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Record W4415403441 · doi:10.1038/s41531-025-01147-0

Neural networks reveal novel gene signatures in Parkinson disease from single-nuclei transcriptomes

2025· article· en· W4415403441 on OpenAlexafffund
Michael R. Fiorini, Jialun Li, Edward A. Fon, Sali M.K. Farhan, Rhalena A. Thomas

Bibliographic record

Venuenpj Parkinson s Disease · 2025
Typearticle
Languageen
FieldMedicine
TopicParkinson's Disease Mechanisms and Treatments
Canadian institutionsMcGill University Health CentreMcGill UniversityMcGill Genome CentreMontreal Neurological Institute and Hospital
FundersMontreal Neurological Institute and HospitalFondation Brain CanadaMcGill UniversityCanadian Institutes of Health ResearchQuébec Consortium for Drug DiscoveryFonds de Recherche du Québec - SantéMichael J. Fox Foundation for Parkinson's Research
KeywordsTranscriptomeGeneParkinson's diseaseDiseaseCandidate geneLRRK2PhenomeGenomicsDopaminergic

Abstract

fetched live from OpenAlex

Parkinson disease (PD) is a progressive neurodegenerative disease with an incompletely understood genetic architecture that necessitates novel discovery methods. We introduce an explainable machine learning framework that uses single-cell/nuclei RNA sequencing (sc/snRNAseq) to identify molecular markers of diseased cells and nominate candidate genes for targeted genomic analysis. Application to four snRNAseq datasets characterizing the post-mortem midbrain identified cell type-specific gene sets that consistently distinguished PD from healthy cells across all datasets (mean balanced accuracy = 0.92) and highlighted ten novel candidate genes in PD. Among these, GPC6 was identified as a marker of PD dopaminergic neurons and a member of the heparan sulfate proteoglycan family, implicated in the intracellular accumulation of α-synuclein preformed fibrils-a hallmark of PD. We further validated the enrichment of rare GPC6 variants in PD across three case-control cohorts. This open-source framework is broadly applicable across diseases and promises to accelerate gene discovery in complex diseases.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.001
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Simulation or modeling · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.001
Threshold uncertainty score0.003

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.001
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0010.000
Science and technology studies0.0000.000
Scholarly communication0.0010.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0010.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.019
GPT teacher head0.261
Teacher spread0.242 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designSimulation or modeling
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations2
Published2025
Admission routes2
Has abstractyes

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