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Record W2986932567 · doi:10.1016/s1474-4422(19)30320-5

Identification of novel risk loci, causal insights, and heritable risk for Parkinson's disease: a meta-analysis of genome-wide association studies

2019· review· en· W2986932567 on OpenAlexaff
Mike A. Nalls, Cornelis Blauwendraat, Costanza L. Vallerga, Karl Heilbron, Sara Bandrés‐Ciga, Diana Chang, Manuela Tan, Demis A. Kia, Alastair J. Noyce, Angli Xue, José Brás, Emily Young, Rainer von Coelln, Claudia Schulte, Manu Sharma, Lynne Krohn, Lasse Pihlstrøm, Ari Siitonen, Hampton L. Leonard, Faraz Faghri, Dena Hernández, Sonja W. Scholz, Juan A. Botía, María Martínez, Jean‐Christophe Corvol, Joseph Jankovic, Lisa M. Shulman, Margaret Sutherland, Pentti J. Tienari, Kari Majamaa, Mathias Toft, Ole A. Andreassen, Tushar Bangale, Alexis Brice, Jian Yang, Ziv Gan‐Or, Thomas Gasser, Joshua Shulman, Nicholas Wood, David A. Hinds, John Hardy, Peter M. Visscher, Robert Graham, Astrid Adarmes‐Gómez, Miquel Aguilar, Akbota Aitkulova, Vadim Akhmetzhanov, Roy N. Alcalay, Ignacio Álvarez, Victoria Álvarez, Francisco Javier Barrero, Jesús Alberto Bergareche Yarza, Inmaculada Bernal‐Bernal, Kimberley J. Billingsley, Marta Bonilla‐Toribio, María Teresa Boungiorno, Kathrin Brockmann, Vivien J. Bubb, Dolores Buiza‐Rueda, Anna Maria Novella Càmara, Fátima Carrillo, Mario Carrión‐Claro, Debora Cerdan, Viorica Chelban, Jordi Clarimón, Carl E Clarke, Yaroslau Compta, Mark Cookson, David W. Craig, Fabrice Danjou, Mónica Díez-Fairén, Oriol Dols‐Icardo, J. Duarte, Raquel Durán, Francisco Escamilla‐Sevilla, Valentina Escott‐Price, Mario Ezquerra, Cici Feliz, Manel Fernández, Rubén Fernández‐Santiago, Steven Finkbeiner, Thomas Foltynie, Ciara García, Pedro Ruiz, María José Gómez Heredia, Pilar Gómez‐Garre, Manuel Menéndez‐González, Isabel González Aramburu, Sebastian Guelfi, Rita Guerreiro, Sharon Hassin‐Baer, Janet Hoenicka, Peter Holmans, Henry Houlden, Jon Infante, Silvia Jesús, Adriano Jiménez‐Escrig, Gulnaz Kaishybayeva, Rauan Kaiyrzhanov, Altynay Karimova, Kerri J. Kinghorn, Sulev Kõks, Jaime Kulisevsky, Miguel A. Labrador‐Espinosa, Patrick A. Lewis, José Luis López-Sendón, Ruth C. Lovering, Steven Lubbe, Codrin Lungu, Daniel Macías, Claudia Manzoni, Juan Marín‐Lahoz, Johan Marinus, Marı́a José Martı́, Irene Martínez‐Torres, Juan Carlos Martínez‐Castrillo, Marina Mata, Niccolò E. Mencacci, Carlota Méndez‐del‐Barrio, Ben Middlehurst, Adolfo Mínguez‐Castellanos, Pablo Mir, Kin Y. Mok, Esteban Muñoz, Derek P. Narendra, Oluwadamilola O. Ojo, Njideka Okubadejo, Ana Gorostidi Pagola, Pau Pástor, Francisco Pérez Errazquin, María Teresa Periñán, Hélène Plun‐Favreau, John P. Quinn, Lea R’Bibo, Xylena Reed, Elisabet Mondragón Rezola, Mie Rizig, Patrizia Rizzu, Laurie Robak, A Rodríguez, Guy A. Rouleau, Javier Ruiz‐Martínez, Clara Ruz, Mina Ryten, Dinara Sadykova, Sebastian R. Schreglmann, Chingiz Shashkin, María Sierra, Esther Suárez-Sanmartín, Pille Taba, César Tabernero, Manuela X Tan, Juan Pablo Tartari, Cristina Tejera‐Parrado, Eduard Tolosa, Daniah Trabzuni, Francesc Valldeoriola, Jacobus J. van Hilten, Kendall Van Keuren‐Jensen, Laura Vargas‐González, Lydia Vela, Francisco Vives, Nigel Williams, Nazira Zharkinbekova, Elena Zholdybayeva, Alexander Zimprich, Pauli Ylikotila, Stephen G. Reich, Joseph M. Savitt, Michelle Agee, Babak Alipanahi, Adam Auton, Robert K. Bell, Katarzyna Bryc, Sarah L. Elson, Pierre Fontanillas, Nicholas A. Furlotte, Karen E. Huber, Barry Hicks, Ethan M. Jewett, Yunxuan Jiang, Aaron Kleinman, Keng‐Han Lin, Nadia K. Litterman, Jennifer C. McCreight, Matthew H. McIntyre, Kimberly F. McManus, Joanna L. Mountain, Elizabeth S. Noblin, Carrie A. M. Northover, Steven J. Pitts, G. David Poznik, J. Fah Sathirapongsasuti, Janie F. Shelton, Suyash Shringarpure, Chao Tian, Joyce Y. Tung, Vladimir Vacic, Xin Wang, Catherine H. Wilson, Tim Anderson, Steven R. Bentley, John C. Dalrymple‐Alford, Javed Fowdar, Glenda M. Halliday, Anjali K. Henders, Ian B. Hickie, Irfahan Kassam, Martin A. Kennedy, John B. Kwok, Simon J.G. Lewis, George D. Mellick, Grant W. Montgomery, John F. Pearson, Toni L. Pitcher, Julia Sidorenko, Peter A. Silburn, Leanne Wallace, Naomi R. Wray, Futao Zhang

Bibliographic record

VenueThe Lancet Neurology · 2019
Typereview
Languageen
FieldMedicine
TopicParkinson's Disease Mechanisms and Treatments
Canadian institutionsMcGill UniversityMontreal Neurological Institute and Hospital
FundersDivision of Human Resource ManagementNational Institute on AgingMedical Research CouncilSchool of Public Health, University of California BerkeleyFédération pour la Recherche sur le CerveauNorges ForskningsrådAgence Nationale de la RechercheChung Hua UniversityObstetric Anaesthetists' AssociationBiogenLondon Mathematical SocietyParkinson's UKNovartisPSP AssociationAdrienne Helis Malvin Medical Research FoundationGE HealthcareNorth Carolina GlaxoSmithKline FoundationNational Institutes of HealthRosetrees TrustAssociation France ParkinsonEuropean CommissionSanofiBarts CharityBoehringer IngelheimMichael J. Fox Foundation for Parkinson's ResearchRocheInstitut de FranceFondation Roger de SpoelberchH. Lundbeck A/SBurroughs Wellcome Fund
KeywordsGenome-wide association studyDiseaseLRRK2Genetic associationSingle-nucleotide polymorphismMendelian randomizationGeneticsBiologyMeta-analysisMendelian inheritanceHeritabilityMissing heritability problemParkinson's diseaseBioinformaticsMedicineGenotypeGeneGenetic variantsInternal medicine

Abstract

fetched live from OpenAlex

Background Genome-wide association studies (GWAS) in Parkinson's disease have increased the scope of biological knowledge about the disease over the past decade. We aimed to use the largest aggregate of GWAS data to identify novel risk loci and gain further insight into the causes of Parkinson's disease. Methods We did a meta-analysis of 17 datasets from Parkinson's disease GWAS available from European ancestry samples to nominate novel loci for disease risk. These datasets incorporated all available data. We then used these data to estimate heritable risk and develop predictive models of this heritability. We also used large gene expression and methylation resources to examine possible functional consequences as well as tissue, cell type, and biological pathway enrichments for the identified risk factors. Additionally, we examined shared genetic risk between Parkinson's disease and other phenotypes of interest via genetic correlations followed by Mendelian randomisation. Findings Between Oct 1, 2017, and Aug 9, 2018, we analysed 7·8 million single nucleotide polymorphisms in 37 688 cases, 18 618 UK Biobank proxy-cases (ie, individuals who do not have Parkinson's disease but have a first degree relative that does), and 1·4 million controls. We identified 90 independent genome-wide significant risk signals across 78 genomic regions, including 38 novel independent risk signals in 37 loci. These 90 variants explained 16–36% of the heritable risk of Parkinson's disease depending on prevalence. Integrating methylation and expression data within a Mendelian randomisation framework identified putatively associated genes at 70 risk signals underlying GWAS loci for follow-up functional studies. Tissue-specific expression enrichment analyses suggested Parkinson's disease loci were heavily brain-enriched, with specific neuronal cell types being implicated from single cell data. We found significant genetic correlations with brain volumes (false discovery rate-adjusted p=0·0035 for intracranial volume, p=0·024 for putamen volume), smoking status (p=0·024), and educational attainment (p=0·038). Mendelian randomisation between cognitive performance and Parkinson's disease risk showed a robust association (p=8·00 × 10 −7 ). Interpretation These data provide the most comprehensive survey of genetic risk within Parkinson's disease to date, to the best of our knowledge, by revealing many additional Parkinson's disease risk loci, providing a biological context for these risk factors, and showing that a considerable genetic component of this disease remains unidentified. These associations derived from European ancestry datasets will need to be followed-up with more diverse data. Funding The National Institute on Aging at the National Institutes of Health (USA), The Michael J Fox Foundation, and The Parkinson's Foundation (see appendix for full list of funding sources).

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.010
metaresearch head score (Gemma)0.014
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Meta-analysis · Consensus signal: Meta-analysis
GenreCandidate signal: Review · Consensus signal: Review
Teacher disagreement score0.010
Threshold uncertainty score0.051

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0100.014
Meta-epidemiology (narrow)0.0020.001
Meta-epidemiology (broad)0.0090.014
Bibliometrics0.0030.005
Science and technology studies0.0000.000
Scholarly communication0.0020.001
Open science0.0020.001
Research integrity0.0020.002
Insufficient payload (model declined to judge)0.0020.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.132
GPT teacher head0.362
Teacher spread0.229 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designMeta-analysis
Domainnot available
GenreReview

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

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Citations2,541
Published2019
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