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Record W2806304256 · doi:10.2217/ebo.12.330

Current specific enzyme therapies

2013· other· en· W2806304256 on OpenAlexaff
Can Fıçıcıoğlu, Paige Kaplan

Bibliographic record

Venuenot available
Typeother
Languageen
FieldMedicine
TopicLysosomal Storage Disorders Research
Canadian institutionsNewborn Screening Ontario
Fundersnot available
KeywordsGlucocerebrosideGlucocerebrosidaseEnzyme replacement therapyMedicineMucopolysaccharidosisCHOPSubstrate reduction therapyDiseasePediatricsInternal medicineChemotherapy

Abstract

fetched live from OpenAlex

Gaucher disease, the most common lysosomal storage disorder, is caused by the deficiency of glucocerebrosidase, which catalyzes the breakdown of glucocerebroside into glucose and ceramide. The accumulation of glucocerebroside in macrophages causes dysfunction in multiple organ systems [1]. Supplementation of the deficient enzyme by intravenous administration of recombinant glucocerebrosidase acts like the naturally occurring enzyme to break down the glucocerebroside accumulated in Gaucher cells, and has been shown to be effective and safe [1]. Enzyme replacement therapy (ERT) is the mainstay of therapy for Gaucher disease type 1. In symptomatic children with Gaucher disease types 2 or 3, early ERT may prevent the development of serious, and disabling somatic, but not neurologic complications due to the inability of ERT compounds to cross the blood–brain barrier into the CNS [1]. Lifelong intravenous infusion every 2–4 weeks can be a burden for some patients, particularly in those with poor venous access. The high cost of ERT also makes its use suboptimal or impossible in some countries, and burdens healthcare costs.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.001
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Not applicable · Consensus signal: none
GenreCandidate signal: Other · Consensus signal: Other
Teacher disagreement score0.097
Threshold uncertainty score0.323

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.001
Meta-epidemiology (narrow)0.0010.000
Meta-epidemiology (broad)0.0010.001
Bibliometrics0.0010.001
Science and technology studies0.0000.000
Scholarly communication0.0010.001
Open science0.0010.001
Research integrity0.0010.002
Insufficient payload (model declined to judge)0.0970.056

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.039
GPT teacher head0.321
Teacher spread0.281 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designNot applicable
Domainnot available
GenreOther

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations0
Published2013
Admission routes1
Has abstractyes

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Same topicLysosomal Storage Disorders ResearchFrench-language works237,207