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Record W4411325928 · doi:10.1111/ijlh.14513

Molecular Testing in Sickle Cell Disease: From Newborn Screening to Transfusion Care

2025· review· en· W4411325928 on OpenAlexaff
Thomas Pincez, Yves Pastore

Bibliographic record

VenueInternational Journal of Laboratory Hematology · 2025
Typereview
Languageen
FieldMedicine
TopicHemoglobinopathies and Related Disorders
Canadian institutionsUniversité de MontréalCentre Hospitalier Universitaire Sainte-Justine
Fundersnot available
KeywordsGenotypingDiseaseMedicinePopulationNewborn screeningPrenatal diagnosisMolecular diagnosticsComputational biologyBioinformaticsIntensive care medicineBiologyPregnancyPathologyPediatricsGeneticsGeneGenotype

Abstract

fetched live from OpenAlex

Sickle cell disease (SCD) is one of the most frequent monogenic diseases worldwide and a highly heterogeneous and complex disease. SCD care carries several challenges. This includes early and accurate diagnosis as well as optimal red blood cell transfusion matching in this population carrying a high risk of alloimmunization. For decades, molecular biology has used hemoglobin and SCD as models for the development of several molecular tools. Such tools can now be used for various aspects of SCD care. Molecular diagnosis is notably the root of noninvasive prenatal testing. In postnatal diagnosis, including newborn screening, molecular approaches can overcome several limitations of protein-based methods. Simple approaches such as polymerase chain reaction can be used as a high-throughput and low-cost screening test. Moreover, combining sequence and deletion analyses allows for a comprehensive study of the β-globin locus, resolving complex cases. In transfusion care, genotyping for blood group determination has been shown to be more accurate compared to protein-based serological testing. Future development of molecular testing in SCD includes their use as prognostic tools and recent molecular diagnosis approaches. However, despite carrying major advantages, molecular testing may also present some limitations, such as high cost, limited accessibility in many countries, and limited information using targeted approaches. Molecular testing has a different pattern of advantages and limitations than protein-based analyses. Therefore, the optimal use of molecular testing is frequently not as a standalone approach but in combination with protein-based techniques. The optimal combination depends on the resources available and the clinical challenge, to ultimately improve SCD care.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.001
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMeta-epidemiology (narrow)
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Other design · Consensus signal: none
GenreCandidate signal: Review · Consensus signal: Review
Teacher disagreement score0.964
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.001
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0010.000
Bibliometrics0.0010.001
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.001
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.015
GPT teacher head0.320
Teacher spread0.305 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

Study designOther design
Domainnot available
GenreReview

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations2
Published2025
Admission routes1
Has abstractyes

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