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Genetics of the Pathophysiology of Retinoblastoma

2018· other· en· W2944661722 on OpenAlexaff
Dietmar Lohmann, Brenda L. Gallie

Bibliographic record

VenueEncyclopedia of Life Sciences · 2018
Typeother
Languageen
FieldMedicine
TopicOcular Oncology and Treatments
Canadian institutionsUniversity of Toronto
Fundersnot available
KeywordsRetinoblastomaPenetranceAlleleBiologyGeneticsGermlinePhenotypeVariable ExpressionGermline mutationGeneCancer researchMutation

Abstract

fetched live from OpenAlex

Abstract Retinoblastoma is a malignant tumour that originates from cone precursors of the developing retina and is usually diagnosed in children under age of 5 years. This tumour emerges from cells with inactivating alterations of both alleles of the tumour suppressor gene RB1 . In nonheritable retinoblastoma, these two alterations have occurred in somatic cells and are not passed to offspring. Variant alleles of the RB1 gene transmitted via the germline cause heritable predisposition to retinoblastoma and some other neoplasms (second cancers). In families, this trait shows autosomal dominant inheritance with variable phenotypic expression and incomplete penetrance. Analysis of genotype–phenotype associations has shown that the mean number of tumour foci that develop in carriers of mutant RB1 alleles varies depending on which, and to what extent the mutant allele has retained functions of the normal allele. The RB1 gene product, pRb, has a role in several cellular processes. One of its functions is to be a gatekeeper that negatively regulates progression through G 1 phase of the cell cycle. The RB1 gene is imprinted and this may explain some of the observed parent‐of‐origin effects. Key Concepts Two‐step inactivation of the retinoblastoma gene ( RB1 ) is a prerequisite for the development of retinoblastoma. Germ‐line variants in the RB1 gene can cause heritable retinoblastoma that is transmitted as an autosomal dominant trait with incomplete penetrance and variable expressivity. Variable phenotypic expression of heritable retinoblastoma is in part explained by allelic heterogeneity of RB1 gene variants. In patients with nonheritable retinoblastoma, the two alleles of the retinoblastoma gene are inactivated by somatic mutations. The human RB1 gene is imprinted with skewed expression in favour of the maternal allele.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Not applicable · Consensus signal: none
GenreCandidate signal: Other · Consensus signal: Other
Teacher disagreement score0.314
Threshold uncertainty score0.946

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.002
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0010.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.013
GPT teacher head0.283
Teacher spread0.270 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designNot applicable
Domainnot available
GenreOther

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations2
Published2018
Admission routes1
Has abstractyes

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