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Record W4407632561 · doi:10.1038/s41467-025-56855-1

Copy number variants and the tangential expansion of the cerebral cortex

2025· article· en· W4407632561 on OpenAlexafffund
Zhijie Liao, Kuldeep Kumar, Jakub Kopál, Guillaume Huguet, Zohra Saci, Martineau Jean‐Louis, Zdenka Pausová, Igor Jurišica, Carrie E. Bearden, Sébastien Jacquemont, Tomáš Paus

Bibliographic record

VenueNature Communications · 2025
Typearticle
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicGenomic variations and chromosomal abnormalities
Canadian institutionsDiscovery CentreHospital for Sick ChildrenUniversity Health NetworkSickKids FoundationMila - Quebec Artificial Intelligence InstituteUniversity of TorontoMcGill UniversityUniversité de MontréalCentre Hospitalier Universitaire Sainte-Justine
FundersNational Institute on Drug AbuseNational Center for Mental HealthMedical Research CouncilNational Institute of Biomedical Imaging and BioengineeringCanadian Institutes of Health ResearchNational Institutes of HealthCentre Hospitalier Universitaire VaudoisNational Institute of Mental HealthFondation pour la Recherche MédicaleMission Interministérielle de Lutte Contre les Drogues et les Conduites AddictivesScience Foundation IrelandFondation Brain CanadaEuropean CommissionCIHR Skin Research Training CentreFondation de FranceBundesministerium für Bildung und ForschungNational Institute on AgingNational Institute for Health and Care ResearchHealth and Care Research WalesDeutsche ForschungsgemeinschaftSouth London and Maudsley NHS Foundation TrustGovernment of CanadaSimons Foundation Autism Research InitiativeCompute CanadaKing's College LondonInstitut National de la Santé et de la Recherche MédicaleSchweizerischer Nationalfonds zur Förderung der Wissenschaftlichen ForschungWellcome TrustFondation de l'Avenir pour la Recherche Médicale AppliquéeAgence Nationale de la RechercheFédération pour la Recherche sur le CerveauHeart and Stroke Foundation of Canada
KeywordsCerebral cortexCopy-number variationBiologyNeuroscienceGeneticsComputational biologyGenomeGene

Abstract

fetched live from OpenAlex

The tangential expansion of the human cerebral cortex, indexed by its surface area (SA), occurs mainly during prenatal and early postnatal periods, and is influenced by genetic factors. Here we investigate the role of rare copy number variants (CNVs) in shaping SA, and the underlying mechanisms, by aggregating CNVs across the genome in community-based cohorts (N = 39,015). We reveal that genome-wide CNV deletions and duplications are associated with smaller SA. Subsequent analyses with gene expression in fetal cortex suggest that CNVs influence SA by interrupting the proliferation of neural progenitor cells during fetal development. Notably, the deletion of genes with strong (but not weak) coexpression with neural progenitor genes is associated with smaller SA. Follow up analyses reveal similar mechanisms at play in three clinical CNVs, 1q21.1, 16p11.2 and 22q11.2. Together, this study of rare CNVs expands our knowledge about genetic architecture of human cerebral cortex. Variation in cortical surface area in adults can reflect developmental events occurring during prenatal and early postnatal periods. Here, the authors find rare copy number variants associated with cortical surface area, which are also found to disrupt neural progenitor proliferation during fetal development.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.002
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Bench or experimental · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.002
Threshold uncertainty score0.006

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0000.002
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0010.001
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0020.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.005
GPT teacher head0.253
Teacher spread0.248 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designBench or experimental
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations3
Published2025
Admission routes2
Has abstractyes

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