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Record W4311279646 · doi:10.1111/joim.13593

Global guidance for the recognition, diagnosis, and management of tumor‐induced osteomalacia

2022· review· en· W4311279646 on OpenAlexaff
Suzanne M. Jan de Beur, Salvatore Minisola, Weibo Xia, Bo Abrahamsen, Jean‐Jacques Body, Maria Luisa Brandi, Roderick Clifton‐Bligh, Michael T. Collins, Pablo Florenzano, Pascal Houillier, Yasuo Imanishi, Erik A. Imel, Aliya Khan, M. Carola Zillikens, Seiji Fukumoto

Bibliographic record

VenueJournal of Internal Medicine · 2022
Typereview
Languageen
FieldMedicine
TopicParathyroid Disorders and Treatments
Canadian institutionsMcMaster UniversityMcMaster University Medical Centre
FundersNHLBI Division of Intramural ResearchNational Institutes of HealthAustralian and New Zealand Bone and Mineral SocietyInternational Osteoporosis FoundationAboca S.p.A. Società AgricolaEuropean Calcified Tissue SocietyUltragenyx PharmaceuticalAmerican Society for Bone and Mineral ResearchAlexion PharmaceuticalsEli Lilly and CompanyChugai PharmaceuticalAmgen
KeywordsMedicineOsteomalaciaIntensive care medicinePathologyOsteoporosis

Abstract

fetched live from OpenAlex

Abstract Tumor‐induced osteomalacia (TIO) is a rare paraneoplastic syndrome caused by mesenchymal tumors that secrete fibroblast growth factor 23 (FGF23). Patients present with progressive bone pain, muscle weakness, and fragility fractures. TIO is characterized by hypophosphatemia, excess renal phosphate excretion, and low/inappropriately normal 1,25‐dihydroxyvitamin D (1,25(OH) 2 D) levels. Rarity and enigmatic clinical presentation of TIO contribute to limited awareness among the medical community. Accordingly, appropriate diagnostic tests may not be requested, leading to delayed diagnosis and poorer patient outcomes. We have developed a global guidance document to improve the knowledge of TIO in the medical community, enabling the recognition of patients with TIO and appropriate referral. We provide recommendations aiding diagnosis, referral, and treatment, helping promote a global standard of patient management. We reviewed the literature and conducted a three‐round Delphi survey of TIO experts. Statements were drafted based on published evidence and expert opinions (≥70% consensus required for final recommendations). Serum phosphate should be measured in patients presenting with chronic muscle pain or weakness, fragility fractures, or bone pain. Physical examination should establish features of myopathy and identify masses that could be causative tumors. Priority laboratory evaluations should include urine/serum phosphate and creatinine to assess renal tubular reabsorption of phosphate and TmP/GFR, alkaline phosphatase, parathyroid hormone, 25‐hydroxyvitamin D, 1,25(OH) 2 D, and FGF23. Patients with the clinical/biochemical suspicion of TIO should be referred to a specialist for diagnosis confirmation, and functional imaging should be used to localize causative tumor(s). Recommended treatment is tumor resection or, with unresectable/unidentifiable tumors, phosphate salts plus active vitamin D, or burosumab.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.065
metaresearch head score (Gemma)0.132
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Not applicable · Consensus signal: Not applicable
GenreCandidate signal: Review · Consensus signal: none
Teacher disagreement score0.065
Threshold uncertainty score0.346

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0650.132
Meta-epidemiology (narrow)0.0010.001
Meta-epidemiology (broad)0.0010.003
Bibliometrics0.0050.002
Science and technology studies0.0030.003
Scholarly communication0.0040.005
Open science0.0030.008
Research integrity0.0110.007
Insufficient payload (model declined to judge)0.0080.004

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.097
GPT teacher head0.397
Teacher spread0.301 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designNot applicable
Domainnot available
GenreReview

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations88
Published2022
Admission routes1
Has abstractyes

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