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Record W2015691301 · doi:10.1017/s0317167100007940

Adult-Type Metachromatic Leukodystrophy Mimicking Multiple Sclerosis

2009· article· fr· W2015691301 on OpenAlexvenueno aff
S. Chebel, Ilhem Barboura, A. Boughammoura-Bouatay, Manel Ammar, Salima Ferchichi, Abdelhédi Miled, Mahbouba Frih-Ayed

Bibliographic record

VenueCanadian Journal of Neurological Sciences / Journal Canadien des Sciences Neurologiques · 2009
Typearticle
Languagefr
FieldBiochemistry, Genetics and Molecular Biology
TopicRNA regulation and disease
Canadian institutionsnot available
Fundersnot available
KeywordsMetachromatic leukodystrophyMultiple sclerosisLeukodystrophyMedicineNeurosciencePathologyPsychologyDiseaseImmunology

Abstract

fetched live from OpenAlex

Metachromatic leukodystrophy (MLD) is an autosomal recessive lysosomal storage disease caused by a deficiency of arylsulphatase A (ASA).It is characterized by accumulation of sulphatide in the white matter in the central nervous system and peripheral nerves 1 .The disease is divided in four subtypes, according to onset, severity and progression of the disease: late infantile (before age 4), early juvenile (age 4 to 6), late juvenile (age 6 to 16) and adult-type (after age 16) 1 .The disorder has different clinical presentations depending on the age at onset.Most patients with adult-type MLD present psychiatric symptoms and a schizophrenia-like condition 2,3 .More recent reports indicate that dementia together with pure neurological symptoms are also prominent [3][4][5] .Before examination by magnetic resonance imaging (MRI) or ASA activity dosage, the patients are often misdiagnosed as having schizophrenia, affective disorder, or personality disorder.We report a patient with an adult-type MLD, in which the clinical course and neuroimaging results could suggest the diagnosis of multiple sclerosis (MS). CASE REPORTA 44-year-old woman presented a history of primary sterility.There were no family history of neurological or mental disease, nor had she had any previous episodes of neurotrauma or infection.The patient worked as a medical secretary.She was initially seen at the age of 18 years because of two episodes of generalized tonic and clonic seizures treated with Phenobarbital and patient was seizures-free since this date.In December 2003, the patient gradually developed a lack of interest, social withdrawal, blunted affect and she could not take care of her home and work.She showed signs of inappropriate giggling.In May 2005, when she first visited our department she became untidy and disinhibited.She lost depth of feeling and had no insight into her illness.She was less worried and had the feeling of euphoria.She had difficulty with abstract thinking and problem solving.At any time of the disease evolution, there was no hallucination or paranoid delusion and neither had she had any episodes of visual, or sensory nor motor disturbances.Neurological examination showed pyramidal features in all limbs without paresis (she had brisk reflexes in four limbs with bilateral Babinski sign).Cranial nerves examination, cerebellar, sensory, and gallbladder functions were all normal.Ophthalmologic examination and ocular funds were also normal.On the mini mental state examination, she scored 13 (perfect score: 30).

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.001
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Case report · Consensus signal: Case report
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.003
Threshold uncertainty score0.011

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.001
Meta-epidemiology (narrow)0.0010.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0010.001
Science and technology studies0.0000.000
Scholarly communication0.0000.001
Open science0.0000.001
Research integrity0.0010.001
Insufficient payload (model declined to judge)0.0030.001

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.037
GPT teacher head0.254
Teacher spread0.217 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designCase report
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations9
Published2009
Admission routes1
Has abstractyes

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