MétaCan
Menu
Back to cohort
Record W4213350342 · doi:10.1038/s41380-022-01437-6

Rare variants in IFFO1, DTNB, NLRC3 and SLC22A10 associate with Alzheimer’s disease CSF profile of neuronal injury and inflammation

2022· article· en· W4213350342 on OpenAlexfundno aff
Alexander Neumann, Fahri Küçükali, Isabelle Bos, Stephanie J. B. Vos, Sebastiaan Engelborghs, Tim De Pooter, Geert Joris, Peter De Rijk, Ellen De Roeck, Magda Tsolaki, Frans R.J. Verhey, Pablo Martínez‐Lage, Giovanni B. Frisoni, Oliver Blin, Jill Richardson, Régis Bordet, Philip Scheltens, Julius Popp, Gwendoline Peyratout, Peter Johannsen, Rik Vandenberghe, Yvonne Freund‐Levi, Johannes Streffer, Simon Lovestone, Cristina Legido‐Quigley, Frederik Barkhof, Mojca Stražišar, Henrik Zetterberg, Lars Bertram, Pieter Jelle Visser, Christine Van Broeckhoven, Kristel Sleegers

Bibliographic record

VenueMolecular Psychiatry · 2022
Typearticle
Languageen
FieldMedicine
TopicAlzheimer's disease research and treatments
Canadian institutionsnot available
FundersNational Institutes of HealthOlav Thon StiftelsenIXICOH. Lundbeck A/SGenentechVlaamse regeringServierInnovative Medicines InitiativeUniversity College London Hospitals NHS Foundation TrustVetenskapsrådetEisaiNational Institute of Biomedical Imaging and BioengineeringCanadian Institutes of Health ResearchFonds Wetenschappelijk OnderzoekSchweizerischer Nationalfonds zur Förderung der Wissenschaftlichen ForschungNational Research FoundationUK Dementia Research InstituteEuropean Federation of Pharmaceutical Industries and AssociationsNational Institute on AgingNational Institute for Health and Care ResearchNorthern California Institute for Research and EducationPfizerBiogenBioClinicaUniversiteit AntwerpenAlzheimer's AssociationStiftelsen för Gamla TjänarinnorHjärnfondenEuropean CommissionFamiljen Erling-Perssons StiftelseSteno Diabetes Center CopenhagenUniversity of Southern CaliforniaNovartis Pharmaceuticals CorporationEusko JaurlaritzaU.S. Department of DefenseEli Lilly and CompanyBristol-Myers SquibbF. Hoffmann-La RocheAlzheimer's Drug Discovery FoundationAlzheimer's Disease Neuroimaging InitiativeMeso Scale DiagnosticsFoundation for the National Institutes of Health
KeywordsNeurograninInflammationDementiaBiomarkerNeuroscienceFrontotemporal dementiaAlzheimer's diseaseMedicineBiologyDiseaseGeneticsInternal medicineSignal transduction

Abstract

fetched live from OpenAlex

Alzheimer's disease (AD) biomarkers represent several neurodegenerative processes, such as synaptic dysfunction, neuronal inflammation and injury, as well as amyloid pathology. We performed an exome-wide rare variant analysis of six AD biomarkers (β-amyloid, total/phosphorylated tau, NfL, YKL-40, and Neurogranin) to discover genes associated with these markers. Genetic and biomarker information was available for 480 participants from two studies: EMIF-AD and ADNI. We applied a principal component (PC) analysis to derive biomarkers combinations, which represent statistically independent biological processes. We then tested whether rare variants in 9576 protein-coding genes associate with these PCs using a Meta-SKAT test. We also tested whether the PCs are intermediary to gene effects on AD symptoms with a SMUT test. One PC loaded on NfL and YKL-40, indicators of neuronal injury and inflammation. Four genes were associated with this PC: IFFO1, DTNB, NLRC3, and SLC22A10. Mediation tests suggest, that these genes also affect dementia symptoms via inflammation/injury. We also observed an association between a PC loading on Neurogranin, a marker for synaptic functioning, with GABBR2 and CASZ1, but no mediation effects. The results suggest that rare variants in IFFO1, DTNB, NLRC3, and SLC22A10 heighten susceptibility to neuronal injury and inflammation, potentially by altering cytoskeleton structure and immune activity disinhibition, resulting in an elevated dementia risk. GABBR2 and CASZ1 were associated with synaptic functioning, but mediation analyses suggest that the effect of these two genes on synaptic functioning is not consequential for AD development.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.010
Threshold uncertainty score0.608

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.010
GPT teacher head0.269
Teacher spread0.259 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations25
Published2022
Admission routes1
Has abstractyes

Explore more

Same venueMolecular PsychiatrySame topicAlzheimer's disease research and treatmentsFrench-language works237,207