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Record W4406034886 · doi:10.1038/s41588-024-02014-z

ZIC1 is a context-dependent medulloblastoma driver in the rhombic lip

2025· article· en· W4406034886 on OpenAlexafffund
John J. Y. Lee, Ran Tao, Zhen You, Parthiv Haldipur, Anders W. Erickson, Hamza Farooq, Liam D. Hendriske, Namal Abeysundara, Cory M. Richman, Evan Y. Wang, Neha Gupta, Jennifer Hadley, Melissa Batts, Christopher Mount, Xiaochong Wu, Alex Rasnitsyn, Swneke D. Bailey, Florence M.G. Cavalli, A. Sorana Morrissy, Livia Garzia, Kulandaimanuvel Antony Michealraj, Abhi Visvanathan, Vernon Fong, Jonelle Palotta, Raúl A. Suárez, Bryn Livingston, Liu Miao, Betty Luu, Craig Daniels, James Loukides, Anne Bendel, Pim J. French, Johan M. Kros, Andrey Korshunov, Marcel Kool, Fernando Chico Ponce de León, Mario Pérezpeña-Díazconti, Bolesław Lach, Sheila K. Singh, Sarah Leary, Byung-Kyu Cho, Seung‐Ki Kim, Kyu‐Chang Wang, Ji-Yeoun Lee, Teiji Tominaga, William A. Weiss, Joanna J. Phillips, Shizhong Dai, Gelareh Zadeh, Ali G. Saad, László Bognár, Álmos Klekner, Ian F. Pollack, Ronald L. Hamilton, Young‐Shin Ra, Wiesława Grajkowska, Marta Perek‐Polnik, Reid C. Thompson, Anna Marie Kenney, Michael K. Cooper, Stephen C. Mack, Nada Jabado, Mathieu Lupien, Marco Gallo, Vijay Ramaswamy, Mario L. Suvà, Hiromichi Suzuki, Kathleen J. Millen, Lei Huang, Paul A. Northcott, Michael D. Taylor

Bibliographic record

VenueNature Genetics · 2025
Typearticle
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicGenomics and Chromatin Dynamics
Canadian institutionsPrincess Margaret Cancer CentreMcMaster UniversityMcGill UniversityUniversity of CalgaryUniversity Health NetworkUniversity of TorontoSickKids FoundationHospital for Sick Children
FundersDOD Peer Reviewed Cancer Research ProgramNational Institute of Neurological Disorders and StrokeBrain Tumour ResearchDebreceni EgyetemHospital for Sick ChildrenNational Cancer InstituteUniversity of TorontoStand Up To CancerGenome British ColumbiaWellcome TrustAmerican Lebanese Syrian Associated CharitiesGenome CanadaSt. Jude Children's Research HospitalMedical Research CouncilCancer Prevention and Research Institute of TexasGovernment of OntarioAmerican Association for Cancer ResearchCanadian Institutes of Health ResearchPediatric Brain Tumor FoundationGovernment of CanadaCanadian Cancer Society Research InstituteNational Institutes of HealthU.S. Department of Health and Human Services
KeywordsMedulloblastomaBiologyContext (archaeology)Cancer researchMutantGeneticsGene

Abstract

fetched live from OpenAlex

Transcription factors are frequent cancer driver genes, exhibiting noted specificity based on the precise cell of origin. We demonstrate that ZIC1 exhibits loss-of-function (LOF) somatic events in group 4 (G4) medulloblastoma through recurrent point mutations, subchromosomal deletions and mono-allelic epigenetic repression (60% of G4 medulloblastoma). In contrast, highly similar SHH medulloblastoma exhibits distinct and diametrically opposed gain-of-function mutations and copy number gains (20% of SHH medulloblastoma). Overexpression of ZIC1 suppresses the growth of group 3 medulloblastoma models, whereas it promotes the proliferation of SHH medulloblastoma precursor cells. SHH medulloblastoma ZIC1 mutants show increased activity versus wild-type ZIC1, whereas G4 medulloblastoma ZIC1 mutants exhibit LOF phenotypes. Distinct ZIC1 mutations affect cells of the rhombic lip in diametrically opposed ways, suggesting that ZIC1 is a critical developmental transcriptional regulator in both the normal and transformed rhombic lip and identifying ZIC1 as an exquisitely context-dependent driver gene in medulloblastoma.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Bench or experimental · Consensus signal: Bench or experimental
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.003
Threshold uncertainty score0.006

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0010.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.003
GPT teacher head0.232
Teacher spread0.229 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designBench or experimental
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations12
Published2025
Admission routes2
Has abstractyes

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