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Record W3113240410 · doi:10.1101/2020.12.14.20224378

Genome-wide association studies of LRRK2 modifiers of Parkinson's disease

2020· preprint· en· W3113240410 on OpenAlexafffund
Dongbing Lai, Babak Alipanahi, Pierre Fontanillas, Tae‐Hwi Schwantes‐An, Jan Aasly, Roy N. Alcalay, Gary W. Beecham, Daniela Berg, Susan Bressman, Alexis Brice, Lorraine N. Clark, Mark Cookson, Sayantan Das, Vivianna M. Van Deerlin, Matthew J. Farrer, Joanne Trinh, Thomas Gasser, Stefano Goldwurm, Emil K. Gustavsson, Christine Klein, Anthony E. Lang, William Langston, Jeanne C. Latourelle, Timothy Lynch, Karen Marder, Connie Marras, Eden R. Martin, Cory Y. McLean, Helen Mejia‐Santana, Eric Molho, Richard H. Myers, Karen Nuytemans, Laurie J. Ozelius, Haydeh Payami, Deborah Raymond, Ekaterina Rogaeva, Michael P. Rogers, Owen A. Ross, Ali Samii, Rachel Saunders‐Pullman, Birgitt Schüle, Claudia Schulte, William K. Scott, Caroline M. Tanner, Eduardo Tolosa, James E. Tomkins, Dolores Vilas, John Q. Trojanowski, Ryan J. Uitti, Jeffery M. Vance, Naomi P. Visanji, Zbigniew K. Wszołek, Cyrus P. Zabetian, Anat Mirelman, Nir Giladi, Avi Orr Urtreger, P. F. Cannon, Brian Fiske, Tatiana Foroud

Bibliographic record

VenuemedRxiv · 2020
Typepreprint
Languageen
FieldMedicine
TopicParkinson's Disease Mechanisms and Treatments
Canadian institutionsUniversity of TorontoOccupational Cancer Research CentreToronto Western HospitalUniversity of British Columbia
FundersNational Institute of Neurological Disorders and StrokeCanadian Institutes of Health ResearchMorsani College of MedicineSchool of Medicine, Stanford UniversityNational Institutes of HealthSorbonne UniversitéSt. Olavs Hospital Universitetssykehuset i TrondheimUniversitat de BarcelonaCentro de Investigación Biomédica en Red sobre Enfermedades NeurodegenerativasCentre National de la Recherche ScientifiqueInstitut National de la Santé et de la Recherche MédicaleDeutsche ForschungsgemeinschaftGoogleUniversity College DublinUniversity of ReadingClinical and Translational Science Institute, University of FloridaParkinson's FoundationLittle Family FoundationUniversity of PennsylvaniaWeston Brain InstituteEberhard Karls Universität TübingenJohns Hopkins UniversityUniversity of WashingtonCenter for Individualized Medicine, Mayo ClinicDeutsches Zentrum für Neurodegenerative ErkrankungenMcKnight FoundationUniversity of MiamiSol Goldman Charitable TrustAmerican Parkinson Disease AssociationOracleConsortium canadien en neurodégénérescence associée au vieillissementAlzheimer's AssociationParkinson's Disease FoundationVagelos College of Physicians and Surgeons, Columbia UniversityLeonard M. Miller School of MedicineUniversity of TorontoU.S. Department of Veterans AffairsSagol School of Neuroscience, Tel Aviv UniversityUniversity of California, San FranciscoBrookdale FoundationTel Aviv UniversityMayo ClinicMichael J. Fox Foundation for Parkinson's ResearchUniversity of South FloridaU.S. Department of Defense
KeywordsPenetranceLRRK2GeneticsDiseaseParkinson's diseaseGenome-wide association studyAlleleGenetic associationBiologyMutationMedicineOncologyInternal medicineGeneSingle-nucleotide polymorphismGenotypePhenotype

Abstract

fetched live from OpenAlex

Objective: The aim of this study was to search for genes/variants that modify the effect of LRRK2 mutations in terms of penetrance and age-at-onset of Parkinson's disease. Methods: We performed the first genome-wide association study of penetrance and age-at-onset of Parkinson's disease in LRRK2 mutation carriers (776 cases and 1,103 non-cases at their last evaluation). Cox proportional hazard models and linear mixed models were used to identify modifiers of penetrance and age-at-onset of LRRK2 mutations, respectively. We also investigated whether a polygenic risk score derived from a published genome-wide association study of Parkinson's disease was able to explain variability in penetrance and age-at-onset in LRRK2 mutation carriers. Results: A variant located in the intronic region of CORO1C on chromosome 12 (rs77395454; P-value=2.5E-08, beta=1.27, SE=0.23, risk allele: C) met genome-wide significance for the penetrance model. A region on chromosome 3, within a previously reported linkage peak for Parkinson's disease susceptibility, showed suggestive associations in both models (penetrance top variant: P-value=1.1E-07; age-at-onset top variant: P-value=9.3E-07). A polygenic risk score derived from publicly available Parkinson's disease summary statistics was a significant predictor of penetrance, but not of age-at-onset. Interpretation: This study suggests that variants within or near CORO1C may modify the penetrance of LRRK2 mutations. In addition, common Parkinson's disease associated variants collectively increase the penetrance of LRRK2 mutations.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.002
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMeta-epidemiology (narrow)
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.009
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.002
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0010.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.051
GPT teacher head0.305
Teacher spread0.254 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations10
Published2020
Admission routes2
Has abstractyes

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