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Record W2955142473 · doi:10.1371/journal.pone.0218115

Pharmacogenomics of statin-related myopathy: Meta-analysis of rare variants from whole-exome sequencing

2019· review· en· W2955142473 on OpenAlexaff
James S. Floyd, Katarzyna Bloch, Jennifer A. Brody, Cyrielle Maroteau, Moneeza K. Siddiqui, Richard I. Gregory, Daniel F. Carr, Mariam Molokhia, Xiaoming Liu, Joshua C. Bis, Ammar Ahmed, Xuan Liu, Pär Hallberg, Qun‐Ying Yue, Patrik K. E. Magnusson, Diane Brisson, Kerri L. Wiggins, Alanna C. Morrison, Étienne Khoury, Paul McKeigue, Bruno H. Stricker, Maryse Lapeyre‐Mestre, Susan R. Heckbert, Arlene M. Gallagher, Hector Chinoy, Richard A. Gibbs, Emmanuelle Bondon‐Guitton, Russell P. Tracy, Eric Boerwinkle, Daniel Gaudet, Anita Conforti, Tjeerd van Staa, Colleen M. Sitlani, Kenneth Rice, Anke H. Maitland‐van der Zee, Mia Wadelius, Andrew P. Morris, Munir Pirmohamed, Bruce M. Psaty, Ana Alfirevic

Bibliographic record

VenuePLoS ONE · 2019
Typereview
Languageen
FieldMedicine
TopicLipoproteins and Cardiovascular Health
Canadian institutionsUniversité de MontréalUniversité du Québec à Chicoutimi
FundersNational Institute on AgingEngineering and Physical Sciences Research CouncilMedical Research CouncilNational Heart, Lung, and Blood InstituteVetenskapsrådetScience for Life LaboratoryNational Institutes of HealthUppsala UniversitetKarolinska InstitutetEconomic and Social Research CouncilEuropean CommissionKnut och Alice Wallenbergs StiftelseKing's College LondonNational Institute for Health and Care ResearchUniversity of LiverpoolNational Human Genome Research InstituteWellcome Trust
KeywordsExome sequencingStatinRhabdomyolysisExomePharmacogenomicsMyopathyMedicineGenome-wide association studyMinor allele frequencyMeta-analysisBioinformaticsGeneticsInternal medicineAlleleAllele frequencyBiologySingle-nucleotide polymorphismGenotypeMutationGenePharmacology

Abstract

fetched live from OpenAlex

AIMS: Statin-related myopathy (SRM), which includes rhabdomyolysis, is an uncommon but important adverse drug reaction because the number of people prescribed statins world-wide is large. Previous association studies of common genetic variants have had limited success in identifying a genetic basis for this adverse drug reaction. We conducted a multi-site whole-exome sequencing study to investigate whether rare coding variants confer an increased risk of SRM. METHODS AND RESULTS: SRM 3-5 cases (N = 505) and statin treatment-tolerant controls (N = 2047) were recruited from multiple sites in North America and Europe. SRM 3-5 was defined as symptoms consistent with muscle injury and an elevated creatine phosphokinase level >4 times upper limit of normal without another likely cause of muscle injury. Whole-exome sequencing and variant calling was coordinated from two analysis centres, and results of single-variant and gene-based burden tests were meta-analysed. No genome-wide significant associations were identified. Given the large number of cases, we had 80% power to identify a variant with minor allele frequency of 0.01 that increases the risk of SRM 6-fold at genome-wide significance. CONCLUSIONS: In this large whole-exome sequencing study of severe statin-related muscle injury conducted to date, we did not find evidence that rare coding variants are responsible for this adverse drug reaction. Larger sample sizes would be required to identify rare variants with small effects, but it is unclear whether such findings would be clinically actionable.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.014
metaresearch head score (Gemma)0.021
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Meta-analysis · Consensus signal: Meta-analysis
GenreCandidate signal: Review · Consensus signal: Review
Teacher disagreement score0.014
Threshold uncertainty score0.073

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0140.021
Meta-epidemiology (narrow)0.0020.001
Meta-epidemiology (broad)0.0060.029
Bibliometrics0.0040.005
Science and technology studies0.0010.001
Scholarly communication0.0020.001
Open science0.0020.002
Research integrity0.0020.002
Insufficient payload (model declined to judge)0.0020.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.280
GPT teacher head0.345
Teacher spread0.065 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designMeta-analysis
Domainnot available
GenreReview

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations51
Published2019
Admission routes1
Has abstractyes

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Same venuePLoS ONESame topicLipoproteins and Cardiovascular HealthFrench-language works237,207