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Record W4413098416 · doi:10.7759/cureus.89002

Aphasia Leading to the Diagnosis of Myotonic Dystrophy Type 1: A Case Report

2025· article· en· W4413098416 on OpenAlexaboutno aff
Shinichiro Maeshima, Akinori Takeda, Keita Sakurai, Aiko Osawa, Hidenori Arai

Bibliographic record

VenueCureus · 2025
Typearticle
Languageen
FieldNeuroscience
TopicGenetic Neurodegenerative Diseases
Canadian institutionsnot available
Fundersnot available
KeywordsMedicineMyotonic dystrophyAphasiaPediatricsAudiologyPhysical medicine and rehabilitationPsychiatryInternal medicine

Abstract

fetched live from OpenAlex

Myotonic dystrophy type 1 (DM1) is a multisystem autosomal dominant disorder primarily characterized by myotonia and distal muscle weakness. Central nervous system (CNS) involvement, including cognitive, executive, and emotional dysfunctions, is increasingly being recognized; however, language impairment as an initial presentation is rare. A 50-year-old right-handed woman with a six-month history of progressive word-finding difficulty, vague speech, and social withdrawal was referred for evaluation. Neurological examination revealed distal muscle atrophy (grip strength: 5 kg right, 8 kg left) without overt dysarthria or dysphagia, and intact reflexes and coordination. Neuropsychological testing revealed fluent spontaneous speech with anomia, semantic paraphasia, impaired comprehension of longer sentences, and surface dyslexia/agraphia (Mini-Mental State Examination-Japanese: 22/30, Frontal Assessment Battery: 8/18, Raven's Colored Progressive Matrices: 28/36, Montreal Cognitive Assessment-Japanese: 21/30). Brain magnetic resonance imaging revealed left-sided frontotemporal and limbic atrophy, and 99mTc-ethyl cysteinate dimer single-photon emission computed tomography showed a corresponding left-dominant hypoperfusion. Amyloid positron emission tomography (PET) scan results were negative. Two weeks later, percussion and grip myotonia emerged. Genetic analysis revealed a cytosine-thymine-guanine repeat expansion (~1500 repeats) in the myotonic protein kinase 1 gene, confirming the diagnosis of DM1. The patient's semantic‐variant primary progressive aphasia-like profile (impaired semantic processing with preserved fluency) and frontotemporal imaging findings were consistent with rare CNS phenotypes reported in DM1. Previous studies have described frontotemporal atrophy, hypoperfusion, and cognitive/emotional changes in DM1. Negative amyloid PET excluded Alzheimer-related primary progressive aphasia. The subsequent detection of myotonia and a positive family history were key to diagnosis. We conclude that this case expands the clinical spectrum of DM1 to include progressive aphasia as an initial manifestation. Clinicians should maintain a high suspicion of neuromuscular disorders and actively pursue targeted genetic testing when atypical aphasia symptoms are accompanied by distal muscle atrophy.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.001
metaresearch head score (Gemma)0.004
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Case report · Consensus signal: Case report
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.008
Threshold uncertainty score0.019

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0010.004
Meta-epidemiology (narrow)0.0040.002
Meta-epidemiology (broad)0.0020.003
Bibliometrics0.0060.003
Science and technology studies0.0050.003
Scholarly communication0.0030.003
Open science0.0030.003
Research integrity0.0080.005
Insufficient payload (model declined to judge)0.0030.002

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.048
GPT teacher head0.333
Teacher spread0.285 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designCase report
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations0
Published2025
Admission routes1
Has abstractyes

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