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Record W2102843554 · doi:10.1212/wnl.0b013e3182a8237e

Anterior brain glucose hypometabolism predates dementia in progranulin mutation carriers

2013· article· en· W2102843554 on OpenAlexfundno aff
Claudia Jacova, Ging‐Yuek Robin Hsiung, Itthipol Tawankanjanachot, Katie Dinelle, Siobhan McCormick, Marjorie Gonzalez, Hyunsoo Lee, Pheth Sengdy, Phoenix Bouchard‐Kerr, Matthew Baker, Rosa Rademakers, Vesna Sossi, A. Jon Stoessl, Howard Feldman, Ian R. Mackenzie

Bibliographic record

VenueNeurology · 2013
Typearticle
Languageen
FieldMedicine
TopicAmyotrophic Lateral Sclerosis Research
Canadian institutionsnot available
FundersNational Institute of Neurological Disorders and StrokeAlzheimer Society of ManitobaFidelity BiosciencesCanadian Institutes of Health ResearchMinistry of Health, British ColumbiaKyowa Hakko KirinAssociation for Frontotemporal DegenerationNational Institutes of HealthCanada Research ChairsAlzheimer SocietyFondation pour la Recherche sur AlzheimerParkinson Study GroupCurePSPF. Hoffmann-La RocheMassachusetts General HospitalTeva Pharmaceutical IndustriesYale UniversityPfizerBiogenALS Therapy AllianceAlzheimer Society of B.C.GenentechEli Lilly and CompanyBristol-Myers SquibbMichael J. Fox Foundation for Parkinson's Research
KeywordsFrontotemporal dementiaPsychologyFluorodeoxyglucoseStatistical parametric mappingFrontotemporal lobar degenerationDementiaInternal medicineMedicineCardiologyPathologyNeurosciencePositron emission tomographyRadiologyMagnetic resonance imagingDisease

Abstract

fetched live from OpenAlex

OBJECTIVE: In this prospective cohort study, we investigated cerebral glucose metabolism reductions on [(18)F]-fluorodeoxyglucose (FDG)-PET in progranulin (GRN) mutation carriers prior to frontotemporal dementia (FTD) onset. METHODS: Nine mutation carriers (age 51.5 ± 13.5 years) and 11 noncarriers (age 52.7 ± 9.5 years) from 5 families with FTD due to GRN mutations underwent brain scanning with FDG-PET and MRI and clinical evaluation. Normalized FDG uptake values were calculated with reference to the pons. PET images were analyzed with regions of interest (ROI) and statistical parametric mapping (SPM) approaches. RESULTS: Compared with noncarriers, GRN mutation carriers had a lowered anterior-to-posterior (AP) ratio of FDG uptake (0.86 ± 0.09 vs 0.92 ± 0.05) and less left-right asymmetry, consistent with an overall pattern of right anterior cerebral hypometabolism. This pattern was observed regardless of whether they were deemed clinically symptomatic no dementia or asymptomatic. Individual ROIs with lowered FDG uptake included right anterior cingulate, insula, and gyrus rectus. SPM analysis supported and extended these findings, demonstrating abnormalities in the right and left medial frontal regions, right insular cortex, right precentral and middle frontal gyri, and right cerebellum. Right AP ratio was correlated with cognitive and clinical scores (modified Mini-Mental State Examination r = 0.74; Functional Rating Scale r = -0.73) but not age and years to estimated onset in mutation carriers. CONCLUSION: The frontotemporal lobar degenerative process associated with GRN mutations appears to begin many years prior to the average age at FTD onset (late 50s-early 60s). Right medial and ventral frontal cortex and insula may be affected in this process but the specific regional patterns associated with specific clinical variants remain to be elucidated.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.650
Threshold uncertainty score0.941

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0010.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.013
GPT teacher head0.276
Teacher spread0.262 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations90
Published2013
Admission routes1
Has abstractyes

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