MétaCan
Menu
← Back to cohort
Record W4404183357 · doi:10.1136/jnnp-2024-abn.44

Collapse, confusion, and clots: an acute presentation of late onset MTHFR deficiency, a treatable leukodystrophy

2024· article· en· W4404183357 on OpenAlexaff
van Rhee Chevonne, Aravindhan Baheerathan, Jaffer Fatima

Bibliographic record

Venuenot available
Typearticle
Languageen
FieldMedicine
TopicFolate and B Vitamins Research
Canadian institutionsSt. Thomas Hospital
Fundersnot available
KeywordsConfusionLeukodystrophyMedicinePresentation (obstetrics)PediatricsInternal medicineSurgeryPsychologyDiseasePsychoanalysis

Abstract

fetched live from OpenAlex

A 29-year-old female of Pakistani-Indian origin presented with collapse and confusion on a background of 12 months of progressive leg weakness. Her medical history included significant psychiatric co-morbidity: initially bipolar affective disorder and depression, later revised to schizophrenia. On admission, she was encephalopathic with GCS 11(E3V3M5), and neurological examination revealed a moderate spastic paraparesis. CTPA demonstrated bilateral pulmonary emboli. Intracranial imaging showed extensive bilateral venous sinus thromboses with symmetrical parieto-occipital T2 hyperintensity suggestive of a leukodystrophy. Spinal imaging was normal. Metabolic testing revealed low- normal total B12 level 212ng/L(180-700ng/L), low folate 1.0ug/L(4.6-18.7ug/L), elevated homocysteine level 180umol/L(0-15umol/L), elevated MMA 340nmol/L(0-280nmol/L), and low methionine level 6umol/L on plasma amino acid profile- diagnostic of methylenetetrahydrofolate reductase (MTHFR) deficiency. Genetic testing confirmed likely pathogenic homozygous mutation, c.973C>T; Arg325Cys, in MTHFR with 20% residual MTHFR activity, and homozygous common polymorphism, c.6777C>T. Treatment included hydroxocobalamin, folinic acid, betaine and rivaroxaban alongside psychiatric management with no further deterioration in neurological deficit or further thromboses. Her siblings have been offered genetic testing. Homocysteine testing remains integral in young-onset stroke work-up. This case highlights the heterogenous adult presentation of treatable MTHFR deficiency. It is an important differential diagnosis in patients presenting with neuropsychiatric symptoms, spastic paraparesis, undifferentiated leukodystrophy, or thromboembolism.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.002
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Case report · Consensus signal: Case report
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.006
Threshold uncertainty score0.011

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.002
Meta-epidemiology (narrow)0.0020.001
Meta-epidemiology (broad)0.0010.001
Bibliometrics0.0020.001
Science and technology studies0.0020.001
Scholarly communication0.0010.001
Open science0.0010.001
Research integrity0.0030.003
Insufficient payload (model declined to judge)0.0020.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.021
GPT teacher head0.338
Teacher spread0.316 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designCase report
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations0
Published2024
Admission routes1
Has abstractyes

Explore more

Same topicFolate and B Vitamins Research→French-language works237,207→