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Record W4399359365 · doi:10.1038/s41588-024-01763-1

Genome-wide meta-analyses of restless legs syndrome yield insights into genetic architecture, disease biology and risk prediction

2024· review· en· W4399359365 on OpenAlexafffund
Barbara Schormair, Chen Zhao, Steven Bell, Maria Didriksen, Muhammad Sulaman Nawaz, Nathalie Schandra, Ambra Stefani, Birgit Högl, Yves Dauvilliers, Cornelius G. Bachmann, David Kemlink, Karel Šonka, Walter Paulus, Claudia Trenkwalder, Wolfgang H. Oertel, Magdolna Hornyak, Maris Teder‐Laving, Andres Metspalu, Georgios M. Hadjigeorgiou, Olli Polo, Ingo Fietze, Owen A. Ross, Zbigniew K. Wszołek, Abubaker Ibrahim, Melanie Bergmann, Volker Kittke, Philip Harrer, Joseph Dowsett, Sofiène Chenini, Sisse Rye Ostrowski, Erik Sørensen, Christian Erikstrup, Ole Birger Pedersen, Mie Topholm Bruun, Kaspar René Nielsen, Adam S. Butterworth, Nicole Soranzo, Willem H. Ouwehand, David J. Roberts, John Danesh, Brendan Burchell, Nicholas A. Furlotte, Priyanka Nandakumar, Amélie Bonnefond, Louis Potier, Christopher J. Earley, William G. Ondo, Lan Xiong, Alex Désautels, Markus Perola, Pavel Vodička, Christian Dina, Monika Stoll, André Franke, Wolfgang Lieb, Alexandre F.R. Stewart, Svati H. Shah, Christian Gieger, Annette Peters, David B. Rye, Guy A. Rouleau, Klaus Berger, Hreinn Stefánsson, Henrik Ullum, David A. Hinds, Emanuele Di Angelantonio, Konrad Oexle, Juliane Winkelmann

Bibliographic record

VenueNature Genetics · 2024
Typereview
Languageen
FieldMedicine
TopicRestless Legs Syndrome Research
Canadian institutionsCanadian Heart Research CentreUniversity of OttawaUniversité de MontréalHôpital du Sacré-Cœur de MontréalMcGill UniversityCanadian Sleep & Circadian NetworkMontreal Neurological Institute and Hospital
FundersNIHR Cambridge Biomedical Research CentreLeibniz-GemeinschaftScience and Technology Facilities CouncilEconomic and Social Research CouncilNatural Sciences and Engineering Research Council of CanadaCanadian Institutes of Health ResearchNIHR BioResourceDanmarks Frie ForskningsfondDell EMCDeutsche ForschungsgemeinschaftHealth and Social Care Research and Development DivisionNovo NordiskPublic Health AgencyEngineering and Physical Sciences Research CouncilUniversity of ThessalyEuropean CommissionMedical Research CouncilDepartment of Health and Social CareEuropean Regional Development FundBundesministerium für Bildung und ForschungNational Institute on AgingNHS Blood and TransplantNational Institute for Health and Care ResearchHeart and Stroke Foundation of CanadaNovo Nordisk FondenNational Institute of Neurological Disorders and StrokeBritish Heart FoundationUniversity of CambridgeWellcome TrustCancer Research UKHelmholtz Zentrum MünchenWestfälische Wilhelms-Universität MünsterEmory UniversityChief Scientist Office, Scottish Government Health and Social Care DirectorateScottish GovernmentNational Institutes of HealthUniverzita Karlova v PrazeRestless Legs Syndrome Foundation
KeywordsBiologyMendelian randomizationGenome-wide association studyGenetic architectureDiseaseLocus (genetics)Genetics1000 Genomes ProjectDrug repositioningRestless legs syndromeEpistasisBioinformaticsComputational biologyGeneQuantitative trait locusDrugInternal medicineGenotypeSingle-nucleotide polymorphismGenetic variantsMedicineNeuroscience

Abstract

fetched live from OpenAlex

Abstract Restless legs syndrome (RLS) affects up to 10% of older adults. Their healthcare is impeded by delayed diagnosis and insufficient treatment. To advance disease prediction and find new entry points for therapy, we performed meta-analyses of genome-wide association studies in 116,647 individuals with RLS (cases) and 1,546,466 controls of European ancestry. The pooled analysis increased the number of risk loci eightfold to 164, including three on chromosome X. Sex-specific meta-analyses revealed largely overlapping genetic predispositions of the sexes ( r g = 0.96). Locus annotation prioritized druggable genes such as glutamate receptors 1 and 4, and Mendelian randomization indicated RLS as a causal risk factor for diabetes. Machine learning approaches combining genetic and nongenetic information performed best in risk prediction (area under the curve (AUC) = 0.82–0.91). In summary, we identified targets for drug development and repurposing, prioritized potential causal relationships between RLS and relevant comorbidities and risk factors for follow-up and provided evidence that nonlinear interactions are likely relevant to RLS risk prediction.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.006
metaresearch head score (Gemma)0.011
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Meta-analysis · Consensus signal: none
GenreCandidate signal: Review · Consensus signal: Review
Teacher disagreement score0.006
Threshold uncertainty score0.033

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0060.011
Meta-epidemiology (narrow)0.0020.001
Meta-epidemiology (broad)0.0060.010
Bibliometrics0.0030.004
Science and technology studies0.0000.000
Scholarly communication0.0020.001
Open science0.0010.001
Research integrity0.0010.002
Insufficient payload (model declined to judge)0.0030.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.113
GPT teacher head0.422
Teacher spread0.309 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designMeta-analysis
Domainnot available
GenreReview

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations52
Published2024
Admission routes2
Has abstractyes

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