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Record W3127587701 · doi:10.1002/mdc3.13158

Laboratory‐Supported Multiple System Atrophy beyond Autonomic Function Testing and Imaging: A Systematic Review by the <scp>MoDiMSA Study Group</scp>

2021· review· en· W3127587701 on OpenAlex
Iva Stanković, Alessandra Fanciulli, Vladimir Kostić, Florian Krismer, Wassilios G. Meissner, Jose‐Alberto Palma, Jalesh N. Panicker, Klaus Seppi, Gregor K. Wenning

Why this work is in the frame

A frame that forgets how it found something cannot be audited. These are the routes that admitted this work.

fundA Canadian funder is recorded on the work.
no affNo Canadian affiliation: this work is invisible to an affiliation-only frame.
No Canadian affiliation. An affiliation-only frame, the usual design, would never have seen this work. It is one of the works that make the case for inverting the frame.

Bibliographic record

VenueMovement Disorders Clinical Practice · 2021
Typereview
Languageen
FieldMedicine
TopicParkinson's Disease Mechanisms and Treatments
Canadian institutionsnot available
FundersFaculty of Medicine and Health, University of SydneyInstituto de Salud Carlos IIICanadian Institutes of Health ResearchMedical Research CouncilMontreal Neurological Institute and HospitalParkinsonfondenAOP OrphanSchool of Medicine, New York UniversityOno PharmaceuticalParkinson CanadaNIH Clinical CenterSun PharmaUniversity College London Hospitals NHS Foundation TrustUniversità degli Studi di SalernoRadboud Universitair Medisch CentrumHirosaki UniversityMedizinische Universität InnsbruckUniversitat de BarcelonaNational and Kapodistrian University of AthensMerz PharmaceuticalsAstellas PharmaUniversity of TokyoEisaiUniversità degli Studi di PadovaBundesministerium für GesundheitBundesministerium für Bildung und ForschungEli Lilly and CompanyRadboud UniversiteitInstitut National de la Santé et de la Recherche MédicaleSydney Medical SchoolH. Lundbeck A/SRosetrees TrustRheinische Friedrich-Wilhelms-Universität BonnNewcastle UniversityUniversity of SydneyUniversity College LondonUniversity of TorontoImperial College LondonUniversität InnsbruckPTC TherapeuticsUniversity of CambridgeMultiple System Atrophy CoalitionFondation Brain CanadaVanderbilt University Medical CenterUniversity of CyprusUniversité de ToulouseUniversity of OxfordSapienza Università di RomaBiogenAeglea BioTherapeuticsProthenaReta Lila Weston Institute of Neurological Studies, UCL Queen Square Institute of Neurology,University College LondonMichael J. Fox Foundation for Parkinson's ResearchJazz PharmaceuticalsUniversität RostockDeutsches Zentrum für Neurodegenerative ErkrankungenSunovionUniversità di BolognaEuropean CommissionDeutsche ForschungsgemeinschaftChristian-Albrechts-Universität zu KielCHDI FoundationMcGill UniversityAustrian Science FundU.S. Department of Veterans AffairsUniversity of PennsylvaniaVanderbilt UniversityUniversidade de LisboaInternational Parkinson and Movement Disorder SocietyNational Institutes of HealthDysautonomia FoundationNHLBI Division of Intramural ResearchNational Institute on AgingRobert Bosch StiftungEberhard Karls Universität TübingenYork UniversityBristol-Myers SquibbTeva Pharmaceutical IndustriesNational Parkinson FoundationPfizerDaiichi Sankyo CompanyMassachusetts General HospitalAarhus UniversitetSanofiOntario Brain InstituteNational Institute for Health and Care ResearchDaiichi Sankyo EuropeHarvard T.H. Chan School of Public HealthUniversidad Técnica Federico Santa MaríaUniversity of California, San DiegoCentro de Investigación Biomédica en Red sobre Enfermedades NeurodegenerativasJohns Hopkins UniversityParkinson Society Canada
KeywordsMedicineNeuroimagingAtrophyPure autonomic failureSpinocerebellar ataxiaREM sleep behavior disorderPhysical medicine and rehabilitationCerebellar ataxiaDementiaProgressive supranuclear palsyNeuropsychologyAutonomic functionNeuroradiologyAtaxiaNeurologyPathologyPediatricsParkinson's diseaseInternal medicineCognitionOrthostatic vital signsPsychiatryDisease

Abstract

fetched live from OpenAlex

BACKGROUND: Neuroimaging has been used to support a diagnosis of possible multiple system atrophy (MSA). Only blood pressure changes upon standing are included in the second consensus criteria but other autonomic function tests (AFT) are also useful to diagnose widespread and progressive autonomic failure typical of MSA. Additional diagnostic tools are of interest to improve accuracy of MSA diagnosis. OBJECTIVES: To assess the utility of diagnostic tools beyond brain imaging and AFT in enhancing a laboratory-supported diagnosis of MSA to support the upcoming revision of the consensus criteria. METHODS: The International Parkinson and Movement Disorders Society MSA Study Group (MoDiMSA) performed a systematic review of original papers on biomarkers, sleep studies, genetic, neuroendocrine, neurophysiological, neuropsychological and other tests including olfactory testing and acute levodopa challenge test published before August 2019. RESULTS: Evaluation of history of levodopa responsiveness and olfaction is useful in patients in whom MSA-parkinsonian subtype is suspected. Neuropsychological testing is useful to exclude dementia at time of diagnosis. Applicability of sphincter EMG is limited. When MSA-cerebellar subtype is suspected, a screening for the common causes of adult-onset progressive ataxia is useful, including spinocerebellar ataxias in selected patients. Diagnosing stridor and REM sleep behavior disorder is useful in both MSA subtypes. However, none of these tools are validated in large longitudinal cohorts of postmortem confirmed MSA cases. CONCLUSIONS: Despite limited evidence, additional laboratory work-up of patients with possible MSA beyond imaging and AFT should be considered to optimize the clinical diagnostic accuracy.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.005
metaresearch head score (Gemma)0.018
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMetaresearch, Meta-epidemiology (narrow)
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Systematic review · Consensus signal: none
GenreCandidate signal: Review · Consensus signal: Review
Teacher disagreement score0.619
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0050.018
Meta-epidemiology (narrow)0.0010.001
Meta-epidemiology (broad)0.0040.001
Bibliometrics0.0000.001
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.001
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.044
GPT teacher head0.361
Teacher spread0.317 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it