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S4570 A Rare Case of Cronkhite-Canada Syndrome in a Young Male: Diagnostic and Therapeutic Challenges

2025· article· en· W7110979544 on OpenAlexaboutno aff

Bibliographic record

VenueThe American Journal of Gastroenterology · 2025
Typearticle
Languageen
FieldMedicine
TopicGenetic factors in colorectal cancer
Canadian institutionsnot available
Fundersnot available
KeywordsMelenaAbdominal painCapsule endoscopyEsophagogastroduodenoscopyHyperpigmentationEnteropathyHypoalbuminemiaColonoscopyGastrointestinal bleeding

Abstract

fetched live from OpenAlex

Introduction: Cronkhite–Canada Syndrome (CCS) is a rare, nonhereditary gastrointestinal polyposis disorder characterized by chronic diarrhea, weight loss, and ectodermal changes such as alopecia and hyperpigmentation. Its pathogenesis remains unclear, and diagnosis relies on clinical, endoscopic, and histological findings. Case Description/Methods: A 38-year-old man presented with a 2-month history of postprandial diarrhea, nausea, vomiting, and generalized weakness, along with a 15 kg unintentional weight loss. He reported chronic abdominal pain worsened by meals and occasional blood-streaked stools, without melena or hematemesis. Physical examination revealed signs of malnutrition and ectodermal changes, including alopecia, nail dystrophy, and hyperpigmentation of the palms and soles. Laboratory workup showed hypoalbuminemia and iron deficiency anemia. Infectious screening, including stool cultures, Clostridioides difficile toxin, ova and parasite testing, and viral panels, was negative. Endoscopic evaluation revealed erythematous mucosa in the stomach, duodenum, terminal ileum, and colon. Biopsies showed polypoid mucosa with cystically dilated glands, edematous lamina propria, and mixed inflammatory infiltrates rich in eosinophils and mononuclear cells, without dysplasia. Video capsule endoscopy demonstrated diffusely edematous and nodular gastric mucosa, elongated villi throughout the small bowel, and dark blood in the proximal ileum without a clear bleeding source. These findings supported a diagnosis of Cronkhite–Canada Syndrome. The patient was started on a short course of intravenous corticosteroids, followed by oral prednisolone and azathioprine (Imuran) as a steroid-sparing agent. He also received nutritional support, proton pump inhibitors, and pancreatic enzyme supplements. At follow-up, the patient reported marked improvement in diarrhea, suggesting a positive response to immunosuppressive therapy. He remains under surveillance with routine labs and a scheduled endoscopy to assess mucosal healing. Discussion: This case underscores the importance of early diagnosis and multidisciplinary care in managing Cronkhite–Canada Syndrome, a rare but serious gastrointestinal polyposis disorder. The patient’s clinical improvement on steroids and azathioprine highlights the role of immunosuppression in addressing the inflammatory nature of CCS. Prompt treatment, nutritional support, and close surveillance are key to improving outcomes and reducing the risk of complications such as malnutrition and malignancy.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.002
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Case report · Consensus signal: Case report
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.007
Threshold uncertainty score0.013

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.002
Meta-epidemiology (narrow)0.0020.001
Meta-epidemiology (broad)0.0010.001
Bibliometrics0.0030.001
Science and technology studies0.0020.001
Scholarly communication0.0010.002
Open science0.0010.001
Research integrity0.0050.002
Insufficient payload (model declined to judge)0.0030.001

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.010
GPT teacher head0.256
Teacher spread0.246 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designCase report
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations0
Published2025
Admission routes1
Has abstractyes

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