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Record W4404167190 · doi:10.1093/rheumatology/keae574

Anti-Sp4 and anti-CCAR1 autoantibodies in UK <i>vs</i> US patients with adult and juvenile-onset anti-TIF1γ-positive myositis

2024· article· en· W4404167190 on OpenAlexfundno aff
Fionnuala K McMorrow, Hector Chinoy, Alexander Oldroyd, Janine A. Lamb, Lisa G. Rider, Andrew L. Mammen, Livia Casciola‐Rosen, Neil McHugh, Sarah Tansley, Kate Armon, Louise Coke, Julie Cook, Amy Nichols, Liza McCann, Ian Roberts, Eileen Baildam, Louise Hanna, Olivia Lloyd, Susan Wadeson, Michelle Andrews, Jane Roach, Phil Riley, Ann McGovern, Verna Cuthbert, Clive Ryder, J Scott, Beverley Thomas, T. R. E. Southwood, Eslam Al-Abadi, Ruth Howman, Sue Wyatt, Gillian Jackson, Mark Wood, Tania Amin, Vanessa VanRooyen, Deborah Burton, Louise Turner, Heather Rostron, Sarah Hanson, Janet Gardner‐Medwin, Neil A. Martin, Sue A. Ferguson, Liz Waxman, Michael Browne, Roisin Boyle, Emily Blyth, Susanne Cathcart, Mark Friswell, Helen Foster, Sharmila Jandial, V. Stevenson, Debbie Wade, Ethan S Sen, Eve Smith, Stuart Watson, Claire Duong, Stephen Crulley, Andrew J. Davies, Miss Caroline Miller, Lynne Bell, Flora McErlane, Sunil Sampath, Sharon King, H Venning, Satyapal Rangaraj, Elizabeth Stretton, Mary Jordan, Ellen Mosley, Lindsay Crate, Kishore Warrier, Stefanie Stafford, Brogan Wrest, Chia-Ping Chou, Paul Pryce, Lucy R. Wedderburn, Clarissa Pilkington, Nathan Hasson, Muthana Al-Obadi, Giulia Varnier, Sandrine Lacassagne, Sue Maillard, Lauren E. Stone, Elizabeth Halkon, Virginia Brown, Audrey Juggins, Sally A. Smith, Sian Lunt, Elli Enayat, Hemlata Varsani, Laura Kassoumeri, Katie Arnold, Yvonne Glackin, Stephanie Simou, Beverley Almeida, Kiran Nistala, Raquel Marques, Claire T. Deakin, Parichat Khaosut, Stefanie Dowle, Charalampia Papadopoulou, Shireena A. Yasin, Christina Boros, Meredyth Wilkinson, Christopher Piper, Cerise Johnson-Moore, Lucy Marshall, Kathryn O’Brien, Emily Robinson, Dominic Igbelina, Polly Livermore, Socrates Varakliotis, Rosie Hamilton, Dario Cancemi, Kevin Murray, Coziana Ciurtin, J Ioannou, Caitlin Clifford, Linda Suffield, Laura Hennelly, Helen Lee, Helen Smith, Anne-Marie McMahon, Heather Chisem, Jeanette Hall, Amy Huffenberger, Nick Wilkinson, Emma Inness, E. J. C. Kendall, Ruth Etherton, Danielle Miller, Kathryn Bailey, Jacqui Clinch, Natalie Fineman, Helen Pluess-Hall, Suzanne Sketchley, Melanie Marsh, Anna Fry, Maisy Dawkins-Lloyd, Manija Asif, Margaret Connon, Lindsay Vallance, Kirsty Haslam, Charlene Bass-Woodcock, Trudy Booth, Louise Akeroyd, Alice Leahy, Amy Collier, Rebecca Cutts, E. J. MacLeod, Hans de Graaf, Brian Davidson, Sarah Hartfree, Elizabeth Fofana, Lorena Caruana

Bibliographic record

VenueLara D. Veeken · 2024
Typearticle
Languageen
FieldMedicine
TopicInflammatory Myopathies and Dermatomyositis
Canadian institutionsnot available
FundersNational Institute of Environmental Health SciencesManchester Biomedical Research CentreMedical Research CouncilVersus ArthritisHospital for Sick ChildrenDeakin UniversityUniversity of OxfordUniversity College LondonArthritis Research UKDepartment of Health and Social CareAction Medical ResearchMyositis AssociationNational Institute for Health and Care ResearchNational Institutes of HealthNIHR Biomedical Research Centre, Royal Marsden NHS Foundation Trust/Institute of Cancer ResearchUniversity Hospital Southampton NHS Foundation TrustWellcome Trust
KeywordsMedicineAutoantibodyJuvenileMyositisInternal medicineAntibodyImmunologyGenetics

Abstract

fetched live from OpenAlex

OBJECTIVES: Anti-transcriptional intermediary factor 1γ (TIF1γ) autoantibodies are associated with malignancy in adult-onset idiopathic inflammatory myopathy (IIM) and this risk is attenuated if patients are also positive for anti-specificity protein 4 (Sp4) or anti-cell division cycle apoptosis regulator protein 1 (CCAR1). In anti-TIF1γ positive dermatomyositis (DM) patients from the USA, anti-Sp4 and anti-CCAR1 autoantibody frequencies are reported as 32% and 43% in adults and 9% and 19% in juveniles, respectively. This study aims to identify the frequency of anti-Sp4 and anti-CCAR1 in adult and juvenile UK anti-TIF1γ-positive myositis populations and report clinical associations. METHODS: Serum samples from 51 UK participants with adult-onset IIM and 55 UK participants with JDM, all anti-TIF1γ autoantibody positive, and 24 healthy control samples were screened for anti-Sp4 and anti-CCAR1 autoantibodies by ELISA. RESULTS: In UK adult anti-TIF1γ positive IIM patients, anti-Sp4 and anti-CCAR1 frequencies were 4% (2/51) and 16% (8/51). Both adult patients with anti-Sp4 were also positive for anti-CCAR1. In UK juveniles, anti-Sp4 was not detected and 13% (7/55) had anti-CCAR1 autoantibodies. Nineteen (37%) anti-TIF1γ positive UK adult myositis patients had cancer; neither of the two patients with anti-Sp4 autoantibodies and 25% (2/8) of anti-CCAR1 autoantibody-positive patients had cancer. No anti-Sp4 or anti-CCAR1 clinical associations were identified. CONCLUSION: Anti-Sp4 and anti-CCAR1 autoantibodies are less common in the adult UK anti-TIF1γ-positive myositis population compared with published data from the USA, limiting their use as biomarkers for cancer risk. In patients with juvenile onset disease, anti-Sp4 is less frequent in UK patients compared with the USA, but the prevalence of anti-CCAR1 autoantibodies is similar.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.001
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.005
Threshold uncertainty score0.009

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.001
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0010.001
Science and technology studies0.0000.000
Scholarly communication0.0010.000
Open science0.0000.000
Research integrity0.0010.000
Insufficient payload (model declined to judge)0.0020.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.004
GPT teacher head0.218
Teacher spread0.214 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations2
Published2024
Admission routes1
Has abstractyes

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