MétaCan
Menu
Back to cohort
Record W2937319110 · doi:10.1002/mds.27659

Parkinson's disease age at onset genome‐wide association study: Defining heritability, genetic loci, and α‐synuclein mechanisms

2019· article· en· W2937319110 on OpenAlexafffund
Cornelis Blauwendraat, Karl Heilbron, Costanza L. Vallerga, Sara Bandrés‐Ciga, Rainer von Coelln, Lasse Pihlstrøm, Javier Simón‐Sánchez, Claudia Schulte, Manu Sharma, Lynne Krohn, Ari Siitonen, Hirotaka Iwaki, Hampton L. Leonard, Alastair J. Noyce, Manuela Tan, J. Raphael Gibbs, Dena Hernández, Sonja W. Scholz, Joseph Jankovic, Lisa M. Shulman, Suzanne Lesage, Jean‐Christophe Corvol, Alexis Brice, Jacobus J. van Hilten, Johan Marinus, Johanna Eerola‐Rautio, Pentti J. Tienari, Kari Majamaa, Mathias Toft, Donald G. Grosset, Thomas Gasser, Peter Heutink, Joshua Shulman, John Hardy, Huw R. Morris, David A. Hinds, Jacob Gratten, Peter M. Visscher, Ziv Gan‐Or, Mike A. Nalls, Andrew Singleton

Bibliographic record

VenueMovement Disorders · 2019
Typearticle
Languageen
FieldMedicine
TopicParkinson's Disease Mechanisms and Treatments
Canadian institutionsMcGill UniversityMcGill Genome CentreMontreal Neurological Institute and Hospital
FundersNational Institute of Environmental Health SciencesNational Institute of Neurological Disorders and StrokeGenentechH. Lundbeck A/SNational Cancer InstituteServierBundesministerium für Bildung und ForschungUniversity of GlasgowParkinson's UKMultiple System Atrophy CoalitionInstitute of GeneticsBarts CharityCanada First Research Excellence FundBristol-Myers SquibbAmerican Parkinson Disease AssociationConsortium canadien en neurodégénérescence associée au vieillissementEU Joint Programme – Neurodegenerative Disease ResearchUniversity College LondonWellcome TrustDeutsche ForschungsgemeinschaftMcGill UniversityHelsingin YliopistoU.S. Department of DefenseEli Lilly and CompanyItä-Suomen YliopistoMichael J. Fox Foundation for Parkinson's ResearchNational Institute on AgingNational Institute for Health and Care ResearchMedical Research CouncilTeva Pharmaceutical IndustriesPfizerBiogenHelsingin ja Uudenmaan SairaanhoitopiiriGlaxoSmithKlineU.S. Department of Health and Human ServicesNational Institutes of HealthRosetrees Trust
KeywordsGenome-wide association studyGenetic associationHeritabilityAge of onsetMissing heritability problemGeneticsBiologyDiseaseAlleleBonferroni correctionParkinson's diseaseGenetic variationMedicineGenotypeSingle-nucleotide polymorphismInternal medicineGene

Abstract

fetched live from OpenAlex

BACKGROUND: Increasing evidence supports an extensive and complex genetic contribution to PD. Previous genome-wide association studies (GWAS) have shed light on the genetic basis of risk for this disease. However, the genetic determinants of PD age at onset are largely unknown. OBJECTIVES: To identify the genetic determinants of PD age at onset. METHODS: Using genetic data of 28,568 PD cases, we performed a genome-wide association study based on PD age at onset. RESULTS: We estimated that the heritability of PD age at onset attributed to common genetic variation was ∼0.11, lower than the overall heritability of risk for PD (∼0.27), likely, in part, because of the subjective nature of this measure. We found two genome-wide significant association signals, one at SNCA and the other a protein-coding variant in TMEM175, both of which are known PD risk loci and a Bonferroni-corrected significant effect at other known PD risk loci, GBA, INPP5F/BAG3, FAM47E/SCARB2, and MCCC1. Notably, SNCA, TMEM175, SCARB2, BAG3, and GBA have all been shown to be implicated in α-synuclein aggregation pathways. Remarkably, other well-established PD risk loci, such as GCH1 and MAPT, did not show a significant effect on age at onset of PD. CONCLUSIONS: Overall, we have performed the largest age at onset of PD genome-wide association studies to date, and our results show that not all PD risk loci influence age at onset with significant differences between risk alleles for age at onset. This provides a compelling picture, both within the context of functional characterization of disease-linked genetic variability and in defining differences between risk alleles for age at onset, or frank risk for disease. © 2019 International Parkinson and Movement Disorder Society.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.004
metaresearch head score (Gemma)0.005
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.005
Threshold uncertainty score0.022

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0040.005
Meta-epidemiology (narrow)0.0010.000
Meta-epidemiology (broad)0.0010.001
Bibliometrics0.0010.002
Science and technology studies0.0010.000
Scholarly communication0.0010.000
Open science0.0000.001
Research integrity0.0010.001
Insufficient payload (model declined to judge)0.0010.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.008
GPT teacher head0.229
Teacher spread0.221 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations374
Published2019
Admission routes2
Has abstractyes

Explore more

Same venueMovement DisordersSame topicParkinson's Disease Mechanisms and TreatmentsFrench-language works237,207