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Record W2593381029 · doi:10.14740/jmc.v8i3.2801

Identification of Novel Mutation in EIF2AK3 Gene as a Causal Variant in a Family With Rare Disease

2017· article· en· W2593381029 on OpenAlexvenueno aff
Raziyeh Khalesi, Masoud Garshasbi

Bibliographic record

VenueJournal of Medical Cases · 2017
Typearticle
Languageen
FieldMedicine
TopicPancreatic function and diabetes
Canadian institutionsnot available
Fundersnot available
KeywordsFrameshift mutationMissense mutationGeneticsExonMedicineGeneMutationDiseaseBiologyInternal medicine

Abstract

fetched live from OpenAlex

Wolcott-Rallison syndrome (WRS) is now identified as the most frequent cause of neonatal/early onset diabetes in patients that initiated before 6 months of age. Inheritance pattern of disease is autosomal recessive and most of patients are from populations with frequent consanguineous marriages. WRS is caused by mutations in EIF2AK3 gene which encodes eukaryotic translation initiation factor 2a kinase. Several mutations have been reported in this gene and they are almost non-sense, frameshift, missense, and splice site. Here, we analyzed the EIF2AK3 gene in an Iranian girl suspicious for WRS. Sequencing analysis of the gene identified a homozygous novel non-sense mutation in exon 9 of the gene, Y479X. J Med Cases. 2017;8(3):102-104 doi: https://doi.org/10.14740/jmc2597e

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.001
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Case report · Consensus signal: Case report
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.004
Threshold uncertainty score0.014

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.001
Meta-epidemiology (narrow)0.0010.001
Meta-epidemiology (broad)0.0010.001
Bibliometrics0.0020.001
Science and technology studies0.0020.001
Scholarly communication0.0010.001
Open science0.0010.001
Research integrity0.0020.001
Insufficient payload (model declined to judge)0.0040.001

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.036
GPT teacher head0.326
Teacher spread0.290 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designCase report
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations1
Published2017
Admission routes1
Has abstractyes

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