Trinidad Caldés, Frans B.L. Hogervorst, Conxi Lázaro, Anna Jakubowska, Marco Montagna, Kenneth Offit, Peter J. Hulick, Irene L. Andrulis, Annika Lindblom, Robert L. Nussbaum, Katherine L. Nathanson, Georgia Chenevix‐Trench, Antonis C. Antoniou, Fergus J. Couch, Amanda B. Spurdle

Bibliographic record

VenueEuropean Journal of Human Genetics · 2017
Typearticle
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicBRCA gene mutations in cancer
Canadian institutionsLunenfeld-Tanenbaum Research InstituteMount Sinai Hospital
FundersNational Cancer InstituteInstituto de Salud Carlos IIICanadian Institutes of Health ResearchUnicancerCentre Léon BérardRoyal Marsden NHS Foundation TrustUmeå UniversitetIstituto Oncologico VenetoNIH Office of the DirectorUniversiteit LeidenInstitut Claudius RegaudHospices Civils de LyonInstitut BergoniéDeutsche KrebshilfeInstitut National Du CancerLeids Universitair Medisch CentrumAssociazione Italiana per la Ricerca sul CancroUniversità degli Studi di FirenzeLinköpings UniversitetLunds UniversitetNederlandse Organisatie voor Wetenschappelijk OnderzoekInstitut Català de la SalutUniversity of PennsylvaniaInstitut Gustave-RoussySahlgrenska UniversitetssjukhusetErasmus Medisch CentrumVrije Universiteit AmsterdamNational Breast Cancer FoundationRadboud Universitair Medisch CentrumGeneralitat de CatalunyaNational Institute for Health and Care ResearchUniversity of California, San FranciscoCreighton UniversityFox Chase Cancer CenterMedical Research CouncilUppsala UniversitetMemorial Sloan-Kettering Cancer CenterNational Institutes of HealthDavid F. and Margaret T. Grohne Family FoundationFundación Mutua MadrileñaRadboud UniversiteitKansas Bioscience AuthorityNational Health and Medical Research CouncilFisher Center for Alzheimer's Research FoundationUniversitair Medisch Centrum GroningenKWF KankerbestrijdingCancer Research UKSusan G. Komen for the CureGeorgetown UniversityCancer Center, University of KansasCancerfondenCancer AustraliaBreast Cancer Research FoundationMinistero della Salute
KeywordsOvarian cancerBreast cancerCopy-number variationSingle-nucleotide polymorphismGenome-wide association studyBiologyGeneticsLocus (genetics)AlleleCancerSNPGeneBioinformaticsGenotypeGenome

Abstract

fetched live from OpenAlex

Genome-wide studies of patients carrying pathogenic variants (mutations) in BRCA1 or BRCA2 have reported strong associations between single-nucleotide polymorphisms (SNPs) and cancer risk. To conduct the first genome-wide association analysis of copy-number variants (CNVs) with breast or ovarian cancer risk in a cohort of 2500 BRCA1 pathogenic variant carriers, CNV discovery was performed using multiple calling algorithms and Illumina 610k SNP array data from a previously published genome-wide association study. Our analysis, which focused on functionally disruptive genomic deletions overlapping gene regions, identified a number of loci associated with risk of breast or ovarian cancer for BRCA1 pathogenic variant carriers. Despite only including putative deletions called by at least two or more algorithms, detection of selected CNVs by ancillary molecular technologies only confirmed 40% of predicted common (>1% allele frequency) variants. These include four loci that were associated (unadjusted P<0.05) with breast cancer (GTF2H2, ZNF385B, NAALADL2 and PSG5), and two loci associated with ovarian cancer (CYP2A7 and OR2A1). An interesting finding from this study was an association of a validated CNV deletion at the CYP2A7 locus (19q13.2) with decreased ovarian cancer risk (relative risk=0.50, P=0.007). Genomic analysis found this deletion coincides with a region displaying strong regulatory potential in ovarian tissue, but not in breast epithelial cells. This study highlighted the need to verify CNVs in vitro, but also provides evidence that experimentally validated CNVs (with plausible biological consequences) can modify risk of breast or ovarian cancer in BRCA1 pathogenic variant carriers.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.003
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Bench or experimental · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.724
Threshold uncertainty score0.589

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0030.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.032
GPT teacher head0.328
Teacher spread0.297 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designBench or experimental
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations40
Published2017
Admission routes2
Has abstractyes

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