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Record W2943293482 · doi:10.1164/rccm.201810-1891oc

Resequencing Study Confirms That Host Defense and Cell Senescence Gene Variants Contribute to the Risk of Idiopathic Pulmonary Fibrosis

2019· article· en· W2943293482 on OpenAlexaff
Camille M. Moore, Rachel Z. Blumhagen, Ivana V. Yang, Avram Walts, Julie Powers, Tarik Walker, Makenna Bishop, Pamela Russell, Brian Vestal, Jonathan Cardwell, Cheryl Markin, Susan Mathai, Marvin I. Schwarz, Mark P. Steele, Joyce Lee, Kevin K. Brown, James E. Loyd, James D. Crapo, Edwin K. Silverman, Michael H. Cho, Judith A. James, Joel M. Guthridge, Joy D. Cogan, Jonathan A. Kropski, Jeffrey J. Swigris, Carol Bair, Dong Soon Kim, Wonjun Ji, Jin Woo Song, Lisa A. Maier, Karin Pacheco, Nikhil Hirani, Azin Poon, Feng Li, Gísli Jenkins, Rebecca Braybrooke, Gauri Saini, Toby M. Maher, Philip L. Molyneaux, Peter Saunders, Yingze Zhang, Kevin F. Gibson, Daniel J. Kass, Mauricio Rojas, John Sembrat, Paul J. Wolters, Harold R. Collard, John S. Sundy, Thomas G. O’Riordan, Mary E. Strek, Imre Noth, Shwu‐Fan Ma, Mary K. Porteous, Maryl Kreider, Namrata Patel, Yoshikazu Inoue, Masaki Hirose, Toru Arai, Shinobu Akagawa, Oliver Eickelberg, Isis E. Fernandez, Jürgen Behr, Nesrin Moğulkoç, Tamera J. Corte, Ian Glaspole, Sara Tomassetti, Claudia Ravaglia, Venerino Poletti, Bruno Crestani, Raphaël Borie, Caroline Kannengiesser, Helen Parfrey, Christine Fiddler, Doris M. Rassl, María Molina‐Molina, Carlos Machahua, Ana Montes Worboys, Gunnar Guðmundsson, Helgi J. Ísaksson, David J. Lederer, Anna J. Podolanczuk, Sydney B. Montesi, Elisabeth Bendstrup, Vivi Danchel, Moisés Selman, Annie Pardo, Michael T. Henry, Michael P. Keane, Peter Doran, Martina Vašáková, Martina Šterclová, Christopher J. Ryerson, Pearce Wilcox, Tsukasa Okamoto, Haruhiko Furusawa, Yasunari Miyazaki, Geoffrey J. Laurent, Svetlana Baltic, Cecilia M. Prêle, Yuben Moodley, Barry S. Shea, Ken Ohta, Maho Suzukawa, Osamu Narumoto, Steven D. Nathan, D. Venuto, Merte Lemma Woldehanna, Nurdan Köktürk, João A. de Andrade, Tracy Luckhardt, Tejaswini Kulkarni, Francesco Bonella, Seamus Donnelly, Aoife McElroy, Michelle E. Armstong, Alvaro U. Aranda, Roberto G. Carbone, Francesco Puppo, Kenneth B. Beckman, Deborah A. Nickerson, Tasha E. Fingerlin, David A. Schwartz

Bibliographic record

VenueAmerican Journal of Respiratory and Critical Care Medicine · 2019
Typearticle
Languageen
FieldMedicine
TopicInterstitial Lung Diseases and Idiopathic Pulmonary Fibrosis
Canadian institutionsUniversity of British Columbia
FundersNational Center for Research ResourcesNational Institute for Health and Care ResearchNational Institute of General Medical SciencesNational Institute of Arthritis and Musculoskeletal and Skin DiseasesNational Institute of Allergy and Infectious DiseasesMedical Research CouncilAstraZenecaNational Heart, Lung, and Blood InstitutePfizerU.S. Department of Veterans AffairsCOPD FoundationGlaxoSmithKlineSunovionU.S. Department of Defense
KeywordsOdds ratioIdiopathic pulmonary fibrosisMedicineAlleleCase-control studyGeneticsGenetic variationConfidence intervalDiseaseGenetic associationGenotypeGenome-wide association studyGeneBioinformaticsBiologyInternal medicineSingle-nucleotide polymorphismLung

Abstract

fetched live from OpenAlex

Abstract Rationale Several common and rare genetic variants have been associated with idiopathic pulmonary fibrosis, a progressive fibrotic condition that is localized to the lung. Objectives To develop an integrated understanding of the rare and common variants located in multiple loci that have been reported to contribute to the risk of disease. Methods We performed deep targeted resequencing (3.69 Mb of DNA) in cases (n = 3,624) and control subjects (n = 4,442) across genes and regions previously associated with disease. We tested for associations between disease and 1) individual common variants via logistic regression and 2) groups of rare variants via sequence kernel association tests. Measurements and Main Results Statistically significant common variant association signals occurred in all 10 of the regions chosen based on genome-wide association studies. The strongest risk variant is the MUC5B promoter variant rs35705950, with an odds ratio of 5.45 (95% confidence interval, 4.91–6.06) for one copy of the risk allele and 18.68 (95% confidence interval, 13.34–26.17) for two copies of the risk allele (P = 9.60 × 10−295). In addition to identifying for the first time that rare variation in FAM13A is associated with disease, we confirmed the role of rare variation in the TERT and RTEL1 gene regions in the risk of IPF, and found that the FAM13A and TERT regions have independent common and rare variant signals. Conclusions A limited number of common and rare variants contribute to the risk of idiopathic pulmonary fibrosis in each of the resequencing regions, and these genetic variants focus on biological mechanisms of host defense and cell senescence.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.001
metaresearch head score (Gemma)0.002
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.002
Threshold uncertainty score0.007

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0010.002
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.001
Bibliometrics0.0010.001
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0010.001
Insufficient payload (model declined to judge)0.0020.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.014
GPT teacher head0.277
Teacher spread0.264 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

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Citations114
Published2019
Admission routes1
Has abstractyes

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