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Record W4399420010 · doi:10.1016/j.nsa.2024.104075

Co-expression of prepulse inhibition and Schizophrenia genes in the mouse and human brain

2024· article· en· W4399420010 on OpenAlex
Lillian Garrett, Dietrich Trümbach, Donghyung Lee, Silvia Mandillo, Rodney C. Samaco, Ann M. Flenniken, Michelle L. Stewart, Juan A. Aguilar-Pimental, Oana V. Amarie, Lore Becker, Julia Calzada‐Wack, Patricia da Silva‐Buttkus, Nathalia Romanelli Vicente Dragano, Markus Kraiger, Christoph Lengger, Stefanie Leuchtenberger, Susan Marschall, Manuela A. Oestereicher, Birgit Rathkolb, Adrián Sanz‐Moreno, Claudia Seisenberger, Nadine Spielmann, Claudia Stoeger, Vivek Kumar, Piia Keskivali, Ruairidh King, Hamed Haselimashhadi, Alexandr Bezginov, Clare Norris, Sarah E. Taylor, Dale Pimm, Lois Kelsey, Zorana Berberovic, Dawei Qu, Abigail D’Souza, Vivian Bradaschia, Mohammed Eskandarian, Xueyuan Shang, Kyle Duffin, Kyle Roberton, Catherine K. Xu, Gloria Baguinat, Valerie Laurin, Qing Lan, Gillian Sleep, Lauri G. Lintott, Marina Gertsenstein, Sandra Tondat, Maribelle Cruz, D. Craig Miller, Tania Sorg, Fabrice Riet, Heather Tolentino, Todd Tolentino, Mike Schuchbauer, Nichole Hockenbury, Karrie Beeman, Sheryl Pedroia, Jason Salazar, Mollie A. Heffner, Joanne Hsu, Colin Fletcher, Maya Vanzanten, Elisabetta Golini, John R. Seavitt, Denise G. Lanza, Isabel Lorenzo, Angelina Gaspero, Amanda Rios, Jacqueline K. White, Colin McKerlie, Lauryl M. J. Nutter, Igor Vukobradovic, Surabi Veeraragavan, Lisa Yuva, Jason D. Heaney, Mary E. Dickinson, Hamid Méziane, Yann Hérault, Sara Wells, K. C. Kent Lloyd, Lynette Bower, Louise Lanoue, Dave Clary, Annemarie Zimprich, Valérie Gailus‐Durner, Helmut Fuchs, Steve D. M. Brown, Elissa J. Chesler, Wolfgang Wurst, Martin Hrabě de Angelis, Sabine M. Hölter

Why this work is in the frame

A frame that forgets how it found something cannot be audited. These are the routes that admitted this work.

affAt least one author lists a Canadian institution in the pinned OpenAlex snapshot.
fundA Canadian funder is recorded on the work.

Bibliographic record

VenueNeuroscience Applied · 2024
Typearticle
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicGenetic Associations and Epidemiology
Canadian institutionsUniversity of TorontoHospital for Sick ChildrenToronto Centre for PhenogenomicsLunenfeld-Tanenbaum Research Institute
FundersNational Institutes of HealthPHENOMININFRAFRONTIERAgence Nationale de la RechercheGenome CanadaOntario GenomicsBundesministerium für Bildung und Forschung
KeywordsBiologyEndophenotypeDISC1Schizophrenia (object-oriented programming)Prepulse inhibitionGeneticsPhenotypeGenome-wide association studyGeneNeuroscienceCandidate geneComputational biologyPsychologySingle-nucleotide polymorphismPsychiatry

Abstract

fetched live from OpenAlex

Schizophrenia is a complex psychiatric disorder with genetic and phenotypic heterogeneity. Accumulating rare and genome-wide association study (GWAS) common risk variant information has yet to yield robust mechanistic insight. Leveraging large-scale gene deletion mouse phenomic data thus has potential to functionally interrogate and prioritize human disease genes. To this end, we applied a cross-species network-based approach to parse an extensive mouse gene set (188 genes) associated with disrupted prepulse inhibition (PPI), a Schizophrenia endophenotype. Integrating PPI genes with high-resolution mouse and human brain transcriptomic data, we identified functional and disease coherent co-expression modules through hierarchical clustering and weighted gene co-expression network analysis (WGCNA). In two modules, Schizophrenia risk and mouse PPI genes converged based on telencephalic patterning. The associated neuronal genes were highly expressed in cingulate cortex- and hippocampus; implicated in synaptic function and neurotransmission and overlapped with the greatest proportion of rare variants. Concordant neuroanatomical patterning revealed novel core Schizophrenia-relevant genes consistent with the Omnigenic hypothesis of complex traits. Among other genes discussed, the developmental and post-synaptic scaffold TANC2 (Tetratricopeptide repeat, ankyrin repeat and coiled-coil containing 2) emerged from both networks as a novel core genetic driver of Schizophrenia altering PPI. Aspects of psychiatric disease comorbidity and phenotypic heterogeneity are also explored. Overall, this study provides a framework and galvanizes the value of mouse preclinical genetics and PPI to prioritize both existing and novel human Schizophrenia candidate genes as druggable targets.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Bench or experimental · Consensus signal: Bench or experimental
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.280
Threshold uncertainty score0.168

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.014
GPT teacher head0.285
Teacher spread0.271 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it