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Record W2838749151 · doi:10.4158/accr-2018-0146

Case Report of Bilateral Pheochromocytomas due to a Novel Max Mutation in a Patient Known to have a Pituitary Prolactinoma

2018· article· en· W2838749151 on OpenAlexaff
Alexandra Kobza, Stephanie Dizon, Amel Arnaout

Bibliographic record

VenueAACE Clinical Case Reports · 2018
Typearticle
Languageen
FieldMedicine
TopicAdrenal and Paraganglionic Tumors
Canadian institutionsOttawa Hospital
Fundersnot available
KeywordsPheochromocytomaMedicineProlactinomaCabergolineNormetanephrinePituitary adenomaAcromegalyEndocrinologyInternal medicineGermline mutationMetanephrinesReference rangeGastroenterologyAdenomaUrologyPathologyMutationHormoneGeneticsBiologyProlactinGene

Abstract

fetched live from OpenAlex

Objective: To report on a patient with a known pituitary prolactinoma also found to have bilateral pheochromocytomas due to a novel germline MAX (MYC-associated factor X) gene mutation. Methods: Case report and literature review. Results: This patient was a 39-year-old female who presented with a 2-year history of episodes of sweating, palpitations, and elevated blood pressure. She had no family history of pheochromocytoma or paraganglioma syndromes. Her past medical history was significant for a pituitary prolactinoma diagnosed 6 years prior and well controlled with cabergoline. Bloodwork showed serum normetanephrine at 6,238 pg/mL (reference range, <148 pg/mL), serum metanephrine at 388 pg/mL (reference range, <57 pg/mL), and parathyroid hormone at 69.8 pg/mL (reference range, 10 to 65 pg/mL). Imaging revealed bilateral adrenal masses with significant uptake on nuclear imaging. Genetic testing was positive for a novel germline MAX gene mutation at c.171+2T>A. Bilateral adrenalectomy normalized all bloodwork and symptoms. Conclusion: To our knowledge, this is the fifth reported case of an association between a pheochromocytoma and pituitary adenoma—three with a prolactinoma and two with acromegaly—in patients with a germline MAX mutation. This supports the possibility of a MAX gene mutation being the cause for a syndromic disease. Abbreviations: MAX = MYC-associated factor X; MIBG = metaiodobenzylguanidine; PCC = pheochromocytoma; PGL = paraganglioma; TH = parathyroid hormone; SDH = succinate dehydrogenase

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.002
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Case report · Consensus signal: Case report
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.005
Threshold uncertainty score0.012

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.002
Meta-epidemiology (narrow)0.0020.001
Meta-epidemiology (broad)0.0010.001
Bibliometrics0.0020.001
Science and technology studies0.0020.001
Scholarly communication0.0020.002
Open science0.0010.002
Research integrity0.0050.002
Insufficient payload (model declined to judge)0.0040.001

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.052
GPT teacher head0.371
Teacher spread0.319 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designCase report
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations19
Published2018
Admission routes1
Has abstractyes

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