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Record W4415126802 · doi:10.1016/j.ajhg.2025.09.012

A scalable framework for identifying allelic series from summary statistics

2025· article· en· W4415126802 on OpenAlexaff
Zachary R. McCaw, Jianhui Gao, Rounak Dey, Simon Tucker, Yiyan Zhang, Jessica Gronsbell, Xihao Li, Emily B. Fox, Colm O’Dushlaine, Thomas W. Soare

Bibliographic record

VenueThe American Journal of Human Genetics · 2025
Typearticle
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicGenetic Associations and Epidemiology
Canadian institutionsUniversity of Toronto
Fundersnot available
KeywordsSeries (stratigraphy)ScalabilityAlleleLinkage disequilibriumGenetic dataTime seriesSummary statistics

Abstract

fetched live from OpenAlex

Genes where a dose-response relationship exists between functionality and phenotypic impact are appealing therapeutic targets, as the effects of pharmacological modulation can be predicted from natural genetic variation. We refer to such genes as harboring allelic series and have introduced the rare coding-variant allelic series test (COAST) for their identification. The original COAST required access to individual-level data. However, these data are often unavailable due to privacy or logistical constraints. Meanwhile, single-variant summary statistics of the type produced by genome-wide association studies are plentiful. Here, we introduce COAST-SS, an extension of COAST that accepts standard summary statistics as input. As a running example, we consider identifying allelic series for circulating lipid traits, drawing on data from the UK Biobank, the Million Veteran Program, and the Trans-Omics of Precision Medicine Program. Through extensive analyses of real and simulated data, we demonstrate that COAST-SS provides p values effectively equivalent to those from the original COAST. Interestingly, we find that when linkage disequilibrium (LD) is low, as is expected among rare variants, COAST-SS is robust to misspecification of the LD matrix. We explore several strategies for annotating the pathogenicity of variants supplied to COAST-SS, finding that they often yield similar power for detecting candidate allelic series. Lastly, we employ COAST-SS to screen for lipid-trait allelic series in a meta-analyzed cohort of up to 840,000 subjects. COAST-SS has been incorporated into the publicly available AllelicSeries R package.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.011
metaresearch head score (Gemma)0.053
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Simulation or modeling · Consensus signal: none
GenreCandidate signal: Methods · Consensus signal: Methods
Teacher disagreement score0.012
Threshold uncertainty score0.057

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0110.053
Meta-epidemiology (narrow)0.0020.001
Meta-epidemiology (broad)0.0020.003
Bibliometrics0.0040.003
Science and technology studies0.0010.001
Scholarly communication0.0030.002
Open science0.0030.003
Research integrity0.0010.003
Insufficient payload (model declined to judge)0.0120.004

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.022
GPT teacher head0.332
Teacher spread0.309 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designSimulation or modeling
Domainnot available
GenreMethods

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations1
Published2025
Admission routes1
Has abstractyes

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