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Record W2781802334 · doi:10.5334/jbr-btr.1439

Fahr’s Syndrome in a Greenlandic Inuit

2018· article· en· W2781802334 on OpenAlexaboutno aff
Anne Toftgaard Pedersen, Ida Kledal, Luit Penninga

Bibliographic record

VenueJournal of the Belgian Society of Radiology · 2018
Typearticle
Languageen
FieldMedicine
TopicThyroid and Parathyroid Surgery
Canadian institutionsnot available
Fundersnot available
KeywordsMedicinePediatrics

Abstract

fetched live from OpenAlex

Fahr's disease or syndrome is a rare inherited or sporadic neurological disorder with a prevalence of less than 1/1,000,000 [1].Recently, a number of genes have been identified, known to be associated with familial primary brain calcification (PFBC), causing Fahr's disease or syndrome [1].These genes are SCL20A2, PDGFB, PDGFRB and XPR1, and a significant correlation was found between the presence of headache in PDGFB mutations, and parkinsonism with SLC20A2 [2].We present the case of a 49-year-old woman with Greenlandic Inuit origin and an otherwise unremarkable medical history.She initially presented with symptoms of headache and diplopia.She was referred to a CT scan of the cerebrum, which showed bilateral calcifications of the thalamus and corpus striatum (Figures 1 and2) compatible with Fahr's syndrome [1].Shortly after, the patient developed tremor of the right hand, fatigability especially of her right side, dizziness, and minor cognitive decline.Laboratory studies showed no metabolic disorders such as hypopituitarism, parathyroid disturbances or significant changes in the calcium-phosphate metabolism, besides a minimal hypocalcaemia (free calcium: 1.12 mmol/L, reference 1.17-1.34mmol/L), which was interpreted as secondary to D-vitamin deficiency (13 nmol/L), very common in the arctic region.No other primary cause for brain calcification was detected, and the patient has a younger sister, who is also diagnosed with Fahr's syndrome, suggestive of an inherited type.The present case shows that symptoms of Fahr's syndrome may be few.Furthermore, this exemplifies that neurological manifestations may be confined to one side of the body, despite the presence of bilateral calcifications [1].This case illustrates the importance of neuroimaging for establishing the diagnosis.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.001
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.395
Threshold uncertainty score0.270

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0010.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0010.001
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.015
GPT teacher head0.262
Teacher spread0.247 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations1
Published2018
Admission routes1
Has abstractyes

Explore more

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