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Record W4415453884 · doi:10.1210/jendso/bvaf149.806

SAT-251 Massive Tissue Deposition Of Cholesterol Leading To Multi-organ Failure In Cholestatic Hypercholesterolemia

2025· article· en· W4415453884 on OpenAlexaff
Daniel R. Barros, Brian G. Ballios, Yogesh Patoida, Shaun Singer, Cheryl F. Rosen, Michael A. Seidman, Robert A. Hegele, G F Lewis

Bibliographic record

VenueJournal of the Endocrine Society · 2025
Typearticle
Languageen
FieldImmunology and Microbiology
TopicBiosimilars and Bioanalytical Methods
Canadian institutionsUniversity Health NetworkToronto Rehabilitation InstituteUniversity of TorontoRobarts Clinical TrialsWestern University
Fundersnot available
KeywordsPlasmapheresisCholesterolRetinalKidney diseaseDisease

Abstract

fetched live from OpenAlex

Abstract Disclosure: D.R. Barros: None. B.G. Ballios: None. Y. Patoida: None. S. Singer: None. C.F. Rosen: None. M.A. Seidman: None. R.A. Hegele: None. G.F. Lewis: None. Background: Cholestasis-induced severe hypercholesterolemia can result in various complications, including xanthomas, although atherosclerosis is not a consistent feature. However, deposition of lipids in organs beyond the skin and tendons secondary to hepatobiliary dysfunction, to the point of eliciting organ dysfunction or failure, has not previously been reported. Case Presentations: Here we present two cases of marked hypercholesterolemia resulting from hepatobiliary disease. Patient 1 presented at a later stage of disease progression, with markedly elevated plasma cholesterol at 62.2 mmol/L (N<5.2 mmol/L) and triglycerides at 3.83 mmol/L (N<1.7 mmol/L). Massive cholesterol deposition in his retinas led to profound vision loss, while myocardium and kidney lipid infiltration ultimately resulted in fatal cardiorenal failure. Patient 2 presented with a lesser degree of hypercholesterolemia, with plasma cholesterol at 18.4 mmol/L. He was noted to have retinal cholesterol deposition without vision loss, along with extensive pruritic and painful tuberoeruptive xanthomas. Management and Outcome: Both patients were treated with weekly or biweekly plasmapheresis to prevent further disease progression, which successfully lowered plasma cholesterol to 6.92 and 5.88 mmol/L in patients 1 and 2, respectively. The multi-organ lipid deposition of patient 1 proved to be irremediable despite plasma exchange therapy. In contrast, six months of biweekly plasmapheresis in patient 2 yielded marked resolution of xanthomas and halted progression of retinal disease and vision loss. These cases reveal previously unappreciated non-atherosclerotic clinical consequences of severe hypercholesterolemia secondary to cholestatic liver disease, which can be ameliorated if detected early and treated with serial plasma exchange. Presentation: Saturday, July 12, 2025

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Bench or experimental · Consensus signal: Bench or experimental
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.080
Threshold uncertainty score0.422

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.001
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.014
GPT teacher head0.317
Teacher spread0.302 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designBench or experimental
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations0
Published2025
Admission routes1
Has abstractyes

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