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Record W2309104237 · doi:10.1136/jmedgenet-2015-103529

No evidence that protein truncating variants in <i>BRIP1</i> are associated with breast cancer risk: implications for gene panel testing

2016· article· en· W2309104237 on OpenAlexaff
Douglas F. Easton, Fabienne Lesueur, Brennan Decker, Kyriaki Michailidou, Jun Li, Jamie Allen, Craig Luccarini, Karen A. Pooley, Mitul Shah, Manjeet K. Bolla, Joe Dennis, Jamil Ahmad, Ella R. Thompson, Francesca Damiola, Maroulio Pertesi, Catherine Voegele, Noura Mebirouk, Nivonirina Robinot, Geoffroy Durand, Nathalie Forey, Robert Luben, Shahana Ahmed, Kristiina Aittomäki, Hoda Anton‐Culver, Volker Arndt, Caroline Baynes, Matthias W. Beckman, Javier Benı́tez, David Van Den Berg, William J. Blot, Natalia Bogdanova, Stig E. Bojesen, Hermann Brenner, Jenny Chang‐Claude, Kee Seng Chia, Ji‐Yeob Choi, Don Conroy, Angela Cox, Simon S. Cross, Kamila Czene, Hatef Darabi, Peter Devilee, Mikael Eriksson, Peter A. Fasching, Jonine D. Figueroa, Henrik Flyger, Florentia Fostira, Montserrat García‐Closas, Graham G. Giles, Gord Glendon, Anna González‐Neira, Pascal Guénel, Christopher A. Haiman, Per Hall, Steven N. Hart, Mikael Hartman, Maartje J. Hooning, Chia‐Ni Hsiung, Hidemi Ito, Anna Jakubowska, Paul A. James, Esther M. John, Nichola Johnson, Michael E. Jones, Maria Kabisch, Daehee Kang, Veli‐Matti Kosma, Vessela Kristensen, Diether Lambrechts, Na Li, Annika Lindblom, Jirong Long, Artitaya Lophatananon, Jan Lubiński, Siranoush Manoukian, Sara Margolin, Keitaro Matsuo, Alfons Meindl, Gillian Mitchell, Kenneth Muir, Ines Nevelsteen, Ans van den Ouweland, Paolo Peterlongo, Sze Yee Phuah, Katri Pylkäs, Simone M. Rowley, Suleeporn Sangrajrang, Rita K. Schmutzler, Chen‐Yang Shen, Xiao‐Ou Shu, Melissa C. Southey, Harald Surowy, Anthony J. Swerdlow, Soo‐Hwang Teo, Rob A.�E.�M. Tollenaar, Ian Tomlinson, Diana Torres, Thérèse Truong, Celine M. Vachon, Senno Verhoef, Michelle W. Wong‐Brown, Wei Zheng, Ying Zheng, Heli Nevanlinna, Rodney J. Scott, Irene L. Andrulis, Anna H. Wu, John L. Hopper, Fergus J. Couch, Robert Winqvist, Barbara Burwinkel, Elinor J. Sawyer, Marjanka K. Schmidt, Anja Rudolph, Thilo Dörk, Hiltrud Brauch, Ute Hamann, Susan L. Neuhausen, Roger L. Milne, Olivia Fletcher, Paul D.P. Pharoah, Ian Campbell, Alison M. Dunning, Florence Le Calvez‐Kelm, Sean V. Tavtigian, Georgia Chenevix‐Trench

Bibliographic record

VenueJournal of Medical Genetics · 2016
Typearticle
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicBRCA gene mutations in cancer
Canadian institutionsUniversity of TorontoLunenfeld-Tanenbaum Research InstituteMount Sinai Hospital
FundersNational Institute for Health and Care ResearchWellcome TrustFrancis Crick InstituteNational Cancer InstituteCancer Research UKWorld Health Organization
KeywordsBreast cancerGeneticsMissense mutationOncologyAlleleMedicineInternal medicineBiologyCancerGeneMutation

Abstract

fetched live from OpenAlex

BACKGROUND: BRCA1 interacting protein C-terminal helicase 1 (BRIP1) is one of the Fanconi Anaemia Complementation (FANC) group family of DNA repair proteins. Biallelic mutations in BRIP1 are responsible for FANC group J, and previous studies have also suggested that rare protein truncating variants in BRIP1 are associated with an increased risk of breast cancer. These studies have led to inclusion of BRIP1 on targeted sequencing panels for breast cancer risk prediction. METHODS: We evaluated a truncating variant, p.Arg798Ter (rs137852986), and 10 missense variants of BRIP1, in 48 144 cases and 43 607 controls of European origin, drawn from 41 studies participating in the Breast Cancer Association Consortium (BCAC). Additionally, we sequenced the coding regions of BRIP1 in 13 213 cases and 5242 controls from the UK, 1313 cases and 1123 controls from three population-based studies as part of the Breast Cancer Family Registry, and 1853 familial cases and 2001 controls from Australia. RESULTS: The rare truncating allele of rs137852986 was observed in 23 cases and 18 controls in Europeans in BCAC (OR 1.09, 95% CI 0.58 to 2.03, p=0.79). Truncating variants were found in the sequencing studies in 34 cases (0.21%) and 19 controls (0.23%) (combined OR 0.90, 95% CI 0.48 to 1.70, p=0.75). CONCLUSIONS: These results suggest that truncating variants in BRIP1, and in particular p.Arg798Ter, are not associated with a substantial increase in breast cancer risk. Such observations have important implications for the reporting of results from breast cancer screening panels.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.001
metaresearch head score (Gemma)0.005
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.522
Threshold uncertainty score0.596

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0010.005
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.058
GPT teacher head0.317
Teacher spread0.259 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations104
Published2016
Admission routes1
Has abstractyes

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