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Record W4285799266 · doi:10.1186/s12969-022-00709-3

Baseline characteristics of children with juvenile dermatomyositis enrolled in the first year of the new Childhood Arthritis and Rheumatology Research Alliance registry

2022· article· en· W4285799266 on OpenAlexaff
Jessica Neely, Kaveh Ardalan, Adam M. Huber, Susan Kim, Novillo Abel, K. Abulaban, Alyce S. Adams, Matthew Adams, R. Agbayani, J. Aiello, S. Akoghlanian, C. Alejandro, E. Allenspach, Risa Alperin, M. Alpizar, G. Amarilyo, W. Ambler, E. Anderson, S. Ardoin, S. Armendariz, Emma H. Baker, I. Balboni, S. Balevic, L. Ballenger, S. Ballinger, N. Balmuri, Fatima Barbar‐Smiley, L. Barillas-Arias, M. Basiaga, K. Baszis, M. Becker, H. Bell-Brunson, E. Beltz, H. Benham, Susanne M. Benseler, W. Bernal, Timothy Beukelman, T. Bigley, B. Binstadt, C. Black, M. Blakley, J. Bohnsack, J. Boland, Alexis Boneparth, S. Bowman, Claudia Bracaglia, E. Brooks, M. Brothers, A. G. P. Brown, H. Brunner, Michael Buckley, Hülya Bükülmez, D. Bullock, B. Cameron, Scott Canna, L. Cannon, P. Carper, V. Cartwright, E. Cassidy, L. Cerracchio, E. Chalom, J. Chang, A. Chang-Hoftman, V. Chauhan, Peter Chira, T. Chinn, K. Chundru, H. Clairman, D. Co, A. Confair, H. Conlon, R. Connor, A. Cooper, Jennifer C. Cooper, S. Cooper, C. Correll, R. Corvalan, D. Costanzo, Randall Cron, L. Curiel-Duran, T. Curington, M. Curry, Annette Dalrymple, Alaina M. Davis, C. Davis, T. Davis, Fabrizio De Benedetti, Deirdre De Ranieri, Jay B. Dean, F. Dedeoglu, M. DeGuzman, Nancy Delnay, V. Dempsey, E. DeSantis, T. Dickson, J. Dingle, Brittany Donaldson, E. Dorsey, Saunya Dover, James J. Dowling, J. Drew, K. Driest, Qing Du, K. Duarte, D. Durkee, Eric Duverger, J. Dvergsten, A. Eberhard, M. Eckert, K. Ede, B. Edelheit, C. Edens, Y. Edgerly, M. Elder, B. Ervin, S. Fadrhonc, C. Failing, D. Fair, M. Falcon, Leslie Favier, S. Federici, B. Feldman, J. Fennell, I. Ferguson, Polly J. Ferguson, B. Ferreira, R. Ferrucho, K. Fields, Terri H. Finkel, M. Fitzgerald, C. Fleming, Orla Flynn, L. Fogel, Emily M. Fox, M. Fox, L. Franco, Michele Freeman, K. Fritz, D. Sean Froese, R. Fuhlbrigge, J. Fuller, N. George, K. Gerhold, Dana Gerstbacher, M. Gilbert, Miriah Gillispie‐Taylor, E. Giverc, C. Godiwala, Y. Ingrid Goh, H. Goheer, Donald P. Goldsmith, E C Gotschlich, Alisa Gotte, Beth S. Gottlieb, C. Gracia, T. Brent Graham, S. Grevich, T. Griffin, John Griswold, Alexei A. Grom, Myriam Guevara, P. Guittar, Marietta De Guzman, Marlene Hager, Taeho Hahn, O. Halyabar, E. Hammelev, M. Hance, A. Hanson, Liora Harel, S. Haro, J. Harris, Onengiya Harry, E. Hartigan, Jonathan S. Hausmann, Arielle Hay, K. Hayward, J. Heiart, K. Hekl, L Henderson, Michael Henrickson, A. Hersh, K. Hickey, P. Hill, S. Hillyer, L. Hiraki, M. Hiskey, Patricia M. Hobday, C. Hoffart, Michael J. Holland, M. Hollander, Seokchan Hong, Mitchell E. Horwitz, Joyce Hsu, John T. Huggins, Joyce Hui‐Yuen, Chien‐Hui Hung, J. Huntington, Anna Huttenlocher, M. Ibarra, L. Imundo, C. Inman, Antonella Insalaco, A. Jackson, S. Jackson, K. James, Ginger Janow, J. Jaquith, S. Jared, Nicole Johnson, J. Jones, Karla Jones, Suzi Jones, S. Joshi, L. Jung, C. Justice, A. Justiniano, N. Karan, K. Kaufman, Andrew H. Kemp, E. Kessler, U. Khalsa, Bernadette Kienzle, S. Kim, Y. Kimura, D. Kingsbury, Maleewan Kitcharoensakkul, T. Klausmeier, K. E. Klein, Marisa Klein‐Gitelman, B. Kompelien, A. Kosikowski, L. Kovalick, J. Kracker, S. Kramer, C. Kremer, J. Lai, J. Lam, Bianca Lang, Sivia Lapidus, B. Lapin, A. Lasky, D. Latham, E. Lawson, Ronald M. Laxer, P. Lee, T. Lee, L. Lentini, Melissa A. Lerman, D. Levy, S. Li, Scott M. Lieberman, L. Lim, C. Lin, N. Ling, M. Lingis, M. Lo, D. Lovell, D. Lowman, Nadia Luca, S. Lvovich, Cindee Madison, J. Madison, B. Malla, J. Maller, Moira Malloy, M.C. Mannion, C. Manos, L. Marques, A. Martyniuk, Thomas G. Mason, S. Mathus, Lindy McAllister, K. McCarthy, K. McConnell, E. McCormick, D. McCurdy, P. McCurdy Stokes, S. McGuire, I. McHale, A. McMonagle, C. McMullen-Jackson, Esra Meidan, E. Mellins, E. Mendoza, R. Mercado, A. Merritt, L. Michalowski, P. Miettunen, Miss Caroline Miller, Diana Milojevic, Emily Mirizio, E. Misajon, Melissa Mitchell, R. Modica, S. Mohan, K. Moore, L. Moorthy, S. Morgan, Esi Morgan DeWitt, C. Moss, T. Moussa, V. Mruk, A. Murphy, E. Muscal, R. Nadler, B. Nahal, K. Nanda, N. Nasah, L. Nassi, Simona Nativ, Marc D. Natter, B. Nelson, L. Newhall, L. Ng, Joseph A. Nicholas, Rebecca Nicolai, P. Nigrovic, J. Nocton, Beatrice Nolan, Edward J. Oberle, B. Obispo, B. O’Brien, T. O’Brien, O. Okeke, M. Oliver, J. Olson, Kathleen M. O’Neil, K. Onel, A. Orandi, M. Orlando, Shirley‐Ann Osei‐Onomah, R. Oz, E. Pagano, A. Paller, NY Pan, S. Panupattanapong, M. Pardeo, J. Paredes, A. Parsons, Jayesh Patel, K. Pentakota, Peri H. Pepmueller, T. Pfeiffer, K. Phillippi, Denise Pires Marafon, L. Ponder, R. Pooni, S. Prahalad, S. Pratt, S. Protopapas, B. Puplava, J. Quach, M. Quinlan-Waters, C. Egla Rabinovich, S. Radhakrishna, J. Rafko, J. Raisian, A. Rakestraw, C. Ramirez, Ey Ramsay, S. Ramsey, R. Randell, A. Reed, H. Reid, K. Remmel, A. Repp, A. Reyes, Ann Richmond, Meredith Riebschleger, S. Ringold, M. Riordan, Mona Riskalla, M. Ritter, R. Rivas-Chacon, Angela Byun Robinson, E. Rodela, M. Rodriquez, K Rojas, Tova Ronis, Margalit Rosenkranz, B. Rosolowski, H. Rothermel, D. Rothman, E. Roth-Wojcicki, Kelly Rouster‐Stevens, Tamar B. Rubinstein, N. Ruth, Nadine Saad, S. Sabbagh, Emanuela Sacco, R. Sadun, C. Sandborg, A. Sanni, L. Santiago, Aliese Sarkissian, S. Savani, Lisabeth V. Scalzi, Laura E. Schanberg, S. Scharnhorst, K. Schikler, A. Schlefman, Heinrike Schmeling, K. Schmidt, E. Schmitt, Raphaël Schneider, K. Schollaert-Fitch, G. Schulert, T. Seay, C. Seper, J. Shalen, R. Sheets, A. Shelly, S. Shenoi, K. Shergill, J. Shirley, M. Shishov, C. Shivers, E. Silverman, N. Singer, Vidya Sivaraman, J. Sletten, A. Smith, Chelsey Smith, Jonathan P. Smith, Emily A. Smitherman, Jennifer B. Soep, Mandy Wat- son, S. Spence, L. Spiegel, J. Spitznagle, R. Sran, Hemalatha Srinivasalu, H. Stapp, K. Steigerwald, Y. Sterba Rakovchik, Sara Stern, A. Stevens, B. Stevens, R. Stevenson, K. Stewart, C. Stingl, J. Stokes, M. Stoll, Elizabeth Stringer, Sangeeta Sule, J. Sumner, R. Sundel, M. Sutter, Roshni Shanavas Syed, G. Syverson, Ann Marie Szymanski, Stephen Taber, R. Tal, Ajay Tambralli, A. Taneja, T. Tanner, S. Tapani, G. Tarshish, S. Tarvin, L. Tate, A. Taxter, J. Taylor, M. Terry, M. Tesher, Akaluck Thatayatikom, B. Thomas, K. Tiffany, Tracy V. Ting, A. Tipp, D. Toib, Kathryn S. Torok, C. Toruner, H. Tory, M. Toth, S. Tse, V. Tubwell, M. Twilt, S. Uriguen, T. Valcarcel, Heather Van Mater, L. Vannoy, C. Varghese, N. Vasquez, K. Vazzana, R. Vehe, Keila Veiga, J. Velez, J. Verbsky, G. Vilar, N. Volpe, Emily von Scheven, S. Vora, Joël Wagner, Linda Wagner‐Weiner, D. Wahezi, H. Waite, J. Walker, Heather M. Walters, Theresa Wampler Muskardin, L. Waqar, Michael Waterfield, M. Watson, A. Watts, P. Weiser, J. Weiss, P. Weiss, E. Wershba, Andrew J. White, Christine L. Williams, A. Wise, Jennifer M. P. Woo, Leandra Woolnough, T. Wright, E. Wu, Ali Yalçindağ, Mandy Yap Yee Yee, E. Yen, R. Yeung, K. Yomogida, Qinze Yu, R. Zapata, A. Zartoshti

Bibliographic record

VenuePediatric Rheumatology · 2022
Typearticle
Languageen
FieldMedicine
TopicInflammatory Myopathies and Dermatomyositis
Canadian institutionsIzaak Walton Killam Health CentreDalhousie University
FundersEunice Kennedy Shriver National Institute of Child Health and Human DevelopmentNational Institute of Arthritis and Musculoskeletal and Skin DiseasesNational Institutes of HealthArthritis Foundation
KeywordsMedicineJuvenile dermatomyositisRheumatologyInternal medicineInterstitial lung diseasePhysical therapyPatient-reported outcomeArthritisPediatricsQuality of life (healthcare)DermatomyositisLung

Abstract

fetched live from OpenAlex

BACKGROUND: To report baseline characteristics, patient reported outcomes and treatment of children with Juvenile Dermatomyositis (JDM) in the Childhood Arthritis and Rheumatology Research Alliance (CARRA) Registry. METHODS: Children newly diagnosed with JDM were enrolled in the CARRA Registry from 41 pediatric rheumatology centers. Baseline patient demographics, disease characteristics, assessments, patient reported outcome and treatments were recorded. RESULTS: In the first year, 119 JDM participants were enrolled. Most were female (63.4%), and white (72.3%) with a median diagnosis age 8.0 years (IQR 4.0-11.5), and median age of disease onset 7.0 years (IQR 3.5-7.5). They had characteristic rashes (92.4%), elevated muscle enzymes (83.2%), physician global score 4.0 (IQR 2.5-5.0) and manual muscle testing score 63.5 (IQR 51.0-75.0). Calcinosis (3.4%) and interstitial lung disease (< 1%) were uncommon. Myositis specific antibodies were measured and reported in nearly half of participants enrolled where anti-MJ followed by Anti-p155/140 were most common (11/49 and 7/53 respectively). Childhood Health Assessment Questionnaire (CHAQ) results showed mild-moderate disability (median 0.750, IQR 0.030-1.875), as did patient/parent global assessments of disease activity (median 3, patient IQR: 1.75-5.25; parent IQR: 1-7). Patient Reported Outcomes Measurement Information System (PROMIS®) Pediatric Global Health 7 scores, Pain Interference, Physical Function scores for Mobility, and Upper Extremity Function were commonly worse than 95% of the general pediatric population. CONCLUSIONS: In its inaugural year, 119 JDM patients were successfully enrolled in participapte in the New CARRA Registy. This registry will provide the necessary foundation to advance clinical research to improve outcomes using traditional measures and patient reported outcomes. With the CARRA biorepository, this infrastructure will enable future translational research. Together, these efforts may aid in future clinical trials, including comparative effectiveness trials.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.001
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.016
Threshold uncertainty score0.588

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0010.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0010.000
Bibliometrics0.0000.001
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.001
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.008
GPT teacher head0.236
Teacher spread0.229 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations14
Published2022
Admission routes1
Has abstractyes

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