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Record W4308957545 · doi:10.1001/jamaneurol.2022.4178

Association of Physical Activity With Neurofilament Light Chain Trajectories in Autosomal Dominant Frontotemporal Lobar Degeneration Variant Carriers

2022· letter· en· W4308957545 on OpenAlexaboutno aff
Kaitlin B. Casaletto, John Kornack, Emily W. Paolillo, Julio C. Rojas, Anna M. VandeBunte, Adam S. Staffaroni, Shannon Lee, Hilary W. Heuer, Leah K. Forsberg, Eliana Marisa Ramos, Bruce L. Miller, Joel H. Kramer, Kristine Yaffe, Leonard Petrucelli, Adam L. Boxer, Bradley F. Boeve, Tania F. Gendron, Howard J. Rosen, Liana G. Apostolova, Brian S. Appleby, Sami J. Barmada, Yvette Bordelon, Hugo Botha, Andrea Bozoki, Danielle Brushaber, David Clark, Ryan Darby, Bradford C. Dickerson, Dennis W. Dickson, Kimiko Domoto-Reilly, Kelley Faber, Anne M. Fagan, Julie A. Fields, Tatiana Foroud, Daniel H. Geschwind, Nupur Ghoshal, Jill Goldman, Douglas Galasko, Ralitza Gavrilova, Jonathon Graff-Radford, Neill R. Graff‐Radford, Ian Grant, Murray Grossman, Matthew Hall, Eric J. Huang, Ging‐Yuek Robin Hsiung, Edward D. Huey, David J. Irwin, Kejal Kantarci, Daniel Kauer, Diana Kerwin, David S. Knopman, John Kornak, Walter K. Kremers, Maria I. Lapid, Argentina Lario Lago, Suzee Lee, Gabriel C. Léger, Peter A. Ljubenkov, Irene Litvan, Diana E. Lucente, Ian R. Mackenzie, Joseph C. Masdeux, Scott McGinnis, Mario F. Mendez, Carly Mester, Chiadi U. Onyike, María Belén Pascual, Peter Pressman, Rosa Rademakers, Vijay K. Ramanan, Meghana Rao, Katya Rascovsky, Katherine P. Rankin, Aaron Ritter, Rodolfo Savica, William W. Seeley, Jeremy A. Syrjanen, Adam M. Staffaroni, Maria Carmela Tartaglia, Jack C. Taylor, Lawren VandeVrede, Sandra Weıntraub, Bonnie Wong

Bibliographic record

VenueJAMA Neurology · 2022
Typeletter
Languageen
FieldMedicine
TopicAmyotrophic Lateral Sclerosis Research
Canadian institutionsnot available
FundersNational Institute of Neurological Disorders and StrokeNational Institute of Mental HealthNational Institute on Aging
KeywordsFrontotemporal lobar degenerationC9orf72Frontotemporal dementiaDementiaCohortAsymptomaticMedicinePsychologyLongitudinal studyInternal medicineGerontologyPathologyDisease

Abstract

fetched live from OpenAlex

Importance: Physical activity is associated with cognitive health, even in autosomal dominant forms of dementia. Higher physical activity is associated with slowed cognitive and functional declines over time in adults carrying autosomal dominant variants for frontotemporal lobar degeneration (FTLD), but whether axonal degeneration is a potential neuroprotective target of physical activity in individuals with FTLD is unknown. Objective: To examine the association between physical activity and longitudinal neurofilament light chain (NfL) trajectories in individuals with autosomal dominant forms of FTLD. Design, Setting, and Participants: This cohort study included individuals from the ALLFTD Consortium, which recruited patients from sites in the US and Canada. Symptomatic and asymptomatic adults with pathogenic variants in one of 3 common genes associated with FTLD (GRN, C9orf72, or MAPT) who reported baseline physical activity levels and completed annual blood draws were assessed annually for up to 4 years. Genotype, clinical measures, and blood draws were collected between December 2014 and June 2019; data were analyzed from August 2021 to January 2022. Associations between reported baseline physical activity and longitudinal plasma NfL changes were assessed using generalized linear mixed-effects models adjusting for baseline age, sex, education, functional severity, and motor symptoms. Exposures: Baseline physical activity levels reported via the Physical Activity Scale for the Elderly. To estimate effect sizes, marginal means were calculated at 3 levels of physical activity: 1 SD above the mean represented high physical activity, 0 SD represented average physical activity, and 1 SD below the mean represented low physical activity. Main Outcomes and Measures: Annual plasma NfL concentrations were measured with single-molecule array technology. Results: Of 160 included FTLD variant carriers, 84 (52.5%) were female, and the mean (SD) age was 50.7 (14.7) years. A total of 51 (31.8%) were symptomatic, and 77 carried the C9orf72 variant; 39, GRN variant; and 44, MAPT variant. Higher baseline physical activity was associated with slower NfL trajectories over time. On average, NfL increased 45.8% (95% CI, 22.5 to 73.7) over 4 years in variant carriers. Variant carriers with high physical activity demonstrated 14.0% (95% CI, -22.7 to -4.3) slower NfL increases compared with those with average physical activity and 30% (95% CI, -52.2 to -8.8) slower NfL increases compared with those with low physical activity. Within genotype, C9orf72 and MAPT carriers with high physical activity evidenced 18% to 21% (95% CI, -43.4 to -7.2) attenuation in NfL, while the association between physical activity and NfL trajectory was not statistically significant in GRN carriers. Activities associated with higher cardiorespiratory and cognitive demands (sports, housework, and yardwork) were most strongly correlated with slower NfL trajectories (vs walking and strength training). Conclusions and Relevance: In this study, higher reported physical activity was associated with slower progression of an axonal degeneration marker in individuals with autosomal dominant FTLD. Physical activity may serve as a primary prevention target in FTLD.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMeta-epidemiology (narrow), Research integrity
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.573
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0010.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0010.004
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.014
GPT teacher head0.252
Teacher spread0.239 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations22
Published2022
Admission routes1
Has abstractyes

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