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Record W2953877276 · doi:10.1016/j.jalz.2019.04.007

Individualized atrophy scores predict dementia onset in familial frontotemporal lobar degeneration

2019· article· en· W2953877276 on OpenAlexafffund
Adam M. Staffaroni, Yann Cobigo, Sheng‐Yang M. Goh, John Kornak, Lynn Bajorek, Kevin Chiang, Brian S. Appleby, Jessica Bove, Yvette Bordelon, Patrick Brannelly, Danielle Brushaber, Christina Caso, Giovanni Coppola, Reilly Dever, Christina Dheel, Bradford C. Dickerson, Susan Dickinson, S. Carbajal Domínguez, Kimiko Domoto‐Reilly, Kelly Faber, Jessica Ferrall, Julie A. Fields, Ann Fishman, Jamie Fong, Tatiana Foroud, Leah K. Forsberg, Ralitza H. Gavrilova, Debra Gearhart, Behnaz Ghazanfari, Nupur Ghoshal, Jill Goldman, Jonathan Graff‐Radford, Neill R. Graff‐Radford, Ian Grant, Murray Grossman, Dana Haley, Hilary W. Heuer, Ging‐Yuek Robin Hsiung, Edward D. Huey, David J. Irwin, David T. Jones, Lynne C. Jones, Kejal Kantarci, Anna Karydas, Daniel Kaufer, Diana Kerwin, David S. Knopman, Ruth Kraft, Joel H. Kramer, Walter K. Kremers, Walter A. Kukull, Irene Litvan, Peter A. Ljubenkov, Diane Lucente, Codrin Lungu, Ian R. Mackenzie, Miranda Maldonado, Masood Manoochehri, Scott M. McGinnis, Emily McKinley, Mario F. Mendez, Bruce L. Miller, Namita Multani, Chiadi U. Onyike, Jaya Padmanabhan, Alexander Pantelyat, Rodney Pearlman, Len Petrucelli, Madeline Potter, Rosa Rademakers, Eliana Marisa Ramos, Katherine P. Rankin, Katya Rascovsky, Erik D. Roberson, Emily Rogalskı, Pheth Sengdy, Leslie M. Shaw, Jeremy A. Syrjanen, Maria Carmela Tartaglia, Nadine Tatton, Joanne Taylor, Arthur W. Toga, John Q. Trojanowski, Sandra Weıntraub, Ping Wang, Bonnie Wong, Zbigniew K. Wszołek, Adam L. Boxer, Bradley F. Boeve, Howard J. Rosen

Bibliographic record

VenueAlzheimer s & Dementia · 2019
Typearticle
Languageen
FieldMedicine
TopicDementia and Cognitive Impairment Research
Canadian institutionsUniversity of British ColumbiaUniversity of Toronto
FundersNational Institute of Neurological Disorders and StrokeNational Institute on AgingJanssen PharmaceuticalsAlzheimer Society of B.C.Canadian Institutes of Health ResearchAvid RadiopharmaceuticalsUniversity of California, San DiegoAssociation for Frontotemporal DegenerationNational Institutes of HealthEisaiLittle Family FoundationNew York State Department of HealthUniversity of PennsylvaniaUniversity of Southern CaliforniaAlzheimer's Drug Discovery FoundationParkinsonfondenUniversity of California, San FranciscoAlzheimer SocietyU.S. Department of DefenseBrightFocus FoundationEli Lilly and CompanyTau ConsortiumBristol-Myers SquibbAllerganAstraZenecaGenentechLarry L. Hillblom FoundationTauRx PharmaceuticalsSol Goldman Charitable TrustIonis PharmaceuticalsAlzheimer's AssociationPfizerBiogenMayo ClinicAmgen
KeywordsFrontotemporal lobar degenerationFrontotemporal dementiaMedicineAtrophyDementiaPediatricsNeurosciencePathologyPsychologyDisease

Abstract

fetched live from OpenAlex

INTRODUCTION: Some models of therapy for neurodegenerative diseases envision starting treatment before symptoms develop. Demonstrating that such treatments are effective requires accurate knowledge of when symptoms would have started without treatment. Familial frontotemporal lobar degeneration offers a unique opportunity to develop predictors of symptom onset. METHODS: We created dementia risk scores in 268 familial frontotemporal lobar degeneration family members by entering covariate-adjusted standardized estimates of brain atrophy into a logistic regression to classify asymptomatic versus demented participants. The score's predictive value was tested in a separate group who were followed up longitudinally (stable vs. converted to dementia) using Cox proportional regressions with dementia risk score as the predictor. RESULTS: Cross-validated logistic regression achieved good separation of asymptomatic versus demented (accuracy = 90%, SE = 0.06). Atrophy scores predicted conversion from asymptomatic or mildly/questionably symptomatic to dementia (HR = 1.51, 95% CI: [1.16,1.98]). DISCUSSION: Individualized quantification of baseline brain atrophy is a promising predictor of progression in asymptomatic familial frontotemporal lobar degeneration mutation carriers.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.001
metaresearch head score (Gemma)0.004
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.003
Threshold uncertainty score0.007

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0010.004
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0010.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0010.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.022
GPT teacher head0.295
Teacher spread0.273 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations40
Published2019
Admission routes2
Has abstractyes

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