MétaCan
Menu
← Back to cohort
Record W4378652487 · doi:10.1101/2023.05.23.23290405

Exploring the common genetic architecture of autism spectrum disorder using a novel multi-polygenic risk score approach

2023· preprint· en· W4378652487 on OpenAlexafffund
Zoe Schmilovich, Vincent-Raphaël Bourque, Guillaume Huguet, Qin He, Jay P. Ross, Martineau Jean‐Louis, Zohra Saci, Boris Chaumette, Patrick A. Dion, Sébastien Jacquemont, Guy A. Rouleau

Bibliographic record

VenuemedRxiv · 2023
Typepreprint
Languageen
FieldNeuroscience
TopicAutism Spectrum Disorder Research
Canadian institutionsUniversité de MontréalCentre Hospitalier Universitaire Sainte-JustineMcGill UniversityMontreal Neurological Institute and Hospital
FundersFonds de Recherche du Québec - SantéCanadian Institutes of Health ResearchFondation Bettencourt SchuellerInstitut National de la Santé et de la Recherche Médicale
KeywordsAutism spectrum disorderGenetic architectureHeritabilityGenome-wide association studyAutismGenetic heterogeneityEndophenotypePedigree chartBiologyGeneticsPsychologyGenotypeSingle-nucleotide polymorphismPhenotypeCognitionNeuroscienceDevelopmental psychologyGene

Abstract

fetched live from OpenAlex

ABSTRACT Compared to disorders of similar heritability and contribution of common variants, few genome-wide significant loci have been implicated in autism spectrum disorder (ASD). This undermines the use of polygenic risk scores (PRSs) to investigate the common genetic architecture of ASD. Deconstructing PRS-ASD into its related traits via “developmental deconstruction” could reveal the underlying genetic liabilities of ASD. Using the data of >24k individuals with ASD and >28k of their unaffected family members from the SSC, SPARK, and MSSNG cohorts, we computed the PRSs for ASD and 11 genetically-related traits. We applied an unsupervised learning approach to the ASD-related PRSs to derive “multi-PRSs” that captured their variability in orthogonal dimensions. We found that multi-PRSs captured a similar proportion of genetic risk for ASD in cases versus intrafamilial controls (OR multi-PRS =1.10, R 2 =0.501%), compared to PRS-ASD itself (OR PRS-ASD =1.16, R 2 =0.619%). While multi-PRS dimensions conferred risk for ASD, they had “mirroring” effects on developmental phenotypes among cases with ASD. We posit that this phenomenon may partially account for the paucity of genome-wide significant loci and the clinical heterogeneity of ASD. This approach can serve as a proxy for PRS-ASD in cases where non-overlapping and well-powered GWAS summary statistics are difficult to obtain, or accounting for heterogeneity in a single dimension is preferable. This approach may also capture the overall liability for a condition ( i.e .: genetic “P-factor”). Altogether, we present a novel approach to studying the role of inherited, additive, and non-specific genetic risk factors in ASD.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.003
metaresearch head score (Gemma)0.008
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.010
Threshold uncertainty score0.019

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0030.008
Meta-epidemiology (narrow)0.0010.000
Meta-epidemiology (broad)0.0010.002
Bibliometrics0.0040.002
Science and technology studies0.0010.001
Scholarly communication0.0010.001
Open science0.0010.002
Research integrity0.0010.001
Insufficient payload (model declined to judge)0.0020.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.222
GPT teacher head0.327
Teacher spread0.104 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations1
Published2023
Admission routes2
Has abstractyes

Explore more

Same venuemedRxiv→Same topicAutism Spectrum Disorder Research→French-language works237,207→