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Record W3186957969 · doi:10.20381/ruor-22149

A Study of the Role of the Six Family of Transcription Factors in Adult Skeletal Muscle Homeostasis

2018· dissertation· en· W3186957969 on OpenAlex
John Girgis

Why this work is in the frame

A frame that forgets how it found something cannot be audited. These are the routes that admitted this work.

fundA Canadian funder is recorded on the work.
no affNo Canadian affiliation: this work is invisible to an affiliation-only frame.
No Canadian affiliation. An affiliation-only frame, the usual design, would never have seen this work. It is one of the works that make the case for inverting the frame.

Bibliographic record

VenueuO Research (University of Ottawa) · 2018
Typedissertation
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicGenetics and Physical Performance
Canadian institutionsnot available
FundersCanadian Institutes of Health Research
KeywordsSkeletal muscleHomeostasisTranscription factorBiologyBioinformaticsMedicineGeneticsCell biologyEndocrinologyGene

Abstract

fetched live from OpenAlex

Duchenne Muscular Dystrophy (DMD) is characterized by persistent deterioration and regeneration of skeletal muscles. This occurs when ablation of the Dystrophin protein – through deleterious, nonsense, or frameshift mutations in the coding gene – destabilizes the Dystrophin-Associated Glycoprotein Complex (DAPC), resulting in a multitude of signaling defects. Upregulation of a closely related protein, Utrophin A, has been shown to alleviate the DMD phenotype, and slow-twitch oxidative muscle fibers express innately increased sarcolemmal Utrophin levels conferring resistance to the disease. Studies have shown that the Six family of Transcription Factors (TFs) promote the formation and maintenance of fast-twitch muscle, suggesting that antagonizing the Six TFs and causing a fiber type switch may be a therapeutic approach to treating DMD. In this study, partial loss-of function through RNA interference methodologies in adult skeletal muscles were combined with bioinformatic analyses, to elucidate the therapeutic potential of the antagonism of the Six TFs. Knockdown of Six1 is shown to increase Utrophin levels, with a suggested increase in Nuclear factor of activated T-cells (NFAT) activity. This may be partially mediated by Six1 regulation of a known inhibitor of the NFAT pathway, Myoz1, described herein. Six1 knockdown is also shown to modulate thyroid hormone regulated gene expression, mediated through a novel target, MCT10. This thesis elucidates putative mechanisms by which Six TFs may regulate pro-fast-twitch skeletal muscle fiber type by both antagonizing NFAT activity and promoting thyroid hormone signaling.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Bench or experimental · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.724
Threshold uncertainty score0.483

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0010.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.020
GPT teacher head0.271
Teacher spread0.251 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it