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Record W4396777491 · doi:10.1016/j.ekir.2024.04.062

Description and Cross-Sectional Analyses of 25,880 Adults and Children in the UK National Registry of Rare Kidney Diseases Cohort

2024· article· en· W4396777491 on OpenAlexaff
Katie Wong, David Pitcher, Fiona Braddon, Lewis Downward, Retha Steenkamp, Sherry Masoud, Nicholas M. P. Annear, Jonathan Barratt, Coralie Bingham, Richard J. Coward, Constantina Chrysochou, David Game, Siân Griffin, Matt Hall, Sally Johnson, Durga Kanigicherla, Fiona Karet Frankl, David Kavanagh, Larissa Kerecuk, Eamonn R. Maher, Shabbir H. Moochhala, Jenny Pinney, John A. Sayer, Roslyn Simms, Smeeta Sinha, Shalabh Srivastava, Frederick W.K. Tam, Kay Thomas, Neil Turner, Stephen B. Walsh, Aoife Waters, Patricia D. Wilson, Edwin Wong, Karla Therese L. Sy, Kui Huang, Jamie Ye, Dorothea Nitsch, Moin Saleem, Detlef Böckenhauer, Kate Bramham, Daniel P. Gale, Sharirose Abat, Shazia Adalat, Joy O. Agbonmwandolor, Zubaidah Ahmad, Abdulfattah Alejmi, Rashid Almasarwah, Ellie Asgari, Amanda Ayers, Jyoti Baharani, Gowrie Balasubramaniam, Felix Kpodo, Tarun Bansal, Alison Barratt, Megan Bates, Janet Bendle, Sarah Benyon, Carsten Bergmann, Sunil Bhandari, Preetham Boddana, Sally L. Bond, Angela Branson, Stephen Brearey, Vicky Brocklebank, Sharanjit Budwal, Conor Byrne, Hugh Cairns, Brian Camilleri, Gary Campbell, A. Capell, Margaret Carmody, Marion Carson, Tracy Cathcart, Christine Catley, Karine Cesar, Melanie Chan, Houda Chea, James Chess, Chee Kay Cheung, Katy-Jane Chick, Nihil Chitalia, Martin Christian, Katherine Clark, Christopher L. Clayton, Rhian Clissold, Helen Cockerill, Joshua Coelho, Elizabeth Colby, Viv Colclough, Eileen Conway, H. Terence Cook, Wendy L. Cook, Theresa Cooper, Sarah Crosbie, Gabor Cserep, Anjali Date, Katherine Davidson, Amanda Davies, Neeraj Dhaun, Ajay Dhaygude, Lynn Diskin, Abhijit Dixit, S Dorey, Lewis Downard, Mark T. Drayson, Gavin Dreyer, Tina Dutt, Kufreabasi Imo Etuk, Dawn Evans, Jenny Finch, Frances Flinter, James Fotheringham, Lucy Francis, Hugh Gallagher, Eva Lozano Garcia, Madita Gavrila, Susie Gear, Colin Geddes, Mark Gilchrist, Matthew Gittus, Paraskevi Goggolidou, Christopher Goldsmith, Patricia Gooden, Andrea Goodlife, Priyanka Goodwin, Tassos Grammatikopoulos, B. A. Gray, Megan Griffith, Steph Gumus, Sanjana Gupta, Patrick Hamilton, Lorraine Harper, Tess Harris, Louise Haskell, Samantha Hayward, Shivaram Hegde, Bruce M. Hendry, Sue Hewins, Nicola Hewitson, Kate Hillman, Mrityunjay Hiremath, A. G. Howson, Zay Htet, Sharon Huish, Richard Hull, A Humphries, David Hunt, Karl Hunter, Samantha Hunter, Marilyn Ijeomah-Orji, David Jayne, Gbemisola Jenfa, Alison Jenkins, Caroline Jones, Colin Jones, Amanda Jones, Rachel Jones, Lavanya Kamesh, Mahzuz Karim, Amrit Kaur, Kelly Kearley, Arif Khwaja, Garry C. King, Grant King, Ewa Kislowska, Edyta Klata, Maria Kokocinska, Mark Lambie, Laura Lawless, Thomas Ledson, Rachel Lennon, Adam P. Levine, Ling Wai Maggie Lai, Graham Lipkin, Graham Lovitt, Paul Lyons, Holly Mabillard, Katherine Mackintosh, Khalid Mahdi, Kevin J. Marchbank, Patrick B. Mark, Bridgett Masunda, Zainab Mavani, Jake Mayfair, Stephen P. McAdoo, Joanna Mckinnell, Nabil Melhem, Simon Meyrick, Putnam Morgan, Ann W Morgan, Fawad Muhammad, Shona Murray, Kristina Novobritskaya, Albert Ong, Louise Oni, Kate Osmaston, Neal Padmanabhan, Sharon Parkes, Jean Patrick, James Pattison, Riny Paul, Rachel Percival, Stephen J. Perkins, Alexandre Persu, William Petchey, Matthew C. Pickering, Jennifer H. Pinney, Lucy Plumb, Zoe Plummer, Joyce Popoola, Frank A. Post, Albert Power, Guy Pratt, Charles D. Pusey, Ria Rabara, May Rabuya, Tina Raju, Chadd Javier, Ian S D Roberts, Candice Roufosse, Adam Rumjon, Alan D. Salama, Richard Sandford, Kanwaljit S. Sandu, Nadia Sarween, Neil J. Sebire, Haresh Selvaskandan, Sapna Shah, Asheesh Sharma, Edward Sharples, Neil Sheerin, Harish Shetty, Rukshana Shroff, Manish D. Sinha, Kerry Smith, Lara Smith, Ian Stott, Katerina Stroud, Pauline A. Swift, Justyna Szklarzewicz, Fred Tam, Kay See Tan, Robert Taylor, Marc Tischkowitz, Yincent Tse, Alison E. Turnbull, Kay Tyerman, Miranda Usher, Gopalakrishnan Venkat‐Raman, Alycon Walker, Angela Watt, Phil Webster, Ashutosh Wechalekar, Gavin I. Welsh, Nicol West, David C. Wheeler, Kate Wiles, Lisa Willcocks, Angharad Williams, Emma Williams, Karen Williams, Deborah Wilson, Paul J.D. Winyard, Grahame Wood, Emma R. Woodward, Len Woodward, Adrian S. Woolf, David Wright

Bibliographic record

VenueKidney International Reports · 2024
Typearticle
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicGenetic and Kidney Cyst Diseases
Canadian institutionsInstitute of Infection and Immunity
FundersCliniques Universitaires Saint-LucLeeds Biomedical Research CentreGreat Ormond Street Institute of Child HealthMedical Research CouncilAkershus UniversitetssykehusFaculty of Medical Sciences, Newcastle UniversityNewcastle upon Tyne Hospitals NHS Foundation TrustCambridge University HospitalsNational Institute for Health and Care ResearchUniversity of LeedsUniversity College CorkNorthern Counties Kidney Research FundUniversity College LondonImperial College LondonNewcastle UniversityUniversity of CambridgeDirectorate for Biological SciencesFakultet Medicinskih Nauka, Univerziteta U KragujevcuKidney Research UKSanofiAlexion PharmaceuticalsPfizer
KeywordsMedicineCohortCross-sectional studyCohort studyPediatricsFamily medicineInternal medicinePathology

Abstract

fetched live from OpenAlex

IntroductionThe National Registry of Rare Kidney Diseases (RaDaR) collects data from people living with rare kidney diseases across the UK, and is the world’s largest rare kidney disease registry. We present the clinical demographics and renal function of 25,880 prevalent patients and sought evidence of bias in recruitment to RaDaR.MethodsRaDaR is linked with the UK Renal Registry (UKRR, with which all UK patients receiving Kidney Replacement Therapy (KRT) are registered). We assessed ethnicity and socioeconomic status in: 1) prevalent RaDaR patients receiving KRT compared with patients with eligible rare disease diagnoses receiving KRT in the UKRR; 2) patients recruited to RaDaR compared with all eligible unrecruited patients at two renal centres; 3) the age-stratified ethnicity distribution of RaDaR patients with Autosomal Dominant Polycystic Kidney Disease was compared to that of the English Census.ResultsWe found evidence of disparities in ethnicity and social deprivation in recruitment to RaDaR, however these were not consistent across comparisons. Compared with either adults recruited to RaDaR or the English population, children recruited to RaDaR were more likely to be of Asian ethnicity (17.3% vs 7.5% , p-value < 0.0001) and live in more socially deprived areas (30.3% vs 17.3% in the most deprived IMD quintile, p-value < 0.0001).ConclusionWe observed no evidence of systematic biases in recruitment of patients into RaDaR but the data provide empirical evidence of negative economic and social consequences (across all ethnicities) experienced by families with children affected by rare kidney diseases.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.001
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.021
Threshold uncertainty score0.402

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.001
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.013
GPT teacher head0.304
Teacher spread0.291 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations10
Published2024
Admission routes1
Has abstractyes

Explore more

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