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Record W4235812272 · doi:10.5334/tohm.490

Generalized Dystonia and Paroxysmal Dystonic Attacks due to a Novel <i>ATP1A3</i> Variant

2019· article· en· W4235812272 on OpenAlexaff
Carlos Zúñiga‐Ramírez, Mirelle Kramis-Hollands, Rodrigo Mercado-Pimentel, Héctor González-Usigli, Michel Sáenz‐Farret, Alberto Soto-Escageda, Alfonso Fasano

Bibliographic record

VenueTremor and Other Hyperkinetic Movements · 2019
Typearticle
Languageen
FieldMedicine
TopicNeurological disorders and treatments
Canadian institutionsOntario Brain InstituteToronto Western HospitalUniversity of Toronto
Fundersnot available
KeywordsParoxysmal dyskinesiaDystoniaDeep brain stimulationMedicineMovement disordersIctalNeurosciencePediatricsEpilepsyPsychologyInternal medicineDyskinesiaParkinson's diseaseDisease

Abstract

fetched live from OpenAlex

<strong>Background:</strong> Paroxysmal movement disorders are a heterogeneous group of neurological diseases, better understood in recent years thanks to widely available genetic testing. <strong>Case report:</strong> A pair of monozygotic twins with dystonia and paroxysmal attacks, resembling paroxysmal non-kinesigenic dyskinesias, due to a novel <em>ATP1A3</em> variant are reported. The complete resolution of their paroxysms was achieved using levodopa and deep brain stimulation of the internal globus pallidus. Improvement of interictal dystonia was also achieved with this therapy. <strong>Discussion:</strong> Paroxysmal worsening of movement disorders should be suspected as part of the <em>ATP1A3</em> spectrum. Treatment outcome might be predicted based on the phenotype.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMeta-epidemiology (narrow), Insufficient payload (model declined to judge)
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.749
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0010.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0010.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.019
GPT teacher head0.253
Teacher spread0.234 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations4
Published2019
Admission routes1
Has abstractyes

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