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Record W4406267890 · doi:10.1016/j.jacadv.2024.101547

Naxos Disease and Related Cardio-Cutaneous Syndromes

2025· review· en· W4406267890 on OpenAlexaff
Alexandros Protonotarios, Angeliki Asimaki, Cristina Basso, Zafeirenia Xylouri, Emanuele Monda, Ioannis Protonotarios, Giulia Crisci, Dominic Jr Abrahms, Aris Anastasakis, Loizos Antoniades, Athanasios Bakalakos, Andreina Carbone, Aman S. Coonar, Juan R. Gimeno, George Lazaros, Stamatis Lerakis, Luisa Mestroni, George Papadopoulos, Leandro Pecchia, Francesca Romana Prandi, Petros Syrris, Julia Cadrin-Turigny, Anargyros Vasilakis, Jeffrey E. Saffitz, Perry Elliott, Juan Pablo Kaski, William J. McKenna, Eduardo Bossone, Giuseppe Limongelli, Adalena Tsatsopoulou

Bibliographic record

VenueJACC Advances · 2025
Typereview
Languageen
FieldMedicine
TopicCardiovascular Effects of Exercise
Canadian institutionsMontreal Heart Institute
FundersMedical Research CouncilBritish Heart Foundation
KeywordsPlakoglobinPalmoplantar keratodermaDesmoplakinMedicineDiseaseCardiomyopathyBioinformaticsDermatologyHeart failureCardiologyPathologyGeneGeneticsHyperkeratosisBiology

Abstract

fetched live from OpenAlex

Naxos disease is a rare autosomal recessive condition combining arrhythmogenic right ventricular cardiomyopathy, woolly hair, and palmoplantar keratoderma. The first identified causative variant was in the gene encoding the desmosomal protein plakoglobin. Naxos disease exhibits fibro-fatty myocardial replacement with immunohistological abnormalities in cardiac protein and signaling pathways, highlighting the role of inflammation and potential anti-inflammatory treatments. Childhood cutaneous signs precede cardiac features, which are diagnosed by familial and genetic evaluation, electrocardiography and cardiac imaging. Disease progression necessitates holistic care with risk management and lifestyle adjustments, often needing treatment for arrhythmia and heart failure. Similar phenotypes have been linked to desmoplakin and rarely desmocollin2 gene variants, highlighting the importance of familial and genetic evaluation. This document summarizes current knowledge on Naxos disease and related cardiocutaneous syndromes and initiates an international endeavor to collect and study all global cases, aiming to improve understanding, treatment, and patient care through shared data and research.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.001
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMeta-epidemiology (narrow)
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Not applicable · Consensus signal: none
GenreCandidate signal: Review · Consensus signal: Review
Teacher disagreement score0.928
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.001
Meta-epidemiology (narrow)0.0010.000
Meta-epidemiology (broad)0.0040.002
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.011
GPT teacher head0.316
Teacher spread0.306 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

Study designNot applicable
Domainnot available
GenreReview

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations7
Published2025
Admission routes1
Has abstractyes

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