MétaCan
Menu
Back to cohort
Record W1619053513 · doi:10.1001/jamaneurol.2015.1700

Association of Long Runs of Homozygosity With Alzheimer Disease Among African American Individuals

2015· article· en· W1619053513 on OpenAlex
Mahdi Ghani, Christiane Reitz, Rong Cheng, Badri N. Vardarajan, Gyungah Jun, Christine Sato, Adam C. Naj, Ruchita Rajbhandary, Li San Wang, Otto Valladares, Chiao‐Feng Lin, Eric B. Larson, Neill R. Graff‐Radford, Denis A. Evans, Philip L. De Jager, Paul K. Crane, Joseph D. Buxbaum, Jill R. Murrell, Towfique Raj, Nilüfer Ertekin‐Taner, Mark Logue, Clinton T. Baldwin, Robert C. Green, Lisa L. Barnes, Laura B. Cantwell, M. Daniele Fallin, Rodney C.P. Go, Patrick Griffith, Thomas O. Obisesan, Jennifer J. Manly, Kathryn L. Lunetta, M. Ilyas Kamboh, Oscar L. López, David A. Bennett, Hugh C. Hendrie, Kathleen Hall, Alison Goate, Goldie S. Byrd, Walter A. Kukull, Tatiana M. Foroud, Jonathan L. Haines, Lindsay A. Farrer, Margaret A. Pericak‐Vance, Joseph H. Lee, Gerard D. Schellenberg, Peter St George‐Hyslop, Richard Mayeux, Ekaterina Rogaeva

Why this work is in the frame

A frame that forgets how it found something cannot be audited. These are the routes that admitted this work.

affAt least one author lists a Canadian institution in the pinned OpenAlex snapshot.
fundA Canadian funder is recorded on the work.

Bibliographic record

VenueJAMA Neurology · 2015
Typearticle
Languageen
FieldMedicine
TopicAlzheimer's disease research and treatments
Canadian institutionsOccupational Cancer Research CentreUniversity of Toronto
FundersNational Center for Research ResourcesNational Cancer InstituteNational Human Genome Research InstituteNational Institute on AgingGeriatric Research Education and Clinical CenterNational Center for Advancing Translational SciencesMedical Research CouncilDepartment of Pathology, Johns Hopkins UniversitySchool of Medicine, Indiana UniversityUniversity of California, IrvineNational Institute of Mental HealthFeinberg School of MedicinePerelman School of Medicine, University of PennsylvaniaUniversity of California, DavisCanadian Institutes of Health ResearchUniversity of California, Los AngelesNational Institutes of HealthUniversity of California, San FranciscoAlzheimer SocietyUniversity of South FloridaNational Alzheimer's Coordinating CenterNational Institute on Minority Health and Health DisparitiesUSF Health Byrd Alzheimer's InstituteJohns Hopkins UniversityUniversity of WashingtonUniversity of MiamiYork UniversityNorthwestern UniversityCleveland ClinicEmory UniversityUniversity of PennsylvaniaVanderbilt UniversityChildren's Hospital of PhiladelphiaRush UniversityUniversity of California, San DiegoOffice of Research and DevelopmentU.S. Department of Veterans AffairsHope Center for Neurological DisordersWellcome TrustUniversity of Southern CaliforniaMassachusetts General HospitalGlaxoSmithKlineNational Institute of Neurological Disorders and StrokeUniversity of PittsburghUniversity of Colorado School of Medicine, Anschutz Medical CampusAlzheimer's Association
KeywordsRuns of HomozygosityGeneticsSingle-nucleotide polymorphismGenotypeSNPBiologyGenome-wide association studyInbreedingPopulationAlleleGenetic associationDiseaseAllele frequencyLocus (genetics)MedicineGeneInternal medicine

Abstract

fetched live from OpenAlex

IMPORTANCE: Mutations in known causal Alzheimer disease (AD) genes account for only 1% to 3% of patients and almost all are dominantly inherited. Recessive inheritance of complex phenotypes can be linked to long (>1-megabase [Mb]) runs of homozygosity (ROHs) detectable by single-nucleotide polymorphism (SNP) arrays. OBJECTIVE: To evaluate the association between ROHs and AD in an African American population known to have a risk for AD up to 3 times higher than white individuals. DESIGN, SETTING, AND PARTICIPANTS: Case-control study of a large African American data set previously genotyped on different genome-wide SNP arrays conducted from December 2013 to January 2015. Global and locus-based ROH measurements were analyzed using raw or imputed genotype data. We studied the raw genotypes from 2 case-control subsets grouped based on SNP array: Alzheimer's Disease Genetics Consortium data set (871 cases and 1620 control individuals) and Chicago Health and Aging Project-Indianapolis Ibadan Dementia Study data set (279 cases and 1367 control individuals). We then examined the entire data set using imputed genotypes from 1917 cases and 3858 control individuals. MAIN OUTCOMES AND MEASURES: The ROHs larger than 1 Mb, 2 Mb, or 3 Mb were investigated separately for global burden evaluation, consensus regions, and gene-based analyses. RESULTS: The African American cohort had a low degree of inbreeding (F ~ 0.006). In the Alzheimer's Disease Genetics Consortium data set, we detected a significantly higher proportion of cases with ROHs greater than 2 Mb (P = .004) or greater than 3 Mb (P = .02), as well as a significant 114-kilobase consensus region on chr4q31.3 (empirical P value 2 = .04; ROHs >2 Mb). In the Chicago Health and Aging Project-Indianapolis Ibadan Dementia Study data set, we identified a significant 202-kilobase consensus region on Chr15q24.1 (empirical P value 2 = .02; ROHs >1 Mb) and a cluster of 13 significant genes on Chr3p21.31 (empirical P value 2 = .03; ROHs >3 Mb). A total of 43 of 49 nominally significant genes common for both data sets also mapped to Chr3p21.31. Analyses of imputed SNP data from the entire data set confirmed the association of AD with global ROH measurements (12.38 ROHs >1 Mb in cases vs 12.11 in controls; 2.986 Mb average size of ROHs >2 Mb in cases vs 2.889 Mb in controls; and 22% of cases with ROHs >3 Mb vs 19% of controls) and a gene-cluster on Chr3p21.31 (empirical P value 2 = .006-.04; ROHs >3 Mb). Also, we detected a significant association between AD and CLDN17 (empirical P value 2 = .01; ROHs >1 Mb), encoding a protein from the Claudin family, members of which were previously suggested as AD biomarkers. CONCLUSIONS AND RELEVANCE: To our knowledge, we discovered the first evidence of increased burden of ROHs among patients with AD from an outbred African American population, which could reflect either the cumulative effect of multiple ROHs to AD or the contribution of specific loci harboring recessive mutations and risk haplotypes in a subset of patients. Sequencing is required to uncover AD variants in these individuals.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.005
Threshold uncertainty score0.444

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.025
GPT teacher head0.292
Teacher spread0.267 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it