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Record W2000852463 · doi:10.1136/bjo.87.5.633-a

Predictive DNA testing in ophthalmology: View 1

2003· letter· en· W2000852463 on OpenAlexafffund
E. Héon

Bibliographic record

VenueBritish Journal of Ophthalmology · 2003
Typeletter
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicRetinal Development and Disorders
Canadian institutionsUniversity Health NetworkHospital for Sick ChildrenUniversity of TorontoSickKids Foundation
FundersHospital for Sick ChildrenUniversity of TorontoUniversity Health Network
KeywordsMedicineOphthalmologyOptometry

Abstract

fetched live from OpenAlex

This family appears to have an early onset autosomal dominant (AD) RP. There is male to male transmission, which excludes X linked RP.1 Although the man‘s father was diagnosed at an older age this may be because the family was unaware of RP at that time. Once the family is aware of the condition and its presenting symptoms they may present earlier, as would appear to be the case with the girl in question. At age 4 years it is unlikely that there would be any abnormality detected on fundus examination. There are at least 13 genes that cause ADRP. These are listed in Table 1. An updated listing of retinal dystrophy genes is available on RetNet (http://www.sph.uth.tmc.edu/Retnet/home.htm) and OMIM (http://www3.ncbi.nlm.nih.gov/Omim/searchomim.html). View this table: Table 1 Retinitis pigmentosa, autosomal dominant Different approaches can be used to determine the genetic background of a disease depending on the type of samples available. When a family with several affected individuals is available, linkage analysis can be used to include or exclude gene loci of interest. Otherwise, for the more common scenario of sporadic cases, mutational analysis of candidate genes is used. ### Linkage analysis If several family members are available for testing and motivated, then a linkage analysis could be performed for the known loci. Definitely unaffected family members are also useful for this analysis. With just three affected members, it may not be possible to be certain which gene is …

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.001
metaresearch head score (Gemma)0.001
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMeta-epidemiology (narrow), Research integrity
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Case report · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.608
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0010.001
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0010.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0010.000
Research integrity0.0010.002
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.023
GPT teacher head0.264
Teacher spread0.241 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

Study designCase report
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations2
Published2003
Admission routes2
Has abstractyes

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