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Record W4402480925 · doi:10.1007/s00415-024-12608-6

Pharmacogenomics of clinical response to Natalizumab in multiple sclerosis: a genome-wide multi-centric association study

2024· article· en· W4402480925 on OpenAlexaff
Ferdinando Clarelli, Andrea Corona, Kimmo Pääkkönen, Melissa Sorosina, Alen Zollo, Fredrik Piehl, Tomas Olsson, Pernilla Stridh, Maja Jagodic, Bernhard Hemmer, Christiane Gasperi, Adil Harroud, Klementy Shchetynsky, Alessandra Mingione, Elisabetta Mascia, Kaalindi Misra, Antonino Giordano, Maria Laura Terzi Mazzieri, Alberto Priori, Janna Saarela, Ingrid Kockum, Massimo Filippi, Federica Esposito, Filippo Martinelli Boneschi

Bibliographic record

VenueJournal of Neurology · 2024
Typearticle
Languageen
FieldMedicine
TopicMultiple Sclerosis Research Studies
Canadian institutionsMcGill University
FundersHorizon 2020 Framework ProgrammeUniversità degli Studi di Milano
KeywordsGenome-wide association studyPharmacogenomicsSingle-nucleotide polymorphismGenetics1000 Genomes ProjectSNPNatalizumabGenetic associationInteractomeBiologyGeneMedicineComputational biologyBioinformaticsOncologyInternal medicineGenotypeDisease

Abstract

fetched live from OpenAlex

Abstract Background Inter-individual differences in treatment response are marked in multiple sclerosis (MS). This is true for Natalizumab (NTZ), to which a subset of patients displays sub-optimal treatment response. We conducted a multi-centric genome-wide association study (GWAS), with additional pathway and network analysis to identify genetic predictors of response to NTZ. Methods MS patients from three different centers were included. Response to NTZ was dichotomized, nominating responders (R) relapse-free patients and non-responders (NR) all the others, over a follow-up of 4 years. Association analysis on ~ 4.7 M imputed autosomal common single-nucleotide polymorphisms (SNPs) was performed fitting logistic regression models, adjusted for baseline covariates, followed by meta-analysis at SNP and gene level. Finally, these signals were projected onto STRING interactome, to elicit modules and hub genes linked to response. Results Overall, 1834 patients were included: 119 from Italy (R = 94, NR = 25), 81 from Germany (R = 61, NR = 20), and 1634 from Sweden (R = 1349, NR = 285). The top-associated variant was rs11132400 T ( p = 1.33 × 10 –6 , OR = 0.58), affecting expression of several genes in the locus, like KLKB1 . The interactome analysis implicated a module of 135 genes, with over-representation of terms like canonical WNT signaling pathway ( p adjust = 7.08 × 10 –6 ). Response-associated genes like GRB2 and LRP6 , already implicated in MS pathogenesis , were topologically prioritized within the module. Conclusion This GWAS, the largest pharmacogenomic study of response to NTZ, suggested MS-implicated genes and Wnt/β-catenin signaling pathway, an essential component for blood–brain barrier formation and maintenance, to be related to treatment response.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.006
metaresearch head score (Gemma)0.018
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMetaresearch
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.056
Threshold uncertainty score0.991

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0060.018
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0010.000
Bibliometrics0.0010.001
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.001
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.182
GPT teacher head0.421
Teacher spread0.239 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations9
Published2024
Admission routes1
Has abstractyes

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