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Record W2153738707 · doi:10.1212/wnl.59.8.1130

Inherited myoclonus-dystonia

2002· letter· en· W2153738707 on OpenAlexaff
Yoshiaki Furukawa, Ali H. Rajput

Bibliographic record

VenueNeurology · 2002
Typeletter
Languageen
FieldMedicine
TopicGlycogen Storage Diseases and Myoclonus
Canadian institutionsCentre for Addiction and Mental Health
Fundersnot available
KeywordsDystoniaMyoclonusGeneticsMedicineLocus (genetics)PsychologyPsychiatryBiologyGene

Abstract

fetched live from OpenAlex

Inherited myoclonus-dystonia (M-D)1 is a relatively new term used to describe patients diagnosed previously with “hereditary essential myoclonus” or “hereditary (alcohol-responsive) myoclonic dystonia”.1,2⇓ Clinical characteristics of this autosomal-dominant disorder (table 1) include myoclonic jerks affecting predominantly the neck, shoulders, and arms and dystonic symptoms, mainly torticollis and writer’s cramp. In addition to these involuntary movements, psychiatric problems (e.g., alcohol abuse, obsessive-compulsive disorder, and panic attacks) have often been noted in M-D families.3 View this table: Table 1 Clinical characteristics of inherited myoclonus-dystonia 1 Recently, Zimprich et al.3 identified five independent heterozygous loss-of-function mutations in the e-sarcoglycan ( SGCE ) gene (chromosome location, 7q21) in six German families with M-D. The sarcoglycans are transmembrane components of the dystrophin-glycoprotein complex, and mutations in four other known sarcoglycan genes have been found in patients with limb-girdle muscular dystrophy.4 Although many other M-D families have supported linkage to the locus on chromosome 7q21,3 in this issue of Neurology , Grimes et al.5 map a new locus for the disorder to a 17-cM region on chromosome 18p11 in a …

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Case report · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.009
Threshold uncertainty score0.029

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0010.001
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0090.001

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.022
GPT teacher head0.244
Teacher spread0.222 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designCase report
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations33
Published2002
Admission routes1
Has abstractyes

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