MétaCan
Menu
Back to cohort
Record W4382181363 · doi:10.1093/braincomms/fcad182

Variation in prognosis and treatment outcome in juvenile myoclonic epilepsy: a Biology of Juvenile Myoclonic Epilepsy Consortium proposal for a practical definition and stratified medicine classifications

2023· review· en· W4382181363 on OpenAlexafffund
Guido Rubboli, Christoph P. Beier, Kaja Kristine Selmer, Marte Syvertsen, Amy Shakeshaft, Amber Collingwood, Anna Hall, Danielle M. Andrade, Choong Yi Fong, Joanna Gesche, David A. Greenberg, Khalid Hamandi, Kheng Seang Lim, Ching Ching Ng, Alessandro Orsini, Lisa J. Strug, Naim Panjwani, Fan Lin, Jana Zárubová, Zuzana Šobíšková, Cechovaz, Pracoviste, Michaela Kajšová, Rikke S. Møller, Elena Gardella, M Miranda, Inga Talvik, Pasquale Striano, Paulina Bala, Amy Kitching, Kate Irwin, Lorna Walding, Lynsey Adams, Uma Jegathasan, Rachel Swingler, Rachel Wane, Julia Aram, Nikil Sudarsan, Dee Mullan, Rebecca Ramsay, Vivien Richmond, M. Sargent, Paul Frattaroli, Matthew D. Taylor, Marie Home, Sal Uka, Susan Kilroy, Tonicha Nortcliffe, Kelly Holroyd, Alison McQueen, Dympna Mcaleer, Dina Jayachandran, Dawn Egginton, Bridget MacDonald, Michael Chang, David Deekollu, Alok Gaurav, Caroline Hamilton, Jaya Natarajan Inyan Takon, Janet Cotta, Nick Moran, Jeremy D.P. Bland, Rosemary Belderbos, Heather Collier, Joanne Henry, Matthew J. Milner, Sam White, Michalis Koutroumanidis, William Stern, Mark P. Richardson, Jennifer M. Quirk, Javier Peña‐Ceballos, Anastasia, Papathanasiou, Ioannis Stavropoulos, Dora A. Lozsádi, Andrew Swain, Charlotte Quamina, Jennifer Crooks, Tahir Majeed, Sonia Raj, Shakeelah Patel, Michael C. Young, Melissa Maguire, Munni Ray, Caroline Peacey, Linetty Makawa, Asyah Chhibda, Eve Sacre, Shanaz Begum, Martin O’Malley, Lap Yeung, Claire Holliday, Louise Woodhead, Karen Helton Rhodes, Rhys H. Thomas, Shan Ellawela, Joanne Glenton, Verity Calder, John M. Davis, Paul McAlinden, Sarah Francis, Lisa Robson, Karen Lanyon, Graham A. Mackay, Elma Stephen, Coleen Thow, Margaret Connon, Martin Kirkpatrick, Susan MacFarlane, Anne Scott MacLeod, Debbie Rice, Siva Kumar, Carolyn Campbell, Vicky Collins, William Whitehouse, Christina Giavasi, Boyanka Petrova, Thomas D. Brown, Catie Picton, Michael O’Donoghue, Charlotte West, Helen Navarra, Sean Slaght, Catherine Edwards, Andrew Gribbin, Liz Nelson, Stephen Warriner, Heather Angus‐Leppan, Loveth Ehiorobo, Bintou Camara, T Samakomva, Rajiv Mohanraj, Rajesh K. Pandey, Lisa Charles, Catherine Cotter, Archana Desurkar, Alison Hyde, Rachel Harrison, Markus Reuber, R. T. Clegg, J Sidebottom, Mayeth Recto, Patrick Easton, Charlotte Waite, Alice Howell, Jacqueline Smith, Shyam Mariguddi, Zena Haslam, Elizabeth Galizia, Hannah R. Cock, Mark Mencias, Samantha Truscott, Déirdre Daly, Hilda Mhandu, Nooria Said, Mark I. Rees, Seo‐Kyung Chung, Beata Fonferko‐Shadrach, Mark D. Baker, Louise Swain, Kirsty O’Brien, Fraser Scott, Naveed Ghaus, Gail Castle, Jacqui Bartholomew, Ann Needle, Julie Ball, Andrea Clough, Shashikiran Sastry, Charlotte Busby Amit Agrawal, Debbie Dickerson, Almu Duran, Muhammad Shamim Khan, Laura Thrasyvoulou, Eve Irvine, Sarah Tittensor, Jacqueline Daglish, Sumant Kumar, Claire Backhouse, Claire Mewies, Denise Skinner, Rahul Bharat, Sarah-Jane Sharman, Arun Saraswatula, Helen Cockerill, Jana Zárubová, Deb K. Pal

Bibliographic record

VenueBrain Communications · 2023
Typereview
Languageen
FieldMedicine
TopicEpilepsy research and treatment
Canadian institutionsHospital for Sick ChildrenKrembil FoundationUniversity of Toronto
FundersMedical Research CouncilMedical Research Council Centre for Neurodevelopmental DisordersEngineering and Physical Sciences Research CouncilNational Institute for Health and Care ResearchCanadian Institutes of Health ResearchMinistero dell’Istruzione, dell’Università e della RicercaMinistero della Salute
KeywordsJuvenile myoclonic epilepsyJuvenileEpilepsyMedicineVariation (astronomy)PsychiatryPsychologyPediatricsBiologyGeneticsPhysics

Abstract

fetched live from OpenAlex

Reliable definitions, classifications and prognostic models are the cornerstones of stratified medicine, but none of the current classifications systems in epilepsy address prognostic or outcome issues. Although heterogeneity is widely acknowledged within epilepsy syndromes, the significance of variation in electroclinical features, comorbidities and treatment response, as they relate to diagnostic and prognostic purposes, has not been explored. In this paper, we aim to provide an evidence-based definition of juvenile myoclonic epilepsy showing that with a predefined and limited set of mandatory features, variation in juvenile myoclonic epilepsy phenotype can be exploited for prognostic purposes. Our study is based on clinical data collected by the Biology of Juvenile Myoclonic Epilepsy Consortium augmented by literature data. We review prognosis research on mortality and seizure remission, predictors of antiseizure medication resistance and selected adverse drug events to valproate, levetiracetam and lamotrigine. Based on our analysis, a simplified set of diagnostic criteria for juvenile myoclonic epilepsy includes the following: (i) myoclonic jerks as mandatory seizure type; (ii) a circadian timing for myoclonia not mandatory for the diagnosis of juvenile myoclonic epilepsy; (iii) age of onset ranging from 6 to 40 years; (iv) generalized EEG abnormalities; and (v) intelligence conforming to population distribution. We find sufficient evidence to propose a predictive model of antiseizure medication resistance that emphasises (i) absence seizures as the strongest stratifying factor with regard to antiseizure medication resistance or seizure freedom for both sexes and (ii) sex as a major stratifying factor, revealing elevated odds of antiseizure medication resistance that correlates to self-report of catamenial and stress-related factors including sleep deprivation. In women, there are reduced odds of antiseizure medication resistance associated with EEG-measured or self-reported photosensitivity. In conclusion, by applying a simplified set of criteria to define phenotypic variations of juvenile myoclonic epilepsy, our paper proposes an evidence-based definition and prognostic stratification of juvenile myoclonic epilepsy. Further studies in existing data sets of individual patient data would be helpful to replicate our findings, and prospective studies in inception cohorts will contribute to validate them in real-world practice for juvenile myoclonic epilepsy management.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.002
metaresearch head score (Gemma)0.003
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMeta-epidemiology (narrow)
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Not applicable · Consensus signal: none
GenreCandidate signal: Review · Consensus signal: Review
Teacher disagreement score0.622
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0020.003
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0020.000
Bibliometrics0.0010.001
Science and technology studies0.0000.001
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.001
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.291
GPT teacher head0.466
Teacher spread0.175 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

Study designNot applicable
Domainnot available
GenreReview

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations15
Published2023
Admission routes2
Has abstractyes

Explore more

Same venueBrain CommunicationsSame topicEpilepsy research and treatmentFrench-language works237,207