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Record W4412478761 · doi:10.1101/2025.07.11.25331310

A cross-disorder analysis of CNVs finds novel loci and dose-dependent relationships of genes to psychiatric traits

2025· preprint· en· W4412478761 on OpenAlexaff
Omar Shanta, Marieke Klein, M Sacks, Jeffrey R. MacDonald, Adam X. Maihofer, Mohammad Ahangari, Worrawat Engchuan, Bhooma Thiruvahindrapuram, James P. Guevara, Oanh Hong, Guillaume Huguet, Ida E. Sønderby, Maria Kalyuzhny, Mark J. Adams, Rolf Adolfsson, Ingrid Agartz, Allison E. Aiello, Martin Alda, Judith Allardyce, Ananda B. Amstadter, Till F. M. Andlauer, Ole A. Andreassen, María S. Artigas, S. Bryn Austin, Muhammad Ayub, Dewleen G. Baker, Bernhard T. Baune, Joanna M. Biernacka, Tim B. Bigdeli, Jonathan I. Bisson, D. Blackwood, Marco P. Boks, David Braff, Elvira Bramon, Gerome Breen, T. Brueckl, Richard A. Bryant, Cynthia M. Bulik, Joseph D. Buxbaum, Murray J. Cairns, José Miguel Caldas‐de‐Almeida, Megan Campbell, Dominique Campion, Vaughan J. Carr, Enrique Castelao, Boris Chaumette, Sven Cichon, David Cohen, Aiden Corvin, Jennifer Crosbie, Udo Dannlowski, Franziska Degenhardt, Douglas L. Delahanty, Astrid Dempfle, Guillaume Desachy, Arianna Di Florio, Faith Dickerson, Srdjan Djurovic, Katharina Domschke, Lisa Douglas, Ole Kristian Drange, Laramie E. Duncan, Howard J. Edenberg, Tõnu Esko, Stephen V. Faraone, Norah C. Feeny, Andreas J. Forstner, Barbara Franke, Mark A. Frye, Dong‐Jing Fu, Janice M. Fullerton, А. Э. Гареева, Linda Garvert, Justine M. Gatt, Pablo V. Gejman, Daniel H. Geschwind, Ina Giegling, Stephen J. Glatt, Fernando S. Goes, Katherine Gordon‐Smith, Hans J. Grabe, Melissa J. Green, Michael F. Green, Tiffany A. Greenwood, Maria Grigoroiu‐Serbânescu, Raquel E. Gur, Ruben C. Gur, José Guzmán‐Parra, Jan Haavik, Tim Hahn, Håkon Håkonarson, Joachim Hallmayer, Marian L. Hamshere, Annette M. Hartmann, Arsalan Hassan, Caroline Hayward, Johannes Hebebrand, Sian Hemmings, Stefan Herms, Marisol Herrera-Rivero, Anke Hinney, Georg Homuth, Andrés Ingason, Lucas Toshio Ito, Ian Jones, Lisa Jones, Lina Jönsson, Erik G. Jönsson, René S. Kahn, Robert Karlsson, Milissa L. Kaufman, John R. Kelsoe, James L. Kennedy, Anthony P. King, Tilo Kircher, George Kirov, Per M. Knappskog, James A. Knowles, Karestan C. Koenen, Bettina Konte, Mayuresh S. Korgaonkar, Kaarina Kowalec, Marie‐Odile Krebs, Mikael Landén, Claudine Laurent‐Levinson, Lauren A. M. Lebois, Doug Levinson, Cathryn M. Lewis, Qingqin S. Li, Israel Liberzon, Greg Light, Sandra K. Loo, Yi Lu, Susanne Lucae, Charles R. Marmar, Nick Martin, Fermín Mayoral, Andrew M. McIntosh, Katie A. McLaughlin, Samuel A. McLean, Andrew McQuillin, Sarah E. Medland, Andreas Meyer‐Lindenberg, Vihra Milanova, Philip B. Mitchell, Esther Molina, Bryan Mowry, Bertram Müller‐Myhsok, Niamh Mullins, Robin Murray, Markus M. Nöthen, John I. Nürnberger, Kevin S. O’Connell, Roel A. Ophoff, Holly K. Orcutt, Michael J. Owen, Aarno Palotie, Carlos N. Pato, Michele T. Pato, Joanna Pawlak, Triinu Peters, Tracey L. Petryshen, Giorgio Pistis, James B. Potash, John Powell, Martin Preisig, Digby Quested, Josep Antoni Ramos‐Quiroga, Andreas Reif, Kerry J. Ressler, Marta Ribasés, Marcella Rietschel, Victoria B. Risbrough, Margarita Rivera, Alex O. Rothbaum, Barbara O. Rothbaum, Dan Rujescu, Takeo Saito, Alan R. Sanders, Russell Schachar, Peter R. Schofield, Eva C. Schulte, Thomas G. Schulze, Laura J. Scott, Soraya Seedat, Christina M. Sheerin, Jianxin Shi, Pamela Sklar, Susan L. Smalley, Olav B. Smeland, Jordan W. Smoller, Edmund Sonuga‐Barke, David St Clair, Nils Eiel Steen, Dan J. Stein, Frederike Stein, Murray B. Stein, Fabian Streit, Neal R. Swerdlow, Florence Thibaut, Johan H. Thygesen, И. Ф. Тимербулатов, Claudio Toma, Edward Trapido, Micheline Tremblay, Ming T. Tsuang, Monica Uddin, Marquis P. Vawter, John B. Vincent, Henry Völzke, James Walters, Cynthia Shannon Weickert, Lauren A. Weiss, Myrna M. Weissman, Thomas Werge, Stephanie H. Witt, Miguel Xavier, Robert H. Yolken, Ross McD. Young, Tetyana Zayats, Lori A. Zoellner, Kimberley Kendall, Brien P. Riley, Naomi R. Wray, Michael O‘Donovan, Patrick F. Sullivan, Sandra Sanchez‐Roige, Caroline M. Nievergelt, Sébastien Jacquemont, Stephen W. Scherer, Jonathan Sebat

Bibliographic record

VenuemedRxiv · 2025
Typepreprint
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicGenomic variations and chromosomal abnormalities
Canadian institutionsUniversity of ManitobaCentre for Addiction and Mental HealthUniversité de MontréalCentre Hospitalier Universitaire Sainte-JustineUniversity of TorontoSickKids FoundationDalhousie UniversityHospital for Sick Children
FundersUniversity of California, San DiegoNorges ForskningsrådH. Lundbeck A/SLundbeckfondenTrinity College DublinCardiff University
KeywordsGeneGeneticsPsychiatric geneticsCopy-number variationQuantitative trait locusPsychologyPsychiatryBiologySchizophrenia (object-oriented programming)Genome

Abstract

fetched live from OpenAlex

Abstract Rare copy number variants (CNVs) are a key component of the genetic basis of psychiatric conditions, but have not been well characterized for most. We conducted a genome-wide CNV analysis across six diagnostic categories (N = 574,965): autism (ASD), ADHD, bipolar disorder (BD), major depressive disorder (MDD), PTSD, and schizophrenia (SCZ). We identified 35 genome-wide significant associations at 18 loci, including novel associations in SCZ ( SMYD3, USP7 - HAPSTR1 ) and in the combined cross-disorder analysis ( ASTN2 ). Rare CNVs accounted for 1–3% of heritability across diagnoses. In ASD, associations were uniformly positive, consistent with autism having diverse etiologies and clinical presentations. By contrast, CNVs showed a dose-dependent relationship for other diagnoses, including SCZ and PTSD, with reciprocal deletions and duplications having inversely correlated effects and distinct genotype-phenotype relationships. Our findings suggest that genes have effects that are both dose-dependent and pleiotropic, such that a positive influence on one dimension of psychopathology may be accompanied by positive or negative effects on others.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.001
metaresearch head score (Gemma)0.002
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.004
Threshold uncertainty score0.014

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0010.002
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0010.001
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.001
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0040.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.020
GPT teacher head0.276
Teacher spread0.256 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations6
Published2025
Admission routes1
Has abstractyes

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Same venuemedRxivSame topicGenomic variations and chromosomal abnormalitiesFrench-language works237,207