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Record W2924785753 · doi:10.1212/nxg.0000000000000317

Somatic expansion of the <i>C9orf72</i> hexanucleotide repeat does not occur in ALS spinal cord tissues

2019· article· de· W2924785753 on OpenAlex
Jay P. Ross, Claire S. Leblond, Hélène Catoire, Kathryn Volkening, Michael J. Strong, Lorne Zinman, Janice Robertson, Patrick A. Dion, Guy A. Rouleau

Why this work is in the frame

A frame that forgets how it found something cannot be audited. These are the routes that admitted this work.

affAt least one author lists a Canadian institution in the pinned OpenAlex snapshot.
fundA Canadian funder is recorded on the work.

Bibliographic record

VenueNeurology Genetics · 2019
Typearticle
Languagede
FieldMedicine
TopicAmyotrophic Lateral Sclerosis Research
Canadian institutionsHealth Sciences CentreSunnybrook Health Science CentreOccupational Cancer Research CentreMontreal Neurological Institute and Hospital
FundersSchulich School of Medicine and DentistryUniversity of TorontoMcGill University
KeywordsC9orf72Amyotrophic lateral sclerosisBiologyTrinucleotide repeat expansionSpinal cordSomatic cellAnatomyGeneticsPathologyMedicineGeneNeuroscienceDisease

Abstract

fetched live from OpenAlex

<h3>Objective</h3> To test for somatic <i>C9orf72</i> hexanucleotide repeat expansion (HRE) and hexanucleotide repeat length instability in the spinal cord of amyotrophic lateral sclerosis (ALS) cases. <h3>Methods</h3> Whole and partial spinal cords of 19 ALS cases were dissected into transversal sections (5 mm thick). The presence of <i>C9orf72</i> HRE was tested in each independent section using RepeatPrimed PCR and amplicon-size genotyping. Index measures for the testing of mosaicism were obtained through serial dilutions of genomic DNA from an individual carrying a germline <i>C9orf72</i> HRE in the genomic DNA of an individual without a <i>C9orf72</i> HRE. <h3>Results</h3> None of the sections examined supported the presence of a subpopulation of cells with a <i>C9orf72</i> HRE. Moreover, the <i>C9orf72</i> hexanucleotide repeat lengths measured were identical across all the spinal cord sections of each individual patient. <h3>Conclusions</h3> We did not observe somatic instability of the <i>C9orf72</i> HRE in disease relevant tissues of ALS cases.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.001
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMeta-epidemiology (narrow)
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.348
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0010.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0010.000
Bibliometrics0.0000.000
Science and technology studies0.0000.001
Scholarly communication0.0000.000
Open science0.0010.001
Research integrity0.0000.001
Insufficient payload (model declined to judge)0.0010.001

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.027
GPT teacher head0.307
Teacher spread0.281 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it