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Record W4367303637 · doi:10.1212/wnl.0000000000201791

Chronic Herpes Simplex Virus Encephalitis: Two Surgical Cases with Novel Neuropathologic Findings (P12-10.001)

2023· article· en· W4367303637 on OpenAlexaffabout
Kirsten Sjonnesen, JP Appendino, Walter Hader, Qi Xu, Julia Jacobs-Levan, Paolo Federico, Kristopher D. Langdon

Bibliographic record

VenueNeurology · 2023
Typearticle
Languageen
FieldMedicine
TopicHerpesvirus Infections and Treatments
Canadian institutionsUniversity of CalgaryUniversity of Manitoba
Fundersnot available
KeywordsSubacute sclerosing panencephalitisEncephalitisHerpes simplex virusMedicinePathologyImmunologyVirologyMeasles virusAlphaherpesvirinaeVirusHerpesviridaeMeaslesViral diseaseVaccination

Abstract

fetched live from OpenAlex

Objective: N/A Background: Chronic granulomatous herpes simplex encephalitis (CGHSE) is a rare complication following infantile and pediatric herpes simplex virus encephalitis (HSVE). Clinically, it follows a biphasic course, with acute HSVE later followed by drug-resistant seizures and progressive neurologic deterioration. Convincing evidence is lacking for whether CGHSE occurs due to virus reactivation versus post-infectious inflammatory sequelae. Design/Methods: The neuropathologic findings of two patients who underwent epilepsy surgery following remote infectious encephalitis are herein discussed. The first case is previously unreported and confirmed to be associated with HSV-I, and the second case, newly re-examined, is previously reported and of presumed HSV-I encephalitis. Results: The histological findings in the current cases were consistent with chronic, ongoing inflammation, both of which harboured parenchymal HSV-I DNA by PCR. There were no HSV antigens detected via immunohistochemistry nor viral inclusions seen on the H&E sections. A novel finding, shared by both cases, is the identification of cytoplasmic phosphorylated tau-immunopositive components: neurofibrillary tangles, pretangles and neuropil threads. These were demonstrated within regions of inflammation as well as seemingly uninvolved areas. Conclusions: Tau hyperphosphorylation has been reported following other infections, such as post-measles subacute sclerosing panencephalitis and HIV-associated neurocognitive disorders. HSV-I infection has been postulated to promote tau protein hyperphosphorylation. HSV-I primary infection and reactivation have been associated with phosphorylated tau accumulation in murine models. HSV-I in vitro infection models exposed to acyclovir treatment demonstrate dose-dependent reductions in phosphorylated tau accumulation. While in vitro murine, monkey and human experimental data have demonstrated hyperphosphorylated tau accumulates following HSV-I infection, to our knowledge, this may represent the first patient report of abnormal phosphorylated tau accumulation associated with neuropathologic chronic granulomatous HSVE. Further investigation into the possibility that tau accumulation contributes to long-term neurologic sequelae among HSVE survivors may be warranted. Disclosure: Dr. Sjonnesen has nothing to disclose. Dr. Appendino has nothing to disclose. Walter J. Hader, MD has nothing to disclose. Dr. Xu has nothing to disclose. The institution of Prof. Jacobs has received personal compensation in the range of $10,000-$49,999 for serving as a Consultant for UCB. Prof. Jacobs has received personal compensation in the range of $500-$4,999 for serving as a Consultant for Epilog. Prof. Jacobs has received personal compensation in the range of $500-$4,999 for serving as a Consultant for Eisai. Prof. Jacobs has received personal compensation in the range of $500-$4,999 for serving as a Consultant for Pendopharm. Prof. Jacobs has received personal compensation in the range of $10,000-$49,999 for serving as an Editor, Associate Editor, or Editorial Advisory Board Member for Wiley. Prof. Jacobs has received personal compensation in the range of $500-$4,999 for serving as an Editor, Associate Editor, or Editorial Advisory Board Member for Elsevier. The institution of Prof. Jacobs has received research support from Alberta Childrens Hospital Foundation. Dr. Federico has nothing to disclose. Dr. Langdon has nothing to disclose.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.001
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Case report · Consensus signal: Case report
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.003
Threshold uncertainty score0.008

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.001
Meta-epidemiology (narrow)0.0010.001
Meta-epidemiology (broad)0.0000.001
Bibliometrics0.0010.001
Science and technology studies0.0020.002
Scholarly communication0.0010.001
Open science0.0010.001
Research integrity0.0030.001
Insufficient payload (model declined to judge)0.0020.001

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.036
GPT teacher head0.314
Teacher spread0.279 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designCase report
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations0
Published2023
Admission routes2
Has abstractyes

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