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Record W2959335923 · doi:10.1212/nxg.0000000000000348

Genetic risk of Parkinson disease and progression:

2019· article· en· W2959335923 on OpenAlexfundno aff
Hirotaka Iwaki, Cornelis Blauwendraat, Hampton L. Leonard, Ganqiang Liu, Jodi Maple‐Grødem, Jean‐Christophe Corvol, Lasse Pihlstrøm, Marlies van Nimwegen, Samantha J. Hutten, Khanh‐Dung H. Nguyen, Jacqueline Rick, Shirley Eberly, Faraz Faghri, Peggy Auinger, Kirsten M. Scott, Ruwani Wijeyekoon, Vivianna M. Van Deerlin, Dena Hernández, Aaron Day-Williams, Alexis Brice, Guido Alves, Alastair J. Noyce, Ole‐Bjørn Tysnes, Jonathan Evans, David P. Breen, Karol Estrada, Claire Wegel, Fabrice Danjou, David K. Simon, Bernard Ravina, Mathias Toft, Peter Heutink, Bastiaan R. Bloem, Daniel Weintraub, Roger A. Barker, Caroline H. Williams‐Gray, Bart P. van de Warrenburg, Jacobus J. van Hilten, Clemens R. Scherzer, Andrew Singleton, Mike A. Nalls

Bibliographic record

VenueNeurology Genetics · 2019
Typearticle
Languageen
FieldMedicine
TopicParkinson's Disease Mechanisms and Treatments
Canadian institutionsnot available
FundersNational Center for Research ResourcesNational Human Genome Research InstituteNational Institute on AgingNIHR Cambridge Biomedical Research CentreHelse Sør-Øst RHFMedical Research CouncilParkinsonfondenAllerganNational Institutes of HealthVoyager TherapeuticsNational Institute for Health and Care ResearchAgence Nationale de Sécurité du Médicament et des Produits de SantéCentre National de la Recherche ScientifiqueEvelyn TrustIpsenFonds Wetenschappelijk OnderzoekAssociation France ParkinsonAssistance Publique - Hôpitaux de ParisInstitut National de la Santé et de la Recherche MédicaleBiogenAgence Nationale de la RechercheH. Lundbeck A/SRosetrees TrustParkinson's UKRadboud UniversiteitHersenstichtingVerily Life SciencesGlaxoSmithKlineBarts CharityJohns Hopkins UniversityAmarin CorporationMichael J. Fox Foundation for Parkinson's ResearchParkinson's FoundationKinetics FoundationWellcome TrustZonMwBritannia PharmaceuticalsWeston Brain InstituteNational Institute of Neurological Disorders and StrokeSunovionNorges ForskningsrådUniversity of VirginiaNational Parkinson FoundationEU Joint Programme – Neurodegenerative Disease ResearchPfizerUniversity of RochesterUniversity of PennsylvaniaBrown UniversityCHDI FoundationMassachusetts General HospitalSmart Family FoundationParkinson's Disease FoundationU.S. Department of DefenseOhio State UniversityHarvard NeuroDiscovery CenterParkinson VerenigingNasjonalforeningen for FolkehelsenUniversity of Michigan
KeywordsAlleleOdds ratioHazard ratioLRRK2GenotypeInternal medicineDiseaseGeneticsMedicineBiologyParkinson's diseaseConfidence intervalGene

Abstract

fetched live from OpenAlex

Objective To determine if any association between previously identified alleles that confer risk for Parkinson disease and variables measuring disease progression. Methods We evaluated the association between 31 risk variants and variables measuring disease progression. A total of 23,423 visits by 4,307 patients of European ancestry from 13 longitudinal cohorts in Europe, North America, and Australia were analyzed. Results We confirmed the importance of GBA on phenotypes. GBA variants were associated with the development of daytime sleepiness (p.N370S: hazard ratio [HR] 3.28 [1.69–6.34]) and possible REM sleep behavior (p.T408M: odds ratio 6.48 [2.04–20.60]). We also replicated previously reported associations of GBA variants with motor/cognitive declines. The other genotype-phenotype associations include an intergenic variant near LRRK2 and the faster development of motor symptom (Hoehn and Yahr scale 3.0 HR 1.33 [1.16–1.52] for the C allele of rs76904798) and an intronic variant in PMVK and the development of wearing-off effects (HR 1.66 [1.19–2.31] for the C allele of rs114138760). Age at onset was associated with TMEM175 variant p.M393T (−0.72 [−1.21 to −0.23] in years), the C allele of rs199347 (intronic region of GPNMB, 0.70 [0.27–1.14]), and G allele of rs1106180 (intronic region of CCDC62, 0.62 [0.21–1.03]). Conclusions This study provides evidence that alleles associated with Parkinson disease risk, in particular GBA variants, also contribute to the heterogeneity of multiple motor and nonmotor aspects. Accounting for genetic variability will be a useful factor in understanding disease course and in minimizing heterogeneity in clinical trials.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.001
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.006
Threshold uncertainty score0.011

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.001
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.001
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0010.001
Insufficient payload (model declined to judge)0.0030.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.010
GPT teacher head0.258
Teacher spread0.249 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations162
Published2019
Admission routes1
Has abstractyes

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